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Natural history and comorbidities of generalised and partial lipodystrophy syndromes in Spain
The rarity of lipodystrophies implies that they are not well-known, leading to delays in diagnosis/misdiagnosis. The aim of this study was to assess the natural course and comorbidities of generalised and partial lipodystrophy in Spain to contribute to their understanding. Thus, a total of 140 patie...
Autores principales: | , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
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Frontiers Media S.A.
2023
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Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10687442/ https://www.ncbi.nlm.nih.gov/pubmed/38034001 http://dx.doi.org/10.3389/fendo.2023.1250203 |
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author | Fernández-Pombo, Antía Sánchez-Iglesias, Sofía Castro-Pais, Ana I. Ginzo-Villamayor, Maria José Cobelo-Gómez, Silvia Prado-Moraña, Teresa Díaz-López, Everardo Josué Casanueva, Felipe F. Loidi, Lourdes Araújo-Vilar, David |
author_facet | Fernández-Pombo, Antía Sánchez-Iglesias, Sofía Castro-Pais, Ana I. Ginzo-Villamayor, Maria José Cobelo-Gómez, Silvia Prado-Moraña, Teresa Díaz-López, Everardo Josué Casanueva, Felipe F. Loidi, Lourdes Araújo-Vilar, David |
author_sort | Fernández-Pombo, Antía |
collection | PubMed |
description | The rarity of lipodystrophies implies that they are not well-known, leading to delays in diagnosis/misdiagnosis. The aim of this study was to assess the natural course and comorbidities of generalised and partial lipodystrophy in Spain to contribute to their understanding. Thus, a total of 140 patients were evaluated (77.1% with partial lipodystrophy and 22.9% with generalised lipodystrophy). Clinical data were collected in a longitudinal setting with a median follow-up of 4.7 (0.5-17.6) years. Anthropometry and body composition studies were carried out and analytical parameters were also recorded. The estimated prevalence of all lipodystrophies in Spain, excluding Köbberling syndrome, was 2.78 cases/million. The onset of phenotype occurred during childhood in generalised lipodystrophy and during adolescence-adulthood in partial lipodystrophy, with the delay in diagnosis being considerable for both cohorts. There are specific clinical findings that should be highlighted as useful features to take into account when making the differential diagnosis of these disorders. Patients with generalised lipodystrophy were found to develop their first metabolic abnormalities sooner and a different lipid profile has also been observed. Mean time to death was 83.8 ± 2.5 years, being shorter among patients with generalised lipodystrophy. These results provide an initial point of comparison for ongoing prospective studies such as the ECLip Registry study. |
format | Online Article Text |
id | pubmed-10687442 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2023 |
publisher | Frontiers Media S.A. |
record_format | MEDLINE/PubMed |
spelling | pubmed-106874422023-11-30 Natural history and comorbidities of generalised and partial lipodystrophy syndromes in Spain Fernández-Pombo, Antía Sánchez-Iglesias, Sofía Castro-Pais, Ana I. Ginzo-Villamayor, Maria José Cobelo-Gómez, Silvia Prado-Moraña, Teresa Díaz-López, Everardo Josué Casanueva, Felipe F. Loidi, Lourdes Araújo-Vilar, David Front Endocrinol (Lausanne) Endocrinology The rarity of lipodystrophies implies that they are not well-known, leading to delays in diagnosis/misdiagnosis. The aim of this study was to assess the natural course and comorbidities of generalised and partial lipodystrophy in Spain to contribute to their understanding. Thus, a total of 140 patients were evaluated (77.1% with partial lipodystrophy and 22.9% with generalised lipodystrophy). Clinical data were collected in a longitudinal setting with a median follow-up of 4.7 (0.5-17.6) years. Anthropometry and body composition studies were carried out and analytical parameters were also recorded. The estimated prevalence of all lipodystrophies in Spain, excluding Köbberling syndrome, was 2.78 cases/million. The onset of phenotype occurred during childhood in generalised lipodystrophy and during adolescence-adulthood in partial lipodystrophy, with the delay in diagnosis being considerable for both cohorts. There are specific clinical findings that should be highlighted as useful features to take into account when making the differential diagnosis of these disorders. Patients with generalised lipodystrophy were found to develop their first metabolic abnormalities sooner and a different lipid profile has also been observed. Mean time to death was 83.8 ± 2.5 years, being shorter among patients with generalised lipodystrophy. These results provide an initial point of comparison for ongoing prospective studies such as the ECLip Registry study. Frontiers Media S.A. 2023-11-16 /pmc/articles/PMC10687442/ /pubmed/38034001 http://dx.doi.org/10.3389/fendo.2023.1250203 Text en Copyright © 2023 Fernández-Pombo, Sánchez-Iglesias, Castro-Pais, Ginzo-Villamayor, Cobelo-Gómez, Prado-Moraña, Díaz-López, Casanueva, Loidi and Araújo-Vilar https://creativecommons.org/licenses/by/4.0/This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner(s) are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms. |
spellingShingle | Endocrinology Fernández-Pombo, Antía Sánchez-Iglesias, Sofía Castro-Pais, Ana I. Ginzo-Villamayor, Maria José Cobelo-Gómez, Silvia Prado-Moraña, Teresa Díaz-López, Everardo Josué Casanueva, Felipe F. Loidi, Lourdes Araújo-Vilar, David Natural history and comorbidities of generalised and partial lipodystrophy syndromes in Spain |
title | Natural history and comorbidities of generalised and partial lipodystrophy syndromes in Spain |
title_full | Natural history and comorbidities of generalised and partial lipodystrophy syndromes in Spain |
title_fullStr | Natural history and comorbidities of generalised and partial lipodystrophy syndromes in Spain |
title_full_unstemmed | Natural history and comorbidities of generalised and partial lipodystrophy syndromes in Spain |
title_short | Natural history and comorbidities of generalised and partial lipodystrophy syndromes in Spain |
title_sort | natural history and comorbidities of generalised and partial lipodystrophy syndromes in spain |
topic | Endocrinology |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC10687442/ https://www.ncbi.nlm.nih.gov/pubmed/38034001 http://dx.doi.org/10.3389/fendo.2023.1250203 |
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