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CYB5R3 in type II alveolar epithelial cells protects against lung fibrosis by suppressing TGF-β1 signaling

Type II alveolar epithelial cell (AECII) redox imbalance contributes to the pathogenesis of idiopathic pulmonary fibrosis (IPF), a deadly disease with limited treatment options. Here, we show that expression of membrane-bound cytochrome B5 reductase 3 (CYB5R3), an enzyme critical for maintaining cel...

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Autores principales: Bueno, Marta, Calyeca, Jazmin, Khaliullin, Timur, Miller, Megan P., Alvarez, Diana, Rosas, Lorena, Brands, Judith, Baker, Christian, Nasser, Amro, Shulkowski, Stephanie, Mathien, August, Uzoukwu, Nneoma, Sembrat, John, Mays, Brenton G., Fiedler, Kaitlin, Hahn, Scott A., Salvatore, Sonia R., Schopfer, Francisco J., Rojas, Mauricio, Sandner, Peter, Straub, Adam C., Mora, Ana L.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: American Society for Clinical Investigation 2023
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10077481/
https://www.ncbi.nlm.nih.gov/pubmed/36749633
http://dx.doi.org/10.1172/jci.insight.161487
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author Bueno, Marta
Calyeca, Jazmin
Khaliullin, Timur
Miller, Megan P.
Alvarez, Diana
Rosas, Lorena
Brands, Judith
Baker, Christian
Nasser, Amro
Shulkowski, Stephanie
Mathien, August
Uzoukwu, Nneoma
Sembrat, John
Mays, Brenton G.
Fiedler, Kaitlin
Hahn, Scott A.
Salvatore, Sonia R.
Schopfer, Francisco J.
Rojas, Mauricio
Sandner, Peter
Straub, Adam C.
Mora, Ana L.
author_facet Bueno, Marta
Calyeca, Jazmin
Khaliullin, Timur
Miller, Megan P.
Alvarez, Diana
Rosas, Lorena
Brands, Judith
Baker, Christian
Nasser, Amro
Shulkowski, Stephanie
Mathien, August
Uzoukwu, Nneoma
Sembrat, John
Mays, Brenton G.
Fiedler, Kaitlin
Hahn, Scott A.
Salvatore, Sonia R.
Schopfer, Francisco J.
Rojas, Mauricio
Sandner, Peter
Straub, Adam C.
Mora, Ana L.
author_sort Bueno, Marta
collection PubMed
description Type II alveolar epithelial cell (AECII) redox imbalance contributes to the pathogenesis of idiopathic pulmonary fibrosis (IPF), a deadly disease with limited treatment options. Here, we show that expression of membrane-bound cytochrome B5 reductase 3 (CYB5R3), an enzyme critical for maintaining cellular redox homeostasis and soluble guanylate cyclase (sGC) heme iron redox state, is diminished in IPF AECIIs. Deficiency of CYB5R3 in AECIIs led to sustained activation of the pro-fibrotic factor TGF-β1 and increased susceptibility to lung fibrosis. We further show that CYB5R3 is a critical regulator of ERK1/2 phosphorylation and the sGC/cGMP/protein kinase G axis that modulates activation of the TGF-β1 signaling pathway. We demonstrate that sGC agonists (BAY 41-8543 and BAY 54-6544) are effective in reducing the pulmonary fibrotic outcomes of in vivo deficiency of CYB5R3 in AECIIs. Taken together, these results show that CYB5R3 in AECIIs is required to maintain resilience after lung injury and fibrosis and that therapeutic manipulation of the sGC redox state could provide a basis for treating fibrotic conditions in the lung and beyond.
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spelling pubmed-100774812023-04-07 CYB5R3 in type II alveolar epithelial cells protects against lung fibrosis by suppressing TGF-β1 signaling Bueno, Marta Calyeca, Jazmin Khaliullin, Timur Miller, Megan P. Alvarez, Diana Rosas, Lorena Brands, Judith Baker, Christian Nasser, Amro Shulkowski, Stephanie Mathien, August Uzoukwu, Nneoma Sembrat, John Mays, Brenton G. Fiedler, Kaitlin Hahn, Scott A. Salvatore, Sonia R. Schopfer, Francisco J. Rojas, Mauricio Sandner, Peter Straub, Adam C. Mora, Ana L. JCI Insight Research Article Type II alveolar epithelial cell (AECII) redox imbalance contributes to the pathogenesis of idiopathic pulmonary fibrosis (IPF), a deadly disease with limited treatment options. Here, we show that expression of membrane-bound cytochrome B5 reductase 3 (CYB5R3), an enzyme critical for maintaining cellular redox homeostasis and soluble guanylate cyclase (sGC) heme iron redox state, is diminished in IPF AECIIs. Deficiency of CYB5R3 in AECIIs led to sustained activation of the pro-fibrotic factor TGF-β1 and increased susceptibility to lung fibrosis. We further show that CYB5R3 is a critical regulator of ERK1/2 phosphorylation and the sGC/cGMP/protein kinase G axis that modulates activation of the TGF-β1 signaling pathway. We demonstrate that sGC agonists (BAY 41-8543 and BAY 54-6544) are effective in reducing the pulmonary fibrotic outcomes of in vivo deficiency of CYB5R3 in AECIIs. Taken together, these results show that CYB5R3 in AECIIs is required to maintain resilience after lung injury and fibrosis and that therapeutic manipulation of the sGC redox state could provide a basis for treating fibrotic conditions in the lung and beyond. American Society for Clinical Investigation 2023-03-08 /pmc/articles/PMC10077481/ /pubmed/36749633 http://dx.doi.org/10.1172/jci.insight.161487 Text en © 2023 Bueno et al. https://creativecommons.org/licenses/by/4.0/This work is licensed under the Creative Commons Attribution 4.0 International License. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/ (https://creativecommons.org/licenses/by/4.0/) .
spellingShingle Research Article
Bueno, Marta
Calyeca, Jazmin
Khaliullin, Timur
Miller, Megan P.
Alvarez, Diana
Rosas, Lorena
Brands, Judith
Baker, Christian
Nasser, Amro
Shulkowski, Stephanie
Mathien, August
Uzoukwu, Nneoma
Sembrat, John
Mays, Brenton G.
Fiedler, Kaitlin
Hahn, Scott A.
Salvatore, Sonia R.
Schopfer, Francisco J.
Rojas, Mauricio
Sandner, Peter
Straub, Adam C.
Mora, Ana L.
CYB5R3 in type II alveolar epithelial cells protects against lung fibrosis by suppressing TGF-β1 signaling
title CYB5R3 in type II alveolar epithelial cells protects against lung fibrosis by suppressing TGF-β1 signaling
title_full CYB5R3 in type II alveolar epithelial cells protects against lung fibrosis by suppressing TGF-β1 signaling
title_fullStr CYB5R3 in type II alveolar epithelial cells protects against lung fibrosis by suppressing TGF-β1 signaling
title_full_unstemmed CYB5R3 in type II alveolar epithelial cells protects against lung fibrosis by suppressing TGF-β1 signaling
title_short CYB5R3 in type II alveolar epithelial cells protects against lung fibrosis by suppressing TGF-β1 signaling
title_sort cyb5r3 in type ii alveolar epithelial cells protects against lung fibrosis by suppressing tgf-β1 signaling
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10077481/
https://www.ncbi.nlm.nih.gov/pubmed/36749633
http://dx.doi.org/10.1172/jci.insight.161487
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