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A report of Joubert syndrome in an infant, with literature review

Joubert syndrome (JS) is a rare autosomal recessive disorder with key finding of cerebellar vermis hypoplasia with a complex brainstem malformation that comprises the molar tooth sign on axial magnetic resonance images. This syndrome is difficult to diagnose clinically because of its variable phenot...

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Autores principales: Singh, Paramdeep, Goraya, Jatinder S., Saggar, Kavita, Ahluwalia, Archana
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Medknow Publications 2011
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3173915/
https://www.ncbi.nlm.nih.gov/pubmed/21977088
http://dx.doi.org/10.4103/1817-1745.84407
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author Singh, Paramdeep
Goraya, Jatinder S.
Saggar, Kavita
Ahluwalia, Archana
author_facet Singh, Paramdeep
Goraya, Jatinder S.
Saggar, Kavita
Ahluwalia, Archana
author_sort Singh, Paramdeep
collection PubMed
description Joubert syndrome (JS) is a rare autosomal recessive disorder with key finding of cerebellar vermis hypoplasia with a complex brainstem malformation that comprises the molar tooth sign on axial magnetic resonance images. This syndrome is difficult to diagnose clinically because of its variable phenotype. The exact diagnosis is often not made for several years after birth. This report shows that with the availability of magnetic resonance imaging (MRI), especially in developing countries like India, it is quite feasible to make an early diagnosis which may positively affect the subsequent management and outcome. We present a case of JS in a 7-month-old girl who presented to the pediatric outpatient clinic with developmental delay and abnormal eye movements. MRI showed molar tooth configuration of superior cerebellar peduncles, the fourth ventricle shaped like a bat wing and hypoplasia of the vermis which resulted in median approach of the two cerebellar hemispheres.
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spelling pubmed-31739152011-10-04 A report of Joubert syndrome in an infant, with literature review Singh, Paramdeep Goraya, Jatinder S. Saggar, Kavita Ahluwalia, Archana J Pediatr Neurosci Case Report Joubert syndrome (JS) is a rare autosomal recessive disorder with key finding of cerebellar vermis hypoplasia with a complex brainstem malformation that comprises the molar tooth sign on axial magnetic resonance images. This syndrome is difficult to diagnose clinically because of its variable phenotype. The exact diagnosis is often not made for several years after birth. This report shows that with the availability of magnetic resonance imaging (MRI), especially in developing countries like India, it is quite feasible to make an early diagnosis which may positively affect the subsequent management and outcome. We present a case of JS in a 7-month-old girl who presented to the pediatric outpatient clinic with developmental delay and abnormal eye movements. MRI showed molar tooth configuration of superior cerebellar peduncles, the fourth ventricle shaped like a bat wing and hypoplasia of the vermis which resulted in median approach of the two cerebellar hemispheres. Medknow Publications 2011 /pmc/articles/PMC3173915/ /pubmed/21977088 http://dx.doi.org/10.4103/1817-1745.84407 Text en © Journal of Pediatric Neurosciences http://creativecommons.org/licenses/by-nc-sa/3.0 This is an open-access article distributed under the terms of the Creative Commons Attribution-Noncommercial-Share Alike 3.0 Unported, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Singh, Paramdeep
Goraya, Jatinder S.
Saggar, Kavita
Ahluwalia, Archana
A report of Joubert syndrome in an infant, with literature review
title A report of Joubert syndrome in an infant, with literature review
title_full A report of Joubert syndrome in an infant, with literature review
title_fullStr A report of Joubert syndrome in an infant, with literature review
title_full_unstemmed A report of Joubert syndrome in an infant, with literature review
title_short A report of Joubert syndrome in an infant, with literature review
title_sort report of joubert syndrome in an infant, with literature review
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3173915/
https://www.ncbi.nlm.nih.gov/pubmed/21977088
http://dx.doi.org/10.4103/1817-1745.84407
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