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Intrinsic contracture of the hands in sarcoid myopathy

Hand involvement in sarcoidosis is rare and it presents as tenosynovitis, dactylitis, nodules and osteoarticular bony destruction. We describe an unusual presentation of progressive intrinsic muscle contracture of both hands in a 42-year-old woman with sarcoid myopathy who presented with painful swe...

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Autores principales: Liew, Siew Khei, Park, Jin Kyun, Gong, Hyun Sik
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Korean College of Rheumatology 2023
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10351373/
https://www.ncbi.nlm.nih.gov/pubmed/37476673
http://dx.doi.org/10.4078/jrd.2023.0007
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author Liew, Siew Khei
Park, Jin Kyun
Gong, Hyun Sik
author_facet Liew, Siew Khei
Park, Jin Kyun
Gong, Hyun Sik
author_sort Liew, Siew Khei
collection PubMed
description Hand involvement in sarcoidosis is rare and it presents as tenosynovitis, dactylitis, nodules and osteoarticular bony destruction. We describe an unusual presentation of progressive intrinsic muscle contracture of both hands in a 42-year-old woman with sarcoid myopathy who presented with painful swelling and weakness of all four extremities. Her systemic symptoms improved with oral corticosteroids, but the hand muscle contracture remained after resolution of myositis. Serial soft tissue releases of intrinsic muscle contracture improved hand function markedly. This case highlights that surgery is a viable option to treat intrinsic muscle contracture in patients with chronic sarcoid myopathy complicated with severe muscle contracture.
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spelling pubmed-103513732023-07-20 Intrinsic contracture of the hands in sarcoid myopathy Liew, Siew Khei Park, Jin Kyun Gong, Hyun Sik J Rheum Dis Case Report Hand involvement in sarcoidosis is rare and it presents as tenosynovitis, dactylitis, nodules and osteoarticular bony destruction. We describe an unusual presentation of progressive intrinsic muscle contracture of both hands in a 42-year-old woman with sarcoid myopathy who presented with painful swelling and weakness of all four extremities. Her systemic symptoms improved with oral corticosteroids, but the hand muscle contracture remained after resolution of myositis. Serial soft tissue releases of intrinsic muscle contracture improved hand function markedly. This case highlights that surgery is a viable option to treat intrinsic muscle contracture in patients with chronic sarcoid myopathy complicated with severe muscle contracture. Korean College of Rheumatology 2023-07-01 2023-03-14 /pmc/articles/PMC10351373/ /pubmed/37476673 http://dx.doi.org/10.4078/jrd.2023.0007 Text en Copyright © 2023 by The Korean College of Rheumatology. All rights reserved. https://creativecommons.org/licenses/by-nc/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/4.0 (https://creativecommons.org/licenses/by-nc/4.0/) ) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Liew, Siew Khei
Park, Jin Kyun
Gong, Hyun Sik
Intrinsic contracture of the hands in sarcoid myopathy
title Intrinsic contracture of the hands in sarcoid myopathy
title_full Intrinsic contracture of the hands in sarcoid myopathy
title_fullStr Intrinsic contracture of the hands in sarcoid myopathy
title_full_unstemmed Intrinsic contracture of the hands in sarcoid myopathy
title_short Intrinsic contracture of the hands in sarcoid myopathy
title_sort intrinsic contracture of the hands in sarcoid myopathy
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10351373/
https://www.ncbi.nlm.nih.gov/pubmed/37476673
http://dx.doi.org/10.4078/jrd.2023.0007
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