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Bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis

BACKGROUND: Relapsing polychondritis (RP) is a rare inflammatory disease characterized by recurrent chondritis and inflammation of other proteoglycan-rich tissues. An RP patient with co-existing respiratory tract problems could have a poor prognosis. CASE REPORT: We reported a case of RP died with r...

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Autores principales: Kawano, Tetsuya, Matsuse, Hiroto, Kinoshita, Naoe, Tsuchida, Tomoko, Nishino, Tomoya, Fukushima, Chizu, Hayashi, Tomayoshi, Kohno, Shigeru
Formato: Online Artículo Texto
Lenguaje:English
Publicado: International Scientific Literature, Inc. 2012
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3616182/
https://www.ncbi.nlm.nih.gov/pubmed/23569504
http://dx.doi.org/10.12659/AJCR.883091
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author Kawano, Tetsuya
Matsuse, Hiroto
Kinoshita, Naoe
Tsuchida, Tomoko
Nishino, Tomoya
Fukushima, Chizu
Hayashi, Tomayoshi
Kohno, Shigeru
author_facet Kawano, Tetsuya
Matsuse, Hiroto
Kinoshita, Naoe
Tsuchida, Tomoko
Nishino, Tomoya
Fukushima, Chizu
Hayashi, Tomayoshi
Kohno, Shigeru
author_sort Kawano, Tetsuya
collection PubMed
description BACKGROUND: Relapsing polychondritis (RP) is a rare inflammatory disease characterized by recurrent chondritis and inflammation of other proteoglycan-rich tissues. An RP patient with co-existing respiratory tract problems could have a poor prognosis. CASE REPORT: We reported a case of RP died with recurrent suffocation. At the early stage in this case, unusual deformities of bronchial cartilage were observed. Following systemic corticosteroid therapy, these deformities disappeared, and typical diffuse mucosal edema and dynamic collapse of airways developed. CONCLUSIONS: These bronchoscopic abnormalities could be the early stage of RP.
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spelling pubmed-36161822013-04-08 Bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis Kawano, Tetsuya Matsuse, Hiroto Kinoshita, Naoe Tsuchida, Tomoko Nishino, Tomoya Fukushima, Chizu Hayashi, Tomayoshi Kohno, Shigeru Am J Case Rep Case Report BACKGROUND: Relapsing polychondritis (RP) is a rare inflammatory disease characterized by recurrent chondritis and inflammation of other proteoglycan-rich tissues. An RP patient with co-existing respiratory tract problems could have a poor prognosis. CASE REPORT: We reported a case of RP died with recurrent suffocation. At the early stage in this case, unusual deformities of bronchial cartilage were observed. Following systemic corticosteroid therapy, these deformities disappeared, and typical diffuse mucosal edema and dynamic collapse of airways developed. CONCLUSIONS: These bronchoscopic abnormalities could be the early stage of RP. International Scientific Literature, Inc. 2012-06-19 /pmc/articles/PMC3616182/ /pubmed/23569504 http://dx.doi.org/10.12659/AJCR.883091 Text en © Am J Case Rep, 2012 This work is licensed under a Creative Commons Attribution-NonCommercial-NoDerivs 3.0 Unported License.
spellingShingle Case Report
Kawano, Tetsuya
Matsuse, Hiroto
Kinoshita, Naoe
Tsuchida, Tomoko
Nishino, Tomoya
Fukushima, Chizu
Hayashi, Tomayoshi
Kohno, Shigeru
Bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis
title Bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis
title_full Bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis
title_fullStr Bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis
title_full_unstemmed Bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis
title_short Bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis
title_sort bronchoscopic observation of unusual deformities of bronchial cartilage and subsequent airway narrowing in respiratory relapsing polychondritis
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3616182/
https://www.ncbi.nlm.nih.gov/pubmed/23569504
http://dx.doi.org/10.12659/AJCR.883091
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