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An Unusual Developmental Profile of Salla Disease in a Patient with the SallaFIN Mutation
Salla disease (SD) is a disorder caused by defective storage of free sialic acid and results from mutations in the SLC17A5 gene. Early developmental delay of motor functions, and later cognitive skills, is typical. We describe a developmental profile of an unusual homozygous patient, who harboured t...
Autores principales: | , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Hindawi Publishing Corporation
2012
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3512220/ https://www.ncbi.nlm.nih.gov/pubmed/23227378 http://dx.doi.org/10.1155/2012/615721 |
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author | Paavola, Liisa E. Remes, Anne M. Sonninen, Pirkko H. Kiviniemi, Vesa V. Korhonen, Tapio T. Majamaa, Kari |
author_facet | Paavola, Liisa E. Remes, Anne M. Sonninen, Pirkko H. Kiviniemi, Vesa V. Korhonen, Tapio T. Majamaa, Kari |
author_sort | Paavola, Liisa E. |
collection | PubMed |
description | Salla disease (SD) is a disorder caused by defective storage of free sialic acid and results from mutations in the SLC17A5 gene. Early developmental delay of motor functions, and later cognitive skills, is typical. We describe a developmental profile of an unusual homozygous patient, who harboured the SallaFIN (p.R39C) mutation gene. The study involved neurological examination, neuropsychological investigation, and brain imaging. The neurocognitive findings were atypical in comparison with other patients with the SallaFIN mutation. Interestingly, there was no deterioration in the patient's neurological condition during adulthood. Her neurocognitive skills were remarkably higher than those of other patients with a conventional phenotype of SD. Our results suggest that the phenotype of SD is broad. Unidentified genetic or environmental variation might explain the unique SD type of this case. |
format | Online Article Text |
id | pubmed-3512220 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2012 |
publisher | Hindawi Publishing Corporation |
record_format | MEDLINE/PubMed |
spelling | pubmed-35122202012-12-07 An Unusual Developmental Profile of Salla Disease in a Patient with the SallaFIN Mutation Paavola, Liisa E. Remes, Anne M. Sonninen, Pirkko H. Kiviniemi, Vesa V. Korhonen, Tapio T. Majamaa, Kari Case Rep Neurol Med Case Report Salla disease (SD) is a disorder caused by defective storage of free sialic acid and results from mutations in the SLC17A5 gene. Early developmental delay of motor functions, and later cognitive skills, is typical. We describe a developmental profile of an unusual homozygous patient, who harboured the SallaFIN (p.R39C) mutation gene. The study involved neurological examination, neuropsychological investigation, and brain imaging. The neurocognitive findings were atypical in comparison with other patients with the SallaFIN mutation. Interestingly, there was no deterioration in the patient's neurological condition during adulthood. Her neurocognitive skills were remarkably higher than those of other patients with a conventional phenotype of SD. Our results suggest that the phenotype of SD is broad. Unidentified genetic or environmental variation might explain the unique SD type of this case. Hindawi Publishing Corporation 2012 2012-11-22 /pmc/articles/PMC3512220/ /pubmed/23227378 http://dx.doi.org/10.1155/2012/615721 Text en Copyright © 2012 Liisa E. Paavola et al. https://creativecommons.org/licenses/by/3.0/ This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited. |
spellingShingle | Case Report Paavola, Liisa E. Remes, Anne M. Sonninen, Pirkko H. Kiviniemi, Vesa V. Korhonen, Tapio T. Majamaa, Kari An Unusual Developmental Profile of Salla Disease in a Patient with the SallaFIN Mutation |
title | An Unusual Developmental Profile of Salla Disease in a Patient with the SallaFIN Mutation |
title_full | An Unusual Developmental Profile of Salla Disease in a Patient with the SallaFIN Mutation |
title_fullStr | An Unusual Developmental Profile of Salla Disease in a Patient with the SallaFIN Mutation |
title_full_unstemmed | An Unusual Developmental Profile of Salla Disease in a Patient with the SallaFIN Mutation |
title_short | An Unusual Developmental Profile of Salla Disease in a Patient with the SallaFIN Mutation |
title_sort | unusual developmental profile of salla disease in a patient with the sallafin mutation |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3512220/ https://www.ncbi.nlm.nih.gov/pubmed/23227378 http://dx.doi.org/10.1155/2012/615721 |
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