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Labrune Syndrome: A Rare Leukodystrophy

Labrune syndrome is a rare neurological disorder, with less than 100 reported cases since its identification. This disorder causes progressive cerebral degeneration. This case report describes a 21-year-old male patient who presented with tonic-clonic seizures. Upon examination, he was found to have...

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Autores principales: Nair, Jishnu, Swamiyappan, Sai Sriram, Bathala, Rav Tej, Gupta, Jayesh, Nayar, Kapil D, D, Balasubramaniam
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Cureus 2023
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10280778/
https://www.ncbi.nlm.nih.gov/pubmed/37346205
http://dx.doi.org/10.7759/cureus.39287
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author Nair, Jishnu
Swamiyappan, Sai Sriram
Bathala, Rav Tej
Gupta, Jayesh
Nayar, Kapil D
D, Balasubramaniam
author_facet Nair, Jishnu
Swamiyappan, Sai Sriram
Bathala, Rav Tej
Gupta, Jayesh
Nayar, Kapil D
D, Balasubramaniam
author_sort Nair, Jishnu
collection PubMed
description Labrune syndrome is a rare neurological disorder, with less than 100 reported cases since its identification. This disorder causes progressive cerebral degeneration. This case report describes a 21-year-old male patient who presented with tonic-clonic seizures. Upon examination, he was found to have symmetrical dense calcifications in the bilateral basal ganglia, thalami, and dentate nuclei, as well as in the white matter of both hemispheres, accompanied by cysts. MRI brain revealed confluent areas of T2/FLAIR hyperintensities involving the deep periventricular white matter in both cerebral hemispheres with sparing of subcortical U-fibres and two cysts in the left frontal and right posterior temporal region. No serologic evidence of a parasitic infection was found. Treatment was directed at addressing symptoms, and surgery was not required as the cysts were not causing a mass effect. The condition is the result of an autosomal mutation in the SNORD118 gene, a non-protein encoding gene that mediates rRNA synthesis.
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spelling pubmed-102807782023-06-21 Labrune Syndrome: A Rare Leukodystrophy Nair, Jishnu Swamiyappan, Sai Sriram Bathala, Rav Tej Gupta, Jayesh Nayar, Kapil D D, Balasubramaniam Cureus Genetics Labrune syndrome is a rare neurological disorder, with less than 100 reported cases since its identification. This disorder causes progressive cerebral degeneration. This case report describes a 21-year-old male patient who presented with tonic-clonic seizures. Upon examination, he was found to have symmetrical dense calcifications in the bilateral basal ganglia, thalami, and dentate nuclei, as well as in the white matter of both hemispheres, accompanied by cysts. MRI brain revealed confluent areas of T2/FLAIR hyperintensities involving the deep periventricular white matter in both cerebral hemispheres with sparing of subcortical U-fibres and two cysts in the left frontal and right posterior temporal region. No serologic evidence of a parasitic infection was found. Treatment was directed at addressing symptoms, and surgery was not required as the cysts were not causing a mass effect. The condition is the result of an autosomal mutation in the SNORD118 gene, a non-protein encoding gene that mediates rRNA synthesis. Cureus 2023-05-21 /pmc/articles/PMC10280778/ /pubmed/37346205 http://dx.doi.org/10.7759/cureus.39287 Text en Copyright © 2023, Nair et al. https://creativecommons.org/licenses/by/3.0/This is an open access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited.
spellingShingle Genetics
Nair, Jishnu
Swamiyappan, Sai Sriram
Bathala, Rav Tej
Gupta, Jayesh
Nayar, Kapil D
D, Balasubramaniam
Labrune Syndrome: A Rare Leukodystrophy
title Labrune Syndrome: A Rare Leukodystrophy
title_full Labrune Syndrome: A Rare Leukodystrophy
title_fullStr Labrune Syndrome: A Rare Leukodystrophy
title_full_unstemmed Labrune Syndrome: A Rare Leukodystrophy
title_short Labrune Syndrome: A Rare Leukodystrophy
title_sort labrune syndrome: a rare leukodystrophy
topic Genetics
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10280778/
https://www.ncbi.nlm.nih.gov/pubmed/37346205
http://dx.doi.org/10.7759/cureus.39287
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