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Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome

Background. Visceral myopathy is rare pathological condition of gastrointestinal tract with uncertain clinical presentation and unknown etiology. It often presents with symptoms of chronic intestinal pseudoobstruction of colon. We report a case of visceral myopathy which presented to us as acute app...

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Autores principales: Kharbuja, Punyaram, Thakur, Raghvendra, Suo, Jian
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Hindawi Publishing Corporation 2013
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3657428/
https://www.ncbi.nlm.nih.gov/pubmed/23738185
http://dx.doi.org/10.1155/2013/906457
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author Kharbuja, Punyaram
Thakur, Raghvendra
Suo, Jian
author_facet Kharbuja, Punyaram
Thakur, Raghvendra
Suo, Jian
author_sort Kharbuja, Punyaram
collection PubMed
description Background. Visceral myopathy is rare pathological condition of gastrointestinal tract with uncertain clinical presentation and unknown etiology. It often presents with symptoms of chronic intestinal pseudoobstruction of colon. We report a case of visceral myopathy which presented to us as acute appendicitis and Ogilvie syndrome, and we managed it surgically. Method and Result. A case report of 20-year female clinically presented as acute appendicitis and we performed laparoscopic exploration which revealed inflamed appendix with grossly dilated ascending colon. We performed laparoscopic appendectomy and postoperatively managed the patients with IV fluids, antibiotics, neostigmine, and extended length rectal tube for enema and decompression. During postoperative period, she developed abdomen distension and peritonitis, and we ordered abdomen CT which revealed colon pseudo- obstruction. We performed right hemicolectomy with permanent ileostomy, and the histopathology reports of resected colon were visceral myopathy. Conclusion. Visceral myopathy is very rare group of disease and poorly understood condition that may present with chronic or acute intestinal pseudo-obstruction and often mimic other more common gastrointestinal disease. VM should be considered as differential diagnosis whenever the patient presents with acute appendicitis, uncharacteristic abdominal symptoms, recurrent attacks of abdominal distention, and pain with no radiological evidence of intestinal obstruction.
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spelling pubmed-36574282013-06-04 Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome Kharbuja, Punyaram Thakur, Raghvendra Suo, Jian Case Rep Surg Case Report Background. Visceral myopathy is rare pathological condition of gastrointestinal tract with uncertain clinical presentation and unknown etiology. It often presents with symptoms of chronic intestinal pseudoobstruction of colon. We report a case of visceral myopathy which presented to us as acute appendicitis and Ogilvie syndrome, and we managed it surgically. Method and Result. A case report of 20-year female clinically presented as acute appendicitis and we performed laparoscopic exploration which revealed inflamed appendix with grossly dilated ascending colon. We performed laparoscopic appendectomy and postoperatively managed the patients with IV fluids, antibiotics, neostigmine, and extended length rectal tube for enema and decompression. During postoperative period, she developed abdomen distension and peritonitis, and we ordered abdomen CT which revealed colon pseudo- obstruction. We performed right hemicolectomy with permanent ileostomy, and the histopathology reports of resected colon were visceral myopathy. Conclusion. Visceral myopathy is very rare group of disease and poorly understood condition that may present with chronic or acute intestinal pseudo-obstruction and often mimic other more common gastrointestinal disease. VM should be considered as differential diagnosis whenever the patient presents with acute appendicitis, uncharacteristic abdominal symptoms, recurrent attacks of abdominal distention, and pain with no radiological evidence of intestinal obstruction. Hindawi Publishing Corporation 2013 2013-04-30 /pmc/articles/PMC3657428/ /pubmed/23738185 http://dx.doi.org/10.1155/2013/906457 Text en Copyright © 2013 Punyaram Kharbuja et al. https://creativecommons.org/licenses/by/3.0/ This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Kharbuja, Punyaram
Thakur, Raghvendra
Suo, Jian
Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_full Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_fullStr Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_full_unstemmed Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_short Visceral Myopathy Presenting as Acute Appendicitis and Ogilvie Syndrome
title_sort visceral myopathy presenting as acute appendicitis and ogilvie syndrome
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3657428/
https://www.ncbi.nlm.nih.gov/pubmed/23738185
http://dx.doi.org/10.1155/2013/906457
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