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A report of Joubert syndrome in an infant, with literature review
Joubert syndrome (JS) is a rare autosomal recessive disorder with key finding of cerebellar vermis hypoplasia with a complex brainstem malformation that comprises the molar tooth sign on axial magnetic resonance images. This syndrome is difficult to diagnose clinically because of its variable phenot...
Autores principales: | , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Medknow Publications
2011
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3173915/ https://www.ncbi.nlm.nih.gov/pubmed/21977088 http://dx.doi.org/10.4103/1817-1745.84407 |
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author | Singh, Paramdeep Goraya, Jatinder S. Saggar, Kavita Ahluwalia, Archana |
author_facet | Singh, Paramdeep Goraya, Jatinder S. Saggar, Kavita Ahluwalia, Archana |
author_sort | Singh, Paramdeep |
collection | PubMed |
description | Joubert syndrome (JS) is a rare autosomal recessive disorder with key finding of cerebellar vermis hypoplasia with a complex brainstem malformation that comprises the molar tooth sign on axial magnetic resonance images. This syndrome is difficult to diagnose clinically because of its variable phenotype. The exact diagnosis is often not made for several years after birth. This report shows that with the availability of magnetic resonance imaging (MRI), especially in developing countries like India, it is quite feasible to make an early diagnosis which may positively affect the subsequent management and outcome. We present a case of JS in a 7-month-old girl who presented to the pediatric outpatient clinic with developmental delay and abnormal eye movements. MRI showed molar tooth configuration of superior cerebellar peduncles, the fourth ventricle shaped like a bat wing and hypoplasia of the vermis which resulted in median approach of the two cerebellar hemispheres. |
format | Online Article Text |
id | pubmed-3173915 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2011 |
publisher | Medknow Publications |
record_format | MEDLINE/PubMed |
spelling | pubmed-31739152011-10-04 A report of Joubert syndrome in an infant, with literature review Singh, Paramdeep Goraya, Jatinder S. Saggar, Kavita Ahluwalia, Archana J Pediatr Neurosci Case Report Joubert syndrome (JS) is a rare autosomal recessive disorder with key finding of cerebellar vermis hypoplasia with a complex brainstem malformation that comprises the molar tooth sign on axial magnetic resonance images. This syndrome is difficult to diagnose clinically because of its variable phenotype. The exact diagnosis is often not made for several years after birth. This report shows that with the availability of magnetic resonance imaging (MRI), especially in developing countries like India, it is quite feasible to make an early diagnosis which may positively affect the subsequent management and outcome. We present a case of JS in a 7-month-old girl who presented to the pediatric outpatient clinic with developmental delay and abnormal eye movements. MRI showed molar tooth configuration of superior cerebellar peduncles, the fourth ventricle shaped like a bat wing and hypoplasia of the vermis which resulted in median approach of the two cerebellar hemispheres. Medknow Publications 2011 /pmc/articles/PMC3173915/ /pubmed/21977088 http://dx.doi.org/10.4103/1817-1745.84407 Text en © Journal of Pediatric Neurosciences http://creativecommons.org/licenses/by-nc-sa/3.0 This is an open-access article distributed under the terms of the Creative Commons Attribution-Noncommercial-Share Alike 3.0 Unported, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited. |
spellingShingle | Case Report Singh, Paramdeep Goraya, Jatinder S. Saggar, Kavita Ahluwalia, Archana A report of Joubert syndrome in an infant, with literature review |
title | A report of Joubert syndrome in an infant, with literature review |
title_full | A report of Joubert syndrome in an infant, with literature review |
title_fullStr | A report of Joubert syndrome in an infant, with literature review |
title_full_unstemmed | A report of Joubert syndrome in an infant, with literature review |
title_short | A report of Joubert syndrome in an infant, with literature review |
title_sort | report of joubert syndrome in an infant, with literature review |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3173915/ https://www.ncbi.nlm.nih.gov/pubmed/21977088 http://dx.doi.org/10.4103/1817-1745.84407 |
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