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Deficiency of the DNA repair enzyme ATM in rheumatoid arthritis

In rheumatoid arthritis (RA), dysfunctional T cells sustain chronic inflammatory immune responses in the synovium. Even unprimed T cells are under excessive replication pressure, suggesting an intrinsic defect in T cell regeneration. In naive CD4 CD45RA(+) T cells from RA patients, DNA damage load a...

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Autores principales: Shao, Lan, Fujii, Hiroshi, Colmegna, Inés, Oishi, Hisashi, Goronzy, Jörg J., Weyand, Cornelia M.
Formato: Texto
Lenguaje:English
Publicado: The Rockefeller University Press 2009
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC2715066/
https://www.ncbi.nlm.nih.gov/pubmed/19451263
http://dx.doi.org/10.1084/jem.20082251
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author Shao, Lan
Fujii, Hiroshi
Colmegna, Inés
Oishi, Hisashi
Goronzy, Jörg J.
Weyand, Cornelia M.
author_facet Shao, Lan
Fujii, Hiroshi
Colmegna, Inés
Oishi, Hisashi
Goronzy, Jörg J.
Weyand, Cornelia M.
author_sort Shao, Lan
collection PubMed
description In rheumatoid arthritis (RA), dysfunctional T cells sustain chronic inflammatory immune responses in the synovium. Even unprimed T cells are under excessive replication pressure, suggesting an intrinsic defect in T cell regeneration. In naive CD4 CD45RA(+) T cells from RA patients, DNA damage load and apoptosis rates were markedly higher than in controls; repair of radiation-induced DNA breaks was blunted and delayed. DNA damage was highest in newly diagnosed untreated patients. RA T cells failed to produce sufficient transcripts and protein of the DNA repair kinase ataxia telangiectasia (AT) mutated (ATM). NBS1, RAD50, MRE11, and p53 were also repressed. ATM knockdown mimicked the biological effects characteristic for RA T cells. Conversely, ATM overexpression reconstituted DNA repair capabilities, response patterns to genotoxic stress, and production of MRE11 complex components and rescued RA T cells from apoptotic death. In conclusion, ATM deficiency in RA disrupts DNA repair and renders T cells sensitive to apoptosis. Apoptotic attrition of naive T cells imposes lymphopenia-induced proliferation, leading to premature immunosenescence and an autoimmune-biased T cell repertoire. Restoration of DNA repair mechanisms emerges as an important therapeutic target in RA.
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spelling pubmed-27150662009-12-08 Deficiency of the DNA repair enzyme ATM in rheumatoid arthritis Shao, Lan Fujii, Hiroshi Colmegna, Inés Oishi, Hisashi Goronzy, Jörg J. Weyand, Cornelia M. J Exp Med Article In rheumatoid arthritis (RA), dysfunctional T cells sustain chronic inflammatory immune responses in the synovium. Even unprimed T cells are under excessive replication pressure, suggesting an intrinsic defect in T cell regeneration. In naive CD4 CD45RA(+) T cells from RA patients, DNA damage load and apoptosis rates were markedly higher than in controls; repair of radiation-induced DNA breaks was blunted and delayed. DNA damage was highest in newly diagnosed untreated patients. RA T cells failed to produce sufficient transcripts and protein of the DNA repair kinase ataxia telangiectasia (AT) mutated (ATM). NBS1, RAD50, MRE11, and p53 were also repressed. ATM knockdown mimicked the biological effects characteristic for RA T cells. Conversely, ATM overexpression reconstituted DNA repair capabilities, response patterns to genotoxic stress, and production of MRE11 complex components and rescued RA T cells from apoptotic death. In conclusion, ATM deficiency in RA disrupts DNA repair and renders T cells sensitive to apoptosis. Apoptotic attrition of naive T cells imposes lymphopenia-induced proliferation, leading to premature immunosenescence and an autoimmune-biased T cell repertoire. Restoration of DNA repair mechanisms emerges as an important therapeutic target in RA. The Rockefeller University Press 2009-06-08 /pmc/articles/PMC2715066/ /pubmed/19451263 http://dx.doi.org/10.1084/jem.20082251 Text en © 2009 Shao et al. This article is distributed under the terms of an Attribution–Noncommercial–Share Alike–No Mirror Sites license for the first six months after the publication date (see http://www.jem.org/misc/terms.shtml). After six months it is available under a Creative Commons License (Attribution–Noncommercial–Share Alike 3.0 Unported license, as described at http://creativecommons.org/licenses/by-nc-sa/3.0/).
spellingShingle Article
Shao, Lan
Fujii, Hiroshi
Colmegna, Inés
Oishi, Hisashi
Goronzy, Jörg J.
Weyand, Cornelia M.
Deficiency of the DNA repair enzyme ATM in rheumatoid arthritis
title Deficiency of the DNA repair enzyme ATM in rheumatoid arthritis
title_full Deficiency of the DNA repair enzyme ATM in rheumatoid arthritis
title_fullStr Deficiency of the DNA repair enzyme ATM in rheumatoid arthritis
title_full_unstemmed Deficiency of the DNA repair enzyme ATM in rheumatoid arthritis
title_short Deficiency of the DNA repair enzyme ATM in rheumatoid arthritis
title_sort deficiency of the dna repair enzyme atm in rheumatoid arthritis
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC2715066/
https://www.ncbi.nlm.nih.gov/pubmed/19451263
http://dx.doi.org/10.1084/jem.20082251
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