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von Willebrand disease with G4022A mutation (vWd Sungnam): a case report.

A 10-year-old male patient affected by type 2 von Willebrand disease (vWD) and his family members were investigated by hemostatic and molecular genetic studies. The propositus, who experienced frequent bleeding episodes, was characterized by a normal level of von Willebrand factor (vWF) antigen (54%...

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Detalles Bibliográficos
Autores principales: Song, K. S., Kang, S. H., Kang, M. S., Park, Y. S., Choi, J. R., Kim, H. K., Park, Q.
Formato: Texto
Lenguaje:English
Publicado: Korean Academy of Medical Sciences 1999
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3054163/
https://www.ncbi.nlm.nih.gov/pubmed/10102532
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author Song, K. S.
Kang, S. H.
Kang, M. S.
Park, Y. S.
Choi, J. R.
Kim, H. K.
Park, Q.
author_facet Song, K. S.
Kang, S. H.
Kang, M. S.
Park, Y. S.
Choi, J. R.
Kim, H. K.
Park, Q.
author_sort Song, K. S.
collection PubMed
description A 10-year-old male patient affected by type 2 von Willebrand disease (vWD) and his family members were investigated by hemostatic and molecular genetic studies. The propositus, who experienced frequent bleeding episodes, was characterized by a normal level of von Willebrand factor (vWF) antigen (54%), reduced vWF ristocetin cofactor activity (5%), decreased factor VIII clotting activity (25%) and absent high molecular weight multimers in the plasma. An exon 28 fragment coding for the A1 and A2 domains was amplified by polymerase chain reaction and sequenced. We found a heterozygous mutation (G4022A), producing an additional PstI restriction site, which resulted in the substitution of Arg578Gln. Family studies, including the parents and a brother, were negative for this mutation and vWF abnormalities were not observed. We confirmed that G to A mutation in the region of the platelet glycoprotein Ib binding domain of vWF causes the qualitative type 2 defect in von Willebrand disease.
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spelling pubmed-30541632011-03-15 von Willebrand disease with G4022A mutation (vWd Sungnam): a case report. Song, K. S. Kang, S. H. Kang, M. S. Park, Y. S. Choi, J. R. Kim, H. K. Park, Q. J Korean Med Sci Research Article A 10-year-old male patient affected by type 2 von Willebrand disease (vWD) and his family members were investigated by hemostatic and molecular genetic studies. The propositus, who experienced frequent bleeding episodes, was characterized by a normal level of von Willebrand factor (vWF) antigen (54%), reduced vWF ristocetin cofactor activity (5%), decreased factor VIII clotting activity (25%) and absent high molecular weight multimers in the plasma. An exon 28 fragment coding for the A1 and A2 domains was amplified by polymerase chain reaction and sequenced. We found a heterozygous mutation (G4022A), producing an additional PstI restriction site, which resulted in the substitution of Arg578Gln. Family studies, including the parents and a brother, were negative for this mutation and vWF abnormalities were not observed. We confirmed that G to A mutation in the region of the platelet glycoprotein Ib binding domain of vWF causes the qualitative type 2 defect in von Willebrand disease. Korean Academy of Medical Sciences 1999-02 /pmc/articles/PMC3054163/ /pubmed/10102532 Text en
spellingShingle Research Article
Song, K. S.
Kang, S. H.
Kang, M. S.
Park, Y. S.
Choi, J. R.
Kim, H. K.
Park, Q.
von Willebrand disease with G4022A mutation (vWd Sungnam): a case report.
title von Willebrand disease with G4022A mutation (vWd Sungnam): a case report.
title_full von Willebrand disease with G4022A mutation (vWd Sungnam): a case report.
title_fullStr von Willebrand disease with G4022A mutation (vWd Sungnam): a case report.
title_full_unstemmed von Willebrand disease with G4022A mutation (vWd Sungnam): a case report.
title_short von Willebrand disease with G4022A mutation (vWd Sungnam): a case report.
title_sort von willebrand disease with g4022a mutation (vwd sungnam): a case report.
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3054163/
https://www.ncbi.nlm.nih.gov/pubmed/10102532
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