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A new genetic cause of spastic ataxia: the p.Glu415Lys variant in TUBA4A
Tubulinopathies encompass neurodevelopmental disorders caused by mutations in genes encoding for different isotypes of α- and β-tubulins, the structural components of microtubules. Less frequently, mutations in tubulins may underlie neurodegenerative disorders. In the present study, we report two fa...
Autores principales: | , , , , , , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Springer Berlin Heidelberg
2023
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10511369/ https://www.ncbi.nlm.nih.gov/pubmed/37418012 http://dx.doi.org/10.1007/s00415-023-11816-w |
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author | Torella, Annalaura Ricca, Ivana Piluso, Giulio Galatolo, Daniele De Michele, Giuseppe Zanobio, Mariateresa Trovato, Rosanna De Michele, Giovanna Zeuli, Roberta Pane, Chiara Cocozza, Sirio Saccà, Francesco Santorelli, Filippo M. Nigro, Vincenzo Filla, Alessandro |
author_facet | Torella, Annalaura Ricca, Ivana Piluso, Giulio Galatolo, Daniele De Michele, Giuseppe Zanobio, Mariateresa Trovato, Rosanna De Michele, Giovanna Zeuli, Roberta Pane, Chiara Cocozza, Sirio Saccà, Francesco Santorelli, Filippo M. Nigro, Vincenzo Filla, Alessandro |
author_sort | Torella, Annalaura |
collection | PubMed |
description | Tubulinopathies encompass neurodevelopmental disorders caused by mutations in genes encoding for different isotypes of α- and β-tubulins, the structural components of microtubules. Less frequently, mutations in tubulins may underlie neurodegenerative disorders. In the present study, we report two families, one with 11 affected individuals and the other with a single patient, carrying a novel, likely pathogenic, variant (p. Glu415Lys) in the TUBA4A gene (NM_006000). The phenotype, not previously described, is that of spastic ataxia. Our findings widen the phenotypic and genetic manifestations of TUBA4A variants and add a new type of spastic ataxia to be taken into consideration in the differential diagnosis. |
format | Online Article Text |
id | pubmed-10511369 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2023 |
publisher | Springer Berlin Heidelberg |
record_format | MEDLINE/PubMed |
spelling | pubmed-105113692023-09-22 A new genetic cause of spastic ataxia: the p.Glu415Lys variant in TUBA4A Torella, Annalaura Ricca, Ivana Piluso, Giulio Galatolo, Daniele De Michele, Giuseppe Zanobio, Mariateresa Trovato, Rosanna De Michele, Giovanna Zeuli, Roberta Pane, Chiara Cocozza, Sirio Saccà, Francesco Santorelli, Filippo M. Nigro, Vincenzo Filla, Alessandro J Neurol Original Communication Tubulinopathies encompass neurodevelopmental disorders caused by mutations in genes encoding for different isotypes of α- and β-tubulins, the structural components of microtubules. Less frequently, mutations in tubulins may underlie neurodegenerative disorders. In the present study, we report two families, one with 11 affected individuals and the other with a single patient, carrying a novel, likely pathogenic, variant (p. Glu415Lys) in the TUBA4A gene (NM_006000). The phenotype, not previously described, is that of spastic ataxia. Our findings widen the phenotypic and genetic manifestations of TUBA4A variants and add a new type of spastic ataxia to be taken into consideration in the differential diagnosis. Springer Berlin Heidelberg 2023-07-07 2023 /pmc/articles/PMC10511369/ /pubmed/37418012 http://dx.doi.org/10.1007/s00415-023-11816-w Text en © The Author(s) 2023 https://creativecommons.org/licenses/by/4.0/Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons licence, and indicate if changes were made. The images or other third party material in this article are included in the article's Creative Commons licence, unless indicated otherwise in a credit line to the material. If material is not included in the article's Creative Commons licence and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this licence, visit http://creativecommons.org/licenses/by/4.0/ (https://creativecommons.org/licenses/by/4.0/) . |
spellingShingle | Original Communication Torella, Annalaura Ricca, Ivana Piluso, Giulio Galatolo, Daniele De Michele, Giuseppe Zanobio, Mariateresa Trovato, Rosanna De Michele, Giovanna Zeuli, Roberta Pane, Chiara Cocozza, Sirio Saccà, Francesco Santorelli, Filippo M. Nigro, Vincenzo Filla, Alessandro A new genetic cause of spastic ataxia: the p.Glu415Lys variant in TUBA4A |
title | A new genetic cause of spastic ataxia: the p.Glu415Lys variant in TUBA4A |
title_full | A new genetic cause of spastic ataxia: the p.Glu415Lys variant in TUBA4A |
title_fullStr | A new genetic cause of spastic ataxia: the p.Glu415Lys variant in TUBA4A |
title_full_unstemmed | A new genetic cause of spastic ataxia: the p.Glu415Lys variant in TUBA4A |
title_short | A new genetic cause of spastic ataxia: the p.Glu415Lys variant in TUBA4A |
title_sort | new genetic cause of spastic ataxia: the p.glu415lys variant in tuba4a |
topic | Original Communication |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10511369/ https://www.ncbi.nlm.nih.gov/pubmed/37418012 http://dx.doi.org/10.1007/s00415-023-11816-w |
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