Pulmonary capillary haemangiomatosis – An unusual cause of hypoxia

We describe the case of a 58-year-old man who presented with progressive dyspnoea on exertion and severe exertional hypoxia. There was a paucity of radiological findings, mild pulmonary hypertension, and no demonstrable anatomical shunt. Post mortem examination of lung tissue suggested a diagnosis o...

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Detalles Bibliográficos
Autores principales: Aston, Kerry, Riddell, Gareth J., Sheppard, Mary N., Wells, Athol U., Riley, Marshall S.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2012
Materias:
Case Report
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3920353/
https://www.ncbi.nlm.nih.gov/pubmed/26029600
http://dx.doi.org/10.1016/j.rmcr.2012.09.001
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author Aston, Kerry
Riddell, Gareth J.
Sheppard, Mary N.
Wells, Athol U.
Riley, Marshall S.
author_facet Aston, Kerry
Riddell, Gareth J.
Sheppard, Mary N.
Wells, Athol U.
Riley, Marshall S.
author_sort Aston, Kerry
collection PubMed
description We describe the case of a 58-year-old man who presented with progressive dyspnoea on exertion and severe exertional hypoxia. There was a paucity of radiological findings, mild pulmonary hypertension, and no demonstrable anatomical shunt. Post mortem examination of lung tissue suggested a diagnosis of pulmonary capillary haemangiomatosis. The case is unusual in displaying few radiological findings. We postulate that the severe hypoxia was due to shunting through the abnormal capillary proliferations.
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spelling pubmed-39203532014-10-15 Pulmonary capillary haemangiomatosis – An unusual cause of hypoxia Aston, Kerry Riddell, Gareth J. Sheppard, Mary N. Wells, Athol U. Riley, Marshall S. Respir Med Case Rep Case Report We describe the case of a 58-year-old man who presented with progressive dyspnoea on exertion and severe exertional hypoxia. There was a paucity of radiological findings, mild pulmonary hypertension, and no demonstrable anatomical shunt. Post mortem examination of lung tissue suggested a diagnosis of pulmonary capillary haemangiomatosis. The case is unusual in displaying few radiological findings. We postulate that the severe hypoxia was due to shunting through the abnormal capillary proliferations. Elsevier 2012-11-08 /pmc/articles/PMC3920353/ /pubmed/26029600 http://dx.doi.org/10.1016/j.rmcr.2012.09.001 Text en © 2012 Elsevier Ltd. http://creativecommons.org/licenses/by-nc-nd/3.0/ This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/3.0/).
spellingShingle Case Report
Aston, Kerry
Riddell, Gareth J.
Sheppard, Mary N.
Wells, Athol U.
Riley, Marshall S.
Pulmonary capillary haemangiomatosis – An unusual cause of hypoxia
title Pulmonary capillary haemangiomatosis – An unusual cause of hypoxia
title_full Pulmonary capillary haemangiomatosis – An unusual cause of hypoxia
title_fullStr Pulmonary capillary haemangiomatosis – An unusual cause of hypoxia
title_full_unstemmed Pulmonary capillary haemangiomatosis – An unusual cause of hypoxia
title_short Pulmonary capillary haemangiomatosis – An unusual cause of hypoxia
title_sort pulmonary capillary haemangiomatosis – an unusual cause of hypoxia
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3920353/
https://www.ncbi.nlm.nih.gov/pubmed/26029600
http://dx.doi.org/10.1016/j.rmcr.2012.09.001
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