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Diphallus with Imperforate Anus and Complete Duplication of Recto-Sigmoid Colon and Lower Urinary Tract

BACKGROUND: Diphallus is a rare anomaly and accompanying anomalies vary from bifid scrotum, bladder exstrophy, imperforate anus and colo-rectal anomaly such as duplication, and other associated anomalies. CASE PRESENTATION: A 2-day old infant is reported with imperforate anus and complete duplicatio...

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Autores principales: Mirshemirani, Alireza, Roshanzamir, Fatollah, Shayeghi, Shahnaz, Mohajerzadeh, Leily, Hasas-yeganeh, Shaghayegh
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Tehran University of Medical Sciences 2010
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3446021/
https://www.ncbi.nlm.nih.gov/pubmed/23056710
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author Mirshemirani, Alireza
Roshanzamir, Fatollah
Shayeghi, Shahnaz
Mohajerzadeh, Leily
Hasas-yeganeh, Shaghayegh
author_facet Mirshemirani, Alireza
Roshanzamir, Fatollah
Shayeghi, Shahnaz
Mohajerzadeh, Leily
Hasas-yeganeh, Shaghayegh
author_sort Mirshemirani, Alireza
collection PubMed
description BACKGROUND: Diphallus is a rare anomaly and accompanying anomalies vary from bifid scrotum, bladder exstrophy, imperforate anus and colo-rectal anomaly such as duplication, and other associated anomalies. CASE PRESENTATION: A 2-day old infant is reported with imperforate anus and complete duplication of recto-sigmoid colon, rectal pouch, doubling of the genitalia with completely formed penis (diphallus), double bladder, urethra and hypospadias. No family history of abnormalities was noted. The patient underwent several operations: laparatory and colostomy at 3rd day of life, and after clinical and paraclinical investigations, cystoplasty, ureteral reimplantation and resection of left phallus were carried out when 4 months old. At the age of 1 year, after colostogram and total colon evaluation, laparatomy, resection of duplicated recto-sigmoid colon, and pull-through was carried out; 3 months later colostomy closure was performed and the patient discharged without complications. CONCLUSION: The patients with diphallus have to be examined carefully because of the high incidence of other systemic anomalies. Treatment of diphallus usually includes excision of the duplicated penile structure, its urethra, and repair of associated anomalies.
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spelling pubmed-34460212012-10-09 Diphallus with Imperforate Anus and Complete Duplication of Recto-Sigmoid Colon and Lower Urinary Tract Mirshemirani, Alireza Roshanzamir, Fatollah Shayeghi, Shahnaz Mohajerzadeh, Leily Hasas-yeganeh, Shaghayegh Iran J Pediatr Case Report BACKGROUND: Diphallus is a rare anomaly and accompanying anomalies vary from bifid scrotum, bladder exstrophy, imperforate anus and colo-rectal anomaly such as duplication, and other associated anomalies. CASE PRESENTATION: A 2-day old infant is reported with imperforate anus and complete duplication of recto-sigmoid colon, rectal pouch, doubling of the genitalia with completely formed penis (diphallus), double bladder, urethra and hypospadias. No family history of abnormalities was noted. The patient underwent several operations: laparatory and colostomy at 3rd day of life, and after clinical and paraclinical investigations, cystoplasty, ureteral reimplantation and resection of left phallus were carried out when 4 months old. At the age of 1 year, after colostogram and total colon evaluation, laparatomy, resection of duplicated recto-sigmoid colon, and pull-through was carried out; 3 months later colostomy closure was performed and the patient discharged without complications. CONCLUSION: The patients with diphallus have to be examined carefully because of the high incidence of other systemic anomalies. Treatment of diphallus usually includes excision of the duplicated penile structure, its urethra, and repair of associated anomalies. Tehran University of Medical Sciences 2010-06 /pmc/articles/PMC3446021/ /pubmed/23056710 Text en © 2010 Iranian Journal of Pediatrics & Tehran University of Medical Sciences http://creativecommons.org/licenses/by-nc/3.0/ This is an open-access article distributed under the terms of the Creative Commons Attribution NonCommercial 3.0 License (CC BY-NC 3.0), which allows users to read, copy, distribute and make derivative works for non-commercial purposes from the material, as long as the author of the original work is cited properly.
spellingShingle Case Report
Mirshemirani, Alireza
Roshanzamir, Fatollah
Shayeghi, Shahnaz
Mohajerzadeh, Leily
Hasas-yeganeh, Shaghayegh
Diphallus with Imperforate Anus and Complete Duplication of Recto-Sigmoid Colon and Lower Urinary Tract
title Diphallus with Imperforate Anus and Complete Duplication of Recto-Sigmoid Colon and Lower Urinary Tract
title_full Diphallus with Imperforate Anus and Complete Duplication of Recto-Sigmoid Colon and Lower Urinary Tract
title_fullStr Diphallus with Imperforate Anus and Complete Duplication of Recto-Sigmoid Colon and Lower Urinary Tract
title_full_unstemmed Diphallus with Imperforate Anus and Complete Duplication of Recto-Sigmoid Colon and Lower Urinary Tract
title_short Diphallus with Imperforate Anus and Complete Duplication of Recto-Sigmoid Colon and Lower Urinary Tract
title_sort diphallus with imperforate anus and complete duplication of recto-sigmoid colon and lower urinary tract
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3446021/
https://www.ncbi.nlm.nih.gov/pubmed/23056710
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