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Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis

INTRODUCTION AND IMPORTANCE: The Rapunzel syndrome embodies an uncommon variation of trichobezoar, predominantly observed among individuals with a history of psychiatric conditions, trichotillomania, and trichophagia. This combination of factors predisposes to the eventual formation of gastric bezoa...

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Autores principales: Belhadj, Anis, Touati, Med Dheker, Othmane, Mohamed Raouf Ben, Khefacha, Fahd, Saidani, Ahmed, Chebbi, Faouzi
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2023
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10520814/
https://www.ncbi.nlm.nih.gov/pubmed/37748384
http://dx.doi.org/10.1016/j.ijscr.2023.108860
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author Belhadj, Anis
Touati, Med Dheker
Othmane, Mohamed Raouf Ben
Khefacha, Fahd
Saidani, Ahmed
Chebbi, Faouzi
author_facet Belhadj, Anis
Touati, Med Dheker
Othmane, Mohamed Raouf Ben
Khefacha, Fahd
Saidani, Ahmed
Chebbi, Faouzi
author_sort Belhadj, Anis
collection PubMed
description INTRODUCTION AND IMPORTANCE: The Rapunzel syndrome embodies an uncommon variation of trichobezoar, predominantly observed among individuals with a history of psychiatric conditions, trichotillomania, and trichophagia. This combination of factors predisposes to the eventual formation of gastric bezoars. Trichobezoars, infrequent gastric masses composed of hair, can lead to complications if left untreated. CASE REPORT: A 19-year-old female hairdresser with a history of trichophagia sought medical attention due to abdominal pain and episodes of vomiting. With an elevated body temperature and abdominal rigidity, imaging revealed the presence of a trichobezoar, accompanied by pneumoperitoneum and intraperitoneal effusion. Urgent surgical intervention confirmed the diagnosis of generalized purulent acute peritonitis, triggered by a gastric perforation caused by a 20 cm trichobezoar with an extension into the duodenum, which defines the Rapunzel syndrome. Gastrotomy was performed to remove the trichobezoar, followed by thorough peritoneal lavage. CLINICAL DISCUSSION: Trichobezoar is a rare condition that involves the abnormal accumulation of solid substances, particularly hair, within the stomach. Known as “Rapunzel syndrome,” it can extend into the duodenum or jejunum. Commonly associated with emotional disorders, trichobezoar can lead to symptoms like epigastric discomfort, vomiting, and weight loss. Diagnosis is through endoscopy, and treatments include fluid intake, endoscopic extraction, chemical dissolution, and surgical removal. Surgical intervention is often preferred, with laparoscopic approaches considered. Psychiatric management is often required for patients. CONCLUSION: This case underscores the uncommon Rapunzel syndrome presentation, emphasizing timely surgical measures and multidisciplinary care for trichobezoars causing acute peritonitis.
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spelling pubmed-105208142023-09-27 Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis Belhadj, Anis Touati, Med Dheker Othmane, Mohamed Raouf Ben Khefacha, Fahd Saidani, Ahmed Chebbi, Faouzi Int J Surg Case Rep Case Report INTRODUCTION AND IMPORTANCE: The Rapunzel syndrome embodies an uncommon variation of trichobezoar, predominantly observed among individuals with a history of psychiatric conditions, trichotillomania, and trichophagia. This combination of factors predisposes to the eventual formation of gastric bezoars. Trichobezoars, infrequent gastric masses composed of hair, can lead to complications if left untreated. CASE REPORT: A 19-year-old female hairdresser with a history of trichophagia sought medical attention due to abdominal pain and episodes of vomiting. With an elevated body temperature and abdominal rigidity, imaging revealed the presence of a trichobezoar, accompanied by pneumoperitoneum and intraperitoneal effusion. Urgent surgical intervention confirmed the diagnosis of generalized purulent acute peritonitis, triggered by a gastric perforation caused by a 20 cm trichobezoar with an extension into the duodenum, which defines the Rapunzel syndrome. Gastrotomy was performed to remove the trichobezoar, followed by thorough peritoneal lavage. CLINICAL DISCUSSION: Trichobezoar is a rare condition that involves the abnormal accumulation of solid substances, particularly hair, within the stomach. Known as “Rapunzel syndrome,” it can extend into the duodenum or jejunum. Commonly associated with emotional disorders, trichobezoar can lead to symptoms like epigastric discomfort, vomiting, and weight loss. Diagnosis is through endoscopy, and treatments include fluid intake, endoscopic extraction, chemical dissolution, and surgical removal. Surgical intervention is often preferred, with laparoscopic approaches considered. Psychiatric management is often required for patients. CONCLUSION: This case underscores the uncommon Rapunzel syndrome presentation, emphasizing timely surgical measures and multidisciplinary care for trichobezoars causing acute peritonitis. Elsevier 2023-09-22 /pmc/articles/PMC10520814/ /pubmed/37748384 http://dx.doi.org/10.1016/j.ijscr.2023.108860 Text en © 2023 The Author(s) https://creativecommons.org/licenses/by-nc-nd/4.0/This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).
spellingShingle Case Report
Belhadj, Anis
Touati, Med Dheker
Othmane, Mohamed Raouf Ben
Khefacha, Fahd
Saidani, Ahmed
Chebbi, Faouzi
Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis
title Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis
title_full Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis
title_fullStr Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis
title_full_unstemmed Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis
title_short Revelation of Rapunzel syndrome: A rare case report of gastric trichobezoar-induced acute purulent peritonitis
title_sort revelation of rapunzel syndrome: a rare case report of gastric trichobezoar-induced acute purulent peritonitis
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10520814/
https://www.ncbi.nlm.nih.gov/pubmed/37748384
http://dx.doi.org/10.1016/j.ijscr.2023.108860
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