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von Willebrand disease with G4022A mutation (vWd Sungnam): a case report.
A 10-year-old male patient affected by type 2 von Willebrand disease (vWD) and his family members were investigated by hemostatic and molecular genetic studies. The propositus, who experienced frequent bleeding episodes, was characterized by a normal level of von Willebrand factor (vWF) antigen (54%...
Autores principales: | , , , , , , |
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Formato: | Texto |
Lenguaje: | English |
Publicado: |
Korean Academy of Medical Sciences
1999
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3054163/ https://www.ncbi.nlm.nih.gov/pubmed/10102532 |
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author | Song, K. S. Kang, S. H. Kang, M. S. Park, Y. S. Choi, J. R. Kim, H. K. Park, Q. |
author_facet | Song, K. S. Kang, S. H. Kang, M. S. Park, Y. S. Choi, J. R. Kim, H. K. Park, Q. |
author_sort | Song, K. S. |
collection | PubMed |
description | A 10-year-old male patient affected by type 2 von Willebrand disease (vWD) and his family members were investigated by hemostatic and molecular genetic studies. The propositus, who experienced frequent bleeding episodes, was characterized by a normal level of von Willebrand factor (vWF) antigen (54%), reduced vWF ristocetin cofactor activity (5%), decreased factor VIII clotting activity (25%) and absent high molecular weight multimers in the plasma. An exon 28 fragment coding for the A1 and A2 domains was amplified by polymerase chain reaction and sequenced. We found a heterozygous mutation (G4022A), producing an additional PstI restriction site, which resulted in the substitution of Arg578Gln. Family studies, including the parents and a brother, were negative for this mutation and vWF abnormalities were not observed. We confirmed that G to A mutation in the region of the platelet glycoprotein Ib binding domain of vWF causes the qualitative type 2 defect in von Willebrand disease. |
format | Text |
id | pubmed-3054163 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 1999 |
publisher | Korean Academy of Medical Sciences |
record_format | MEDLINE/PubMed |
spelling | pubmed-30541632011-03-15 von Willebrand disease with G4022A mutation (vWd Sungnam): a case report. Song, K. S. Kang, S. H. Kang, M. S. Park, Y. S. Choi, J. R. Kim, H. K. Park, Q. J Korean Med Sci Research Article A 10-year-old male patient affected by type 2 von Willebrand disease (vWD) and his family members were investigated by hemostatic and molecular genetic studies. The propositus, who experienced frequent bleeding episodes, was characterized by a normal level of von Willebrand factor (vWF) antigen (54%), reduced vWF ristocetin cofactor activity (5%), decreased factor VIII clotting activity (25%) and absent high molecular weight multimers in the plasma. An exon 28 fragment coding for the A1 and A2 domains was amplified by polymerase chain reaction and sequenced. We found a heterozygous mutation (G4022A), producing an additional PstI restriction site, which resulted in the substitution of Arg578Gln. Family studies, including the parents and a brother, were negative for this mutation and vWF abnormalities were not observed. We confirmed that G to A mutation in the region of the platelet glycoprotein Ib binding domain of vWF causes the qualitative type 2 defect in von Willebrand disease. Korean Academy of Medical Sciences 1999-02 /pmc/articles/PMC3054163/ /pubmed/10102532 Text en |
spellingShingle | Research Article Song, K. S. Kang, S. H. Kang, M. S. Park, Y. S. Choi, J. R. Kim, H. K. Park, Q. von Willebrand disease with G4022A mutation (vWd Sungnam): a case report. |
title | von Willebrand disease with G4022A mutation (vWd Sungnam): a case report. |
title_full | von Willebrand disease with G4022A mutation (vWd Sungnam): a case report. |
title_fullStr | von Willebrand disease with G4022A mutation (vWd Sungnam): a case report. |
title_full_unstemmed | von Willebrand disease with G4022A mutation (vWd Sungnam): a case report. |
title_short | von Willebrand disease with G4022A mutation (vWd Sungnam): a case report. |
title_sort | von willebrand disease with g4022a mutation (vwd sungnam): a case report. |
topic | Research Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3054163/ https://www.ncbi.nlm.nih.gov/pubmed/10102532 |
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