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Clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the Brazilian population
BACKGROUND: Hypertrophic cardiomyopathy is a genetic autosomal dominant disease characterized by left ventricular hypertrophy. The molecular diagnosis is important but still expensive. This work aimed to find clinical predictors of a positive genetic test in a Brazilian tertiary centre cohort of ind...
Autores principales: | , , , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
BioMed Central
2014
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3995628/ https://www.ncbi.nlm.nih.gov/pubmed/24625281 http://dx.doi.org/10.1186/1471-2261-14-36 |
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author | Marsiglia, Julia Daher Carneiro Credidio, Flávia Laghi de Oliveira, Théo Gremen Mimary Reis, Rafael Ferreira Antunes, Murillo de Oliveira de Araujo, Aloir Queiroz Pedrosa, Rodrigo Pinto Barbosa-Ferreira, João Marcos Bemfica Mady, Charles Krieger, José Eduardo Arteaga-Fernandez, Edmundo Pereira, Alexandre Costa |
author_facet | Marsiglia, Julia Daher Carneiro Credidio, Flávia Laghi de Oliveira, Théo Gremen Mimary Reis, Rafael Ferreira Antunes, Murillo de Oliveira de Araujo, Aloir Queiroz Pedrosa, Rodrigo Pinto Barbosa-Ferreira, João Marcos Bemfica Mady, Charles Krieger, José Eduardo Arteaga-Fernandez, Edmundo Pereira, Alexandre Costa |
author_sort | Marsiglia, Julia Daher Carneiro |
collection | PubMed |
description | BACKGROUND: Hypertrophic cardiomyopathy is a genetic autosomal dominant disease characterized by left ventricular hypertrophy. The molecular diagnosis is important but still expensive. This work aimed to find clinical predictors of a positive genetic test in a Brazilian tertiary centre cohort of index cases with HCM. METHODS: In the study were included patients with HCM clinical diagnosis. For genotype x phenotype comparison we have evaluated echocardiographic, electrocardiographic, and nuclear magnetic resonance measures. All patients answered a questionnaire about familial history of HCM and/or sudden death. β-myosin heavy chain, myosin binding protein C, and troponin T genes were sequenced for genetic diagnosis. RESULTS: The variables related to a higher probability of a positive genetic test were familial history of HCM, higher mean heart frequency, presence of NSVT and lower age. Probabilities of having a positive molecular genetic test were calculated from the final multivariate logistic regression model and were used to identify those with a higher probability of a positive molecular diagnosis. CONCLUSIONS: We developed an easy and fast screening method that takes into account only clinical data that can help to select the patients with a high probability of positive genetic results from molecular sequencing of Brazilian HCM patients. |
format | Online Article Text |
id | pubmed-3995628 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2014 |
publisher | BioMed Central |
record_format | MEDLINE/PubMed |
spelling | pubmed-39956282014-05-07 Clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the Brazilian population Marsiglia, Julia Daher Carneiro Credidio, Flávia Laghi de Oliveira, Théo Gremen Mimary Reis, Rafael Ferreira Antunes, Murillo de Oliveira de Araujo, Aloir Queiroz Pedrosa, Rodrigo Pinto Barbosa-Ferreira, João Marcos Bemfica Mady, Charles Krieger, José Eduardo Arteaga-Fernandez, Edmundo Pereira, Alexandre Costa BMC Cardiovasc Disord Research Article BACKGROUND: Hypertrophic cardiomyopathy is a genetic autosomal dominant disease characterized by left ventricular hypertrophy. The molecular diagnosis is important but still expensive. This work aimed to find clinical predictors of a positive genetic test in a Brazilian tertiary centre cohort of index cases with HCM. METHODS: In the study were included patients with HCM clinical diagnosis. For genotype x phenotype comparison we have evaluated echocardiographic, electrocardiographic, and nuclear magnetic resonance measures. All patients answered a questionnaire about familial history of HCM and/or sudden death. β-myosin heavy chain, myosin binding protein C, and troponin T genes were sequenced for genetic diagnosis. RESULTS: The variables related to a higher probability of a positive genetic test were familial history of HCM, higher mean heart frequency, presence of NSVT and lower age. Probabilities of having a positive molecular genetic test were calculated from the final multivariate logistic regression model and were used to identify those with a higher probability of a positive molecular diagnosis. CONCLUSIONS: We developed an easy and fast screening method that takes into account only clinical data that can help to select the patients with a high probability of positive genetic results from molecular sequencing of Brazilian HCM patients. BioMed Central 2014-03-13 /pmc/articles/PMC3995628/ /pubmed/24625281 http://dx.doi.org/10.1186/1471-2261-14-36 Text en Copyright © 2014 Marsiglia et al.; licensee BioMed Central Ltd. http://creativecommons.org/licenses/by/2.0 This is an Open Access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/2.0), which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly credited. The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/) applies to the data made available in this article, unless otherwise stated. |
spellingShingle | Research Article Marsiglia, Julia Daher Carneiro Credidio, Flávia Laghi de Oliveira, Théo Gremen Mimary Reis, Rafael Ferreira Antunes, Murillo de Oliveira de Araujo, Aloir Queiroz Pedrosa, Rodrigo Pinto Barbosa-Ferreira, João Marcos Bemfica Mady, Charles Krieger, José Eduardo Arteaga-Fernandez, Edmundo Pereira, Alexandre Costa Clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the Brazilian population |
title | Clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the Brazilian population |
title_full | Clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the Brazilian population |
title_fullStr | Clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the Brazilian population |
title_full_unstemmed | Clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the Brazilian population |
title_short | Clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the Brazilian population |
title_sort | clinical predictors of a positive genetic test in hypertrophic cardiomyopathy in the brazilian population |
topic | Research Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC3995628/ https://www.ncbi.nlm.nih.gov/pubmed/24625281 http://dx.doi.org/10.1186/1471-2261-14-36 |
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