Colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report

BACKGROUND: Infantile myofibromatosis is a rare mesenchymal disorder of infancy that can extensively involve the viscera including the gastrointestinal tract. CASE PRESENTATION: In this report, an exceptional case of infantile myofibromatosis is described in which rectal prolapse and sigmoid colo-co...

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Autores principales: Dhall, Deepti, Frykman, Philip K, Wang, Hanlin L
Formato: Texto
Lenguaje:English
Publicado: BioMed Central 2008
Materias:
Case Report
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC2621132/
https://www.ncbi.nlm.nih.gov/pubmed/19077316
http://dx.doi.org/10.1186/1757-1626-1-397
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author Dhall, Deepti
Frykman, Philip K
Wang, Hanlin L
author_facet Dhall, Deepti
Frykman, Philip K
Wang, Hanlin L
author_sort Dhall, Deepti
collection PubMed
description BACKGROUND: Infantile myofibromatosis is a rare mesenchymal disorder of infancy that can extensively involve the viscera including the gastrointestinal tract. CASE PRESENTATION: In this report, an exceptional case of infantile myofibromatosis is described in which rectal prolapse and sigmoid colo-colonic intussusception were the initial presentations of colorectal involvement in a 2-month-old premature female infant. CONCLUSION: To the best of our knowledge, this is the first case reporting rectal prolapse and the second case documenting intussusception secondary to gastrointestinal involvement by infantile myofibromatosis.
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spelling pubmed-26211322009-01-13 Colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report Dhall, Deepti Frykman, Philip K Wang, Hanlin L Cases J Case Report BACKGROUND: Infantile myofibromatosis is a rare mesenchymal disorder of infancy that can extensively involve the viscera including the gastrointestinal tract. CASE PRESENTATION: In this report, an exceptional case of infantile myofibromatosis is described in which rectal prolapse and sigmoid colo-colonic intussusception were the initial presentations of colorectal involvement in a 2-month-old premature female infant. CONCLUSION: To the best of our knowledge, this is the first case reporting rectal prolapse and the second case documenting intussusception secondary to gastrointestinal involvement by infantile myofibromatosis. BioMed Central 2008-12-15 /pmc/articles/PMC2621132/ /pubmed/19077316 http://dx.doi.org/10.1186/1757-1626-1-397 Text en Copyright © 2008 Dhall et al; licensee BioMed Central Ltd. http://creativecommons.org/licenses/by/2.0 This is an Open Access article distributed under the terms of the Creative Commons Attribution License ( (http://creativecommons.org/licenses/by/2.0) ), which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Dhall, Deepti
Frykman, Philip K
Wang, Hanlin L
Colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report
title Colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report
title_full Colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report
title_fullStr Colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report
title_full_unstemmed Colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report
title_short Colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report
title_sort colorectal infantile myofibromatosis: an unusual cause of rectal prolapse and sigmoid colo-colonic intussusception: a case report
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC2621132/
https://www.ncbi.nlm.nih.gov/pubmed/19077316
http://dx.doi.org/10.1186/1757-1626-1-397
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AT frykmanphilipk colorectalinfantilemyofibromatosisanunusualcauseofrectalprolapseandsigmoidcolocolonicintussusceptionacasereport
AT wanghanlinl colorectalinfantilemyofibromatosisanunusualcauseofrectalprolapseandsigmoidcolocolonicintussusceptionacasereport

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