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Successful Treatment of Pityriasis Rubra Pilaris with Risankizumab in Children

Pityriasis rubra pilaris (PRP) is a rare inflammatory skin disease that affects men and women of all ages, including children. PRP is characterized by follicular and palmoplantar hyperkeratosis and salmon-colored scaling plaques. The exact pathogenesis of PRP is still unknown; most PRP cases are acq...

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Autores principales: Kołt-Kamińska, Marta, Osińska, Antonina, Kaznowska, Ewa, Reich, Adam
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Springer Healthcare 2023
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10539248/
https://www.ncbi.nlm.nih.gov/pubmed/37704911
http://dx.doi.org/10.1007/s13555-023-01005-y
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author Kołt-Kamińska, Marta
Osińska, Antonina
Kaznowska, Ewa
Reich, Adam
author_facet Kołt-Kamińska, Marta
Osińska, Antonina
Kaznowska, Ewa
Reich, Adam
author_sort Kołt-Kamińska, Marta
collection PubMed
description Pityriasis rubra pilaris (PRP) is a rare inflammatory skin disease that affects men and women of all ages, including children. PRP is characterized by follicular and palmoplantar hyperkeratosis and salmon-colored scaling plaques. The exact pathogenesis of PRP is still unknown; most PRP cases are acquired, but some cases may show a familial occurrence, often associated with a mutation in the CARD14 gene. Due to the rarity of PRP, treatment recommendations are based mainly on case reports, small case series and expert opinions and still represent a major therapeutic challenge, especially in children. A growing number of reports on treatment with biologicals, particularly anti-TNFα, has been published. However, an involvement of the IL-23/Th17 axis in both psoriasis and PRP pathogenesis may suggest that this pathway may be a potential therapeutic target. Here, we present three pediatric patients with PRP successfully treated with risankizumab. All patients exhibited a severe course of PRP and lack of response to conventional therapy, including acitretin, cyclosporine and phototherapy. A single dose of 75 mg risankizumab resulted in almost complete clearance of skin lesions in case 1 and 2 at week 4. In patient 3, clear skin was achieved after the second administration of risankizumab (150 mg). All patients continue the treatment with risankizumab, and no adverse effects have been reported up to the present time. Our study demonstrates that risankizumab, an IL-23 blocker, shows good efficacy and safety among pediatric patients with PRP.
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spelling pubmed-105392482023-09-30 Successful Treatment of Pityriasis Rubra Pilaris with Risankizumab in Children Kołt-Kamińska, Marta Osińska, Antonina Kaznowska, Ewa Reich, Adam Dermatol Ther (Heidelb) Case Series Pityriasis rubra pilaris (PRP) is a rare inflammatory skin disease that affects men and women of all ages, including children. PRP is characterized by follicular and palmoplantar hyperkeratosis and salmon-colored scaling plaques. The exact pathogenesis of PRP is still unknown; most PRP cases are acquired, but some cases may show a familial occurrence, often associated with a mutation in the CARD14 gene. Due to the rarity of PRP, treatment recommendations are based mainly on case reports, small case series and expert opinions and still represent a major therapeutic challenge, especially in children. A growing number of reports on treatment with biologicals, particularly anti-TNFα, has been published. However, an involvement of the IL-23/Th17 axis in both psoriasis and PRP pathogenesis may suggest that this pathway may be a potential therapeutic target. Here, we present three pediatric patients with PRP successfully treated with risankizumab. All patients exhibited a severe course of PRP and lack of response to conventional therapy, including acitretin, cyclosporine and phototherapy. A single dose of 75 mg risankizumab resulted in almost complete clearance of skin lesions in case 1 and 2 at week 4. In patient 3, clear skin was achieved after the second administration of risankizumab (150 mg). All patients continue the treatment with risankizumab, and no adverse effects have been reported up to the present time. Our study demonstrates that risankizumab, an IL-23 blocker, shows good efficacy and safety among pediatric patients with PRP. Springer Healthcare 2023-09-13 /pmc/articles/PMC10539248/ /pubmed/37704911 http://dx.doi.org/10.1007/s13555-023-01005-y Text en © The Author(s) 2023 https://creativecommons.org/licenses/by-nc/4.0/Open Access This article is licensed under a Creative Commons Attribution-NonCommercial 4.0 International License, which permits any non-commercial use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons licence, and indicate if changes were made. The images or other third party material in this article are included in the article's Creative Commons licence, unless indicated otherwise in a credit line to the material. If material is not included in the article's Creative Commons licence and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this licence, visit http://creativecommons.org/licenses/by-nc/4.0/ (https://creativecommons.org/licenses/by-nc/4.0/) .
spellingShingle Case Series
Kołt-Kamińska, Marta
Osińska, Antonina
Kaznowska, Ewa
Reich, Adam
Successful Treatment of Pityriasis Rubra Pilaris with Risankizumab in Children
title Successful Treatment of Pityriasis Rubra Pilaris with Risankizumab in Children
title_full Successful Treatment of Pityriasis Rubra Pilaris with Risankizumab in Children
title_fullStr Successful Treatment of Pityriasis Rubra Pilaris with Risankizumab in Children
title_full_unstemmed Successful Treatment of Pityriasis Rubra Pilaris with Risankizumab in Children
title_short Successful Treatment of Pityriasis Rubra Pilaris with Risankizumab in Children
title_sort successful treatment of pityriasis rubra pilaris with risankizumab in children
topic Case Series
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10539248/
https://www.ncbi.nlm.nih.gov/pubmed/37704911
http://dx.doi.org/10.1007/s13555-023-01005-y
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