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BDNF gene therapy induces auditory nerve survival and fiber sprouting in deaf Pou4f3 mutant mice
Current therapy for patients with hereditary absence of cochlear hair cells, who have severe or profound deafness, is restricted to cochlear implantation, a procedure that requires survival of the auditory nerve. Mouse mutations that serve as models for genetic deafness can be utilized for developin...
Autores principales: | , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Nature Publishing Group
2012
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3495341/ https://www.ncbi.nlm.nih.gov/pubmed/23150788 http://dx.doi.org/10.1038/srep00838 |
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author | Fukui, H. Wong, H. T. Beyer, L. A. Case, B. G. Swiderski, D. L. Di Polo, A. Ryan, A. F. Raphael, Y. |
author_facet | Fukui, H. Wong, H. T. Beyer, L. A. Case, B. G. Swiderski, D. L. Di Polo, A. Ryan, A. F. Raphael, Y. |
author_sort | Fukui, H. |
collection | PubMed |
description | Current therapy for patients with hereditary absence of cochlear hair cells, who have severe or profound deafness, is restricted to cochlear implantation, a procedure that requires survival of the auditory nerve. Mouse mutations that serve as models for genetic deafness can be utilized for developing and enhancing therapies for hereditary deafness. A mouse with Pou4f3 loss of function has no hair cells and a subsequent, progressive degeneration of auditory neurons. Here we tested the influence of neurotrophin gene therapy on auditory nerve survival and peripheral sprouting in Pou4f3 mouse ears. BDNF gene transfer enhanced preservation of auditory neurons compared to control ears, in which nearly all neurons degenerated. Surviving neurons in treated ears exhibited pronounced sprouting of nerve fibers into the auditory epithelium, despite the absence of hair cells. This enhanced nerve survival and regenerative sprouting may improve the outcome of cochlear implant therapy in patients with hereditary deafness. |
format | Online Article Text |
id | pubmed-3495341 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2012 |
publisher | Nature Publishing Group |
record_format | MEDLINE/PubMed |
spelling | pubmed-34953412012-11-13 BDNF gene therapy induces auditory nerve survival and fiber sprouting in deaf Pou4f3 mutant mice Fukui, H. Wong, H. T. Beyer, L. A. Case, B. G. Swiderski, D. L. Di Polo, A. Ryan, A. F. Raphael, Y. Sci Rep Article Current therapy for patients with hereditary absence of cochlear hair cells, who have severe or profound deafness, is restricted to cochlear implantation, a procedure that requires survival of the auditory nerve. Mouse mutations that serve as models for genetic deafness can be utilized for developing and enhancing therapies for hereditary deafness. A mouse with Pou4f3 loss of function has no hair cells and a subsequent, progressive degeneration of auditory neurons. Here we tested the influence of neurotrophin gene therapy on auditory nerve survival and peripheral sprouting in Pou4f3 mouse ears. BDNF gene transfer enhanced preservation of auditory neurons compared to control ears, in which nearly all neurons degenerated. Surviving neurons in treated ears exhibited pronounced sprouting of nerve fibers into the auditory epithelium, despite the absence of hair cells. This enhanced nerve survival and regenerative sprouting may improve the outcome of cochlear implant therapy in patients with hereditary deafness. Nature Publishing Group 2012-11-12 /pmc/articles/PMC3495341/ /pubmed/23150788 http://dx.doi.org/10.1038/srep00838 Text en Copyright © 2012, Macmillan Publishers Limited. All rights reserved http://creativecommons.org/licenses/by-nc-nd/3.0/ This work is licensed under a Creative Commons Attribution-NonCommercial-NoDerivs 3.0 Unported License. To view a copy of this license, visit http://creativecommons.org/licenses/by-nc-nd/3.0/ |
spellingShingle | Article Fukui, H. Wong, H. T. Beyer, L. A. Case, B. G. Swiderski, D. L. Di Polo, A. Ryan, A. F. Raphael, Y. BDNF gene therapy induces auditory nerve survival and fiber sprouting in deaf Pou4f3 mutant mice |
title | BDNF gene therapy induces auditory nerve survival and fiber sprouting in deaf Pou4f3 mutant mice |
title_full | BDNF gene therapy induces auditory nerve survival and fiber sprouting in deaf Pou4f3 mutant mice |
title_fullStr | BDNF gene therapy induces auditory nerve survival and fiber sprouting in deaf Pou4f3 mutant mice |
title_full_unstemmed | BDNF gene therapy induces auditory nerve survival and fiber sprouting in deaf Pou4f3 mutant mice |
title_short | BDNF gene therapy induces auditory nerve survival and fiber sprouting in deaf Pou4f3 mutant mice |
title_sort | bdnf gene therapy induces auditory nerve survival and fiber sprouting in deaf pou4f3 mutant mice |
topic | Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3495341/ https://www.ncbi.nlm.nih.gov/pubmed/23150788 http://dx.doi.org/10.1038/srep00838 |
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