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A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report

INTRODUCTION AND IMPORTANCE: Choledochal cysts are rare congenital bile duct anomalies that lead to cystic dilatations of the biliary tree. This condition is very rare in Africa. When these cysts exceed 10 cm in diameter, they are referred to as giant choledochal cysts, which are much rarer. Giant c...

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Autores principales: Atwine, Oscar, Odongo, Charles Newton, Ainomugisha, Racheal, Tayebwa, Edson, Muhumuza, Joshua, Dreque, Carlos Cabrera
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2023
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10189257/
https://www.ncbi.nlm.nih.gov/pubmed/37148731
http://dx.doi.org/10.1016/j.ijscr.2023.108284
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author Atwine, Oscar
Odongo, Charles Newton
Ainomugisha, Racheal
Tayebwa, Edson
Muhumuza, Joshua
Dreque, Carlos Cabrera
author_facet Atwine, Oscar
Odongo, Charles Newton
Ainomugisha, Racheal
Tayebwa, Edson
Muhumuza, Joshua
Dreque, Carlos Cabrera
author_sort Atwine, Oscar
collection PubMed
description INTRODUCTION AND IMPORTANCE: Choledochal cysts are rare congenital bile duct anomalies that lead to cystic dilatations of the biliary tree. This condition is very rare in Africa. When these cysts exceed 10 cm in diameter, they are referred to as giant choledochal cysts, which are much rarer. Giant choledochal cysts present both a diagnostic and surgical challenge. We present a case of a giant Choledochal cyst surgically managed in a resource limited setting with excellent outcome. CASE PRESENTATION: A 17-year-old female presented with 4 months history of progressive abdominal distension associated with abdominal pain, yellow discoloration of eyes, and occasional constipation. Abdominal CT-scan revealed a huge cystic mass in the right upper quadrant extending inferiorly to the right lumbar region. Complete excision of a type IA choledochal cyst was done plus cholecystectomy in addition to bilioenteric reconstruction. The patient recovered uneventfully. DISCUSSION AND CONCLUSION: To the best of our knowledge, this is the largest giant Choledochal cyst reported in literature. Even in a resource limited settings, sonography and a CT scan may be all that is required to make a diagnosis. During surgical excision, the surgeon should take extra caution to carefully dissect the adhesions off the giant cyst for a successful complete excision.
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spelling pubmed-101892572023-05-18 A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report Atwine, Oscar Odongo, Charles Newton Ainomugisha, Racheal Tayebwa, Edson Muhumuza, Joshua Dreque, Carlos Cabrera Int J Surg Case Rep Case Report INTRODUCTION AND IMPORTANCE: Choledochal cysts are rare congenital bile duct anomalies that lead to cystic dilatations of the biliary tree. This condition is very rare in Africa. When these cysts exceed 10 cm in diameter, they are referred to as giant choledochal cysts, which are much rarer. Giant choledochal cysts present both a diagnostic and surgical challenge. We present a case of a giant Choledochal cyst surgically managed in a resource limited setting with excellent outcome. CASE PRESENTATION: A 17-year-old female presented with 4 months history of progressive abdominal distension associated with abdominal pain, yellow discoloration of eyes, and occasional constipation. Abdominal CT-scan revealed a huge cystic mass in the right upper quadrant extending inferiorly to the right lumbar region. Complete excision of a type IA choledochal cyst was done plus cholecystectomy in addition to bilioenteric reconstruction. The patient recovered uneventfully. DISCUSSION AND CONCLUSION: To the best of our knowledge, this is the largest giant Choledochal cyst reported in literature. Even in a resource limited settings, sonography and a CT scan may be all that is required to make a diagnosis. During surgical excision, the surgeon should take extra caution to carefully dissect the adhesions off the giant cyst for a successful complete excision. Elsevier 2023-05-02 /pmc/articles/PMC10189257/ /pubmed/37148731 http://dx.doi.org/10.1016/j.ijscr.2023.108284 Text en © 2023 The Authors https://creativecommons.org/licenses/by/4.0/This is an open access article under the CC BY license (http://creativecommons.org/licenses/by/4.0/).
spellingShingle Case Report
Atwine, Oscar
Odongo, Charles Newton
Ainomugisha, Racheal
Tayebwa, Edson
Muhumuza, Joshua
Dreque, Carlos Cabrera
A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report
title A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report
title_full A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report
title_fullStr A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report
title_full_unstemmed A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report
title_short A giant choledochal cyst in a 17 year old female managed in a resource limited setting: A case report
title_sort giant choledochal cyst in a 17 year old female managed in a resource limited setting: a case report
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10189257/
https://www.ncbi.nlm.nih.gov/pubmed/37148731
http://dx.doi.org/10.1016/j.ijscr.2023.108284
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