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Epigenetics of cognition and behavior: insights from Mendelian disorders of epigenetic machinery

Epigenetics, one mechanism by which gene expression can change without any changes to the DNA sequence, was described nearly a century ago. However, the importance of epigenetic processes to neurodevelopment and higher order neurological functions like cognition and behavior is only now being realiz...

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Autores principales: Ng, Rowena, Kalinousky, Allison, Harris, Jacqueline
Formato: Online Artículo Texto
Lenguaje:English
Publicado: BioMed Central 2023
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10224589/
https://www.ncbi.nlm.nih.gov/pubmed/37245029
http://dx.doi.org/10.1186/s11689-023-09482-0
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author Ng, Rowena
Kalinousky, Allison
Harris, Jacqueline
author_facet Ng, Rowena
Kalinousky, Allison
Harris, Jacqueline
author_sort Ng, Rowena
collection PubMed
description Epigenetics, one mechanism by which gene expression can change without any changes to the DNA sequence, was described nearly a century ago. However, the importance of epigenetic processes to neurodevelopment and higher order neurological functions like cognition and behavior is only now being realized. A group of disorders known as the Mendelian disorders of the epigenetic machinery are caused by the altered function of epigenetic machinery proteins, which consequently affects downstream expression of many genes. These disorders almost universally have cognitive dysfunction and behavioral issues as core features. Here, we review what is known about the neurodevelopmental phenotypes of some key examples of these disorders divided into categories based on the underlying function of the affected protein. Understanding these Mendelian disorders of the epigenetic machinery can illuminate the role of epigenetic regulation in typical brain function and can lead to future therapies and better management for a host of neurodevelopmental and neuropsychological disorders.
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spelling pubmed-102245892023-05-28 Epigenetics of cognition and behavior: insights from Mendelian disorders of epigenetic machinery Ng, Rowena Kalinousky, Allison Harris, Jacqueline J Neurodev Disord Review Epigenetics, one mechanism by which gene expression can change without any changes to the DNA sequence, was described nearly a century ago. However, the importance of epigenetic processes to neurodevelopment and higher order neurological functions like cognition and behavior is only now being realized. A group of disorders known as the Mendelian disorders of the epigenetic machinery are caused by the altered function of epigenetic machinery proteins, which consequently affects downstream expression of many genes. These disorders almost universally have cognitive dysfunction and behavioral issues as core features. Here, we review what is known about the neurodevelopmental phenotypes of some key examples of these disorders divided into categories based on the underlying function of the affected protein. Understanding these Mendelian disorders of the epigenetic machinery can illuminate the role of epigenetic regulation in typical brain function and can lead to future therapies and better management for a host of neurodevelopmental and neuropsychological disorders. BioMed Central 2023-05-27 /pmc/articles/PMC10224589/ /pubmed/37245029 http://dx.doi.org/10.1186/s11689-023-09482-0 Text en © The Author(s) 2023 https://creativecommons.org/licenses/by/4.0/Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons licence, and indicate if changes were made. The images or other third party material in this article are included in the article's Creative Commons licence, unless indicated otherwise in a credit line to the material. If material is not included in the article's Creative Commons licence and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this licence, visit http://creativecommons.org/licenses/by/4.0/ (https://creativecommons.org/licenses/by/4.0/) . The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/ (https://creativecommons.org/publicdomain/zero/1.0/) ) applies to the data made available in this article, unless otherwise stated in a credit line to the data.
spellingShingle Review
Ng, Rowena
Kalinousky, Allison
Harris, Jacqueline
Epigenetics of cognition and behavior: insights from Mendelian disorders of epigenetic machinery
title Epigenetics of cognition and behavior: insights from Mendelian disorders of epigenetic machinery
title_full Epigenetics of cognition and behavior: insights from Mendelian disorders of epigenetic machinery
title_fullStr Epigenetics of cognition and behavior: insights from Mendelian disorders of epigenetic machinery
title_full_unstemmed Epigenetics of cognition and behavior: insights from Mendelian disorders of epigenetic machinery
title_short Epigenetics of cognition and behavior: insights from Mendelian disorders of epigenetic machinery
title_sort epigenetics of cognition and behavior: insights from mendelian disorders of epigenetic machinery
topic Review
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10224589/
https://www.ncbi.nlm.nih.gov/pubmed/37245029
http://dx.doi.org/10.1186/s11689-023-09482-0
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