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Intrinsic contracture of the hands in sarcoid myopathy
Hand involvement in sarcoidosis is rare and it presents as tenosynovitis, dactylitis, nodules and osteoarticular bony destruction. We describe an unusual presentation of progressive intrinsic muscle contracture of both hands in a 42-year-old woman with sarcoid myopathy who presented with painful swe...
Autores principales: | , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
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Korean College of Rheumatology
2023
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Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10351373/ https://www.ncbi.nlm.nih.gov/pubmed/37476673 http://dx.doi.org/10.4078/jrd.2023.0007 |
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author | Liew, Siew Khei Park, Jin Kyun Gong, Hyun Sik |
author_facet | Liew, Siew Khei Park, Jin Kyun Gong, Hyun Sik |
author_sort | Liew, Siew Khei |
collection | PubMed |
description | Hand involvement in sarcoidosis is rare and it presents as tenosynovitis, dactylitis, nodules and osteoarticular bony destruction. We describe an unusual presentation of progressive intrinsic muscle contracture of both hands in a 42-year-old woman with sarcoid myopathy who presented with painful swelling and weakness of all four extremities. Her systemic symptoms improved with oral corticosteroids, but the hand muscle contracture remained after resolution of myositis. Serial soft tissue releases of intrinsic muscle contracture improved hand function markedly. This case highlights that surgery is a viable option to treat intrinsic muscle contracture in patients with chronic sarcoid myopathy complicated with severe muscle contracture. |
format | Online Article Text |
id | pubmed-10351373 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2023 |
publisher | Korean College of Rheumatology |
record_format | MEDLINE/PubMed |
spelling | pubmed-103513732023-07-20 Intrinsic contracture of the hands in sarcoid myopathy Liew, Siew Khei Park, Jin Kyun Gong, Hyun Sik J Rheum Dis Case Report Hand involvement in sarcoidosis is rare and it presents as tenosynovitis, dactylitis, nodules and osteoarticular bony destruction. We describe an unusual presentation of progressive intrinsic muscle contracture of both hands in a 42-year-old woman with sarcoid myopathy who presented with painful swelling and weakness of all four extremities. Her systemic symptoms improved with oral corticosteroids, but the hand muscle contracture remained after resolution of myositis. Serial soft tissue releases of intrinsic muscle contracture improved hand function markedly. This case highlights that surgery is a viable option to treat intrinsic muscle contracture in patients with chronic sarcoid myopathy complicated with severe muscle contracture. Korean College of Rheumatology 2023-07-01 2023-03-14 /pmc/articles/PMC10351373/ /pubmed/37476673 http://dx.doi.org/10.4078/jrd.2023.0007 Text en Copyright © 2023 by The Korean College of Rheumatology. All rights reserved. https://creativecommons.org/licenses/by-nc/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution Non-Commercial License (http://creativecommons.org/licenses/by-nc/4.0 (https://creativecommons.org/licenses/by-nc/4.0/) ) which permits unrestricted non-commercial use, distribution, and reproduction in any medium, provided the original work is properly cited. |
spellingShingle | Case Report Liew, Siew Khei Park, Jin Kyun Gong, Hyun Sik Intrinsic contracture of the hands in sarcoid myopathy |
title | Intrinsic contracture of the hands in sarcoid myopathy |
title_full | Intrinsic contracture of the hands in sarcoid myopathy |
title_fullStr | Intrinsic contracture of the hands in sarcoid myopathy |
title_full_unstemmed | Intrinsic contracture of the hands in sarcoid myopathy |
title_short | Intrinsic contracture of the hands in sarcoid myopathy |
title_sort | intrinsic contracture of the hands in sarcoid myopathy |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10351373/ https://www.ncbi.nlm.nih.gov/pubmed/37476673 http://dx.doi.org/10.4078/jrd.2023.0007 |
work_keys_str_mv | AT liewsiewkhei intrinsiccontractureofthehandsinsarcoidmyopathy AT parkjinkyun intrinsiccontractureofthehandsinsarcoidmyopathy AT gonghyunsik intrinsiccontractureofthehandsinsarcoidmyopathy |