Corneal Involvement in Xeroderma Pigmentosum;a Histopathologic Report

PURPOSE: To report the histopathologic features of corneal involvement in a patient with xeroderma pigmentosum (XP). CASE REPORT: A 19-year-old man with XP presented with bilateral corneal leukoma and decreased visual acuity predominatly in his right eye. Penetrating keratoplasty was performed in th...

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Autores principales: Rezaei Kanavi, Mozhgan, Javadi, Mohammad-Ali, Zabihi Yeganeh, Hamid-Reza
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Ophthalmic Research Center 2008
Materias:
Case Report
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3589216/
https://www.ncbi.nlm.nih.gov/pubmed/23479524
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author Rezaei Kanavi, Mozhgan
Javadi, Mohammad-Ali
Zabihi Yeganeh, Hamid-Reza
author_facet Rezaei Kanavi, Mozhgan
Javadi, Mohammad-Ali
Zabihi Yeganeh, Hamid-Reza
author_sort Rezaei Kanavi, Mozhgan
collection PubMed
description PURPOSE: To report the histopathologic features of corneal involvement in a patient with xeroderma pigmentosum (XP). CASE REPORT: A 19-year-old man with XP presented with bilateral corneal leukoma and decreased visual acuity predominatly in his right eye. Penetrating keratoplasty was performed in the right eye due to severe corneal opacity, vascularization and lipid deposition. The corneal button underwent histopathologic evaluation which disclosed chronic interstitial lipogranulomatous keratitis. CONCLUSION: To our knowledge, this is the first report of corneal involvement in xeroderma pigmentosum from Iran describing the histopathologic features in this rare condition.
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spelling pubmed-35892162013-03-11 Corneal Involvement in Xeroderma Pigmentosum;a Histopathologic Report Rezaei Kanavi, Mozhgan Javadi, Mohammad-Ali Zabihi Yeganeh, Hamid-Reza J Ophthalmic Vis Res Case Report PURPOSE: To report the histopathologic features of corneal involvement in a patient with xeroderma pigmentosum (XP). CASE REPORT: A 19-year-old man with XP presented with bilateral corneal leukoma and decreased visual acuity predominatly in his right eye. Penetrating keratoplasty was performed in the right eye due to severe corneal opacity, vascularization and lipid deposition. The corneal button underwent histopathologic evaluation which disclosed chronic interstitial lipogranulomatous keratitis. CONCLUSION: To our knowledge, this is the first report of corneal involvement in xeroderma pigmentosum from Iran describing the histopathologic features in this rare condition. Ophthalmic Research Center 2008-01 /pmc/articles/PMC3589216/ /pubmed/23479524 Text en © 2008 Ophthalmic Research Center, Shahid Beheshti University of Medical Sciences http://creativecommons.org/licenses/by-nc/3.0/ This work is licensed under a Creative Commons Attribution-NonCommercial 3.0 Unported License which allows users to read, copy, distribute and make derivative works for non-commercial purposes from the material, as long as the author of the original work is cited properly.
spellingShingle Case Report
Rezaei Kanavi, Mozhgan
Javadi, Mohammad-Ali
Zabihi Yeganeh, Hamid-Reza
Corneal Involvement in Xeroderma Pigmentosum;a Histopathologic Report
title Corneal Involvement in Xeroderma Pigmentosum;a Histopathologic Report
title_full Corneal Involvement in Xeroderma Pigmentosum;a Histopathologic Report
title_fullStr Corneal Involvement in Xeroderma Pigmentosum;a Histopathologic Report
title_full_unstemmed Corneal Involvement in Xeroderma Pigmentosum;a Histopathologic Report
title_short Corneal Involvement in Xeroderma Pigmentosum;a Histopathologic Report
title_sort corneal involvement in xeroderma pigmentosum;a histopathologic report
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3589216/
https://www.ncbi.nlm.nih.gov/pubmed/23479524
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