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Blast crisis Ph+ chronic myeloid leukemia with NUP98/HOXA13 up-regulating MSI2
BACKGROUND: Musashi2(Msi2)-Numb pathway de-regulation is a molecular mechanism underlying the transition of chronic phase Ph + CML to deadly blast crisis, particularly in cases with a NUP98/HOXA9 fusion from a t(7;11)(p15;p15). This study provides new insights on the mechanisms cooperating in drivin...
Autores principales: | , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
BioMed Central
2014
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4071805/ https://www.ncbi.nlm.nih.gov/pubmed/24971156 http://dx.doi.org/10.1186/1755-8166-7-42 |
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author | Di Giacomo, Danika Pierini, Valentina Barba, Gianluca Ceccarelli, Veronica Vecchini, Alba Mecucci, Cristina |
author_facet | Di Giacomo, Danika Pierini, Valentina Barba, Gianluca Ceccarelli, Veronica Vecchini, Alba Mecucci, Cristina |
author_sort | Di Giacomo, Danika |
collection | PubMed |
description | BACKGROUND: Musashi2(Msi2)-Numb pathway de-regulation is a molecular mechanism underlying the transition of chronic phase Ph + CML to deadly blast crisis, particularly in cases with a NUP98/HOXA9 fusion from a t(7;11)(p15;p15). This study provides new insights on the mechanisms cooperating in driving MSI2 over-expression and progression of Ph-positive CML. RESULTS: Herein we describe a t(7;11)(p15;p15) originating a NUP98 fusion with HOXA13, at 7p15, in a 39 year-old man in blast crisis of Ph-positive CML. Both MSI2 and HOXA9 were evaluated by quantitative RT-PCR in our patient and in a series of haematological malignancies. Up-regulation of both genes emerged only in the presence of NUP98/HOXA13 gene fusion. However, over-expression of MSI2, but not HOXA9, was found in 2 cases of Ph + blast crisis with additional chromosome aberrations other than t(7;11). To determine the mechanisms underlying MSI2 over-expression in our patient we performed Chromatin Immunoprecipitation and found that NUP98/HOXA13 fusion protein deregulates MSI2 gene by binding its promoter. CONCLUSIONS: To the best of our knowledge, this is the first molecular characterization of NUP98/HOXA13 fusion in blast crisis of Ph + CML. Our findings suggest cooperative mechanisms of MSI2 over-expression driven by HOXA proteins and strongly supports MSI2 as a prognostic marker and a candidate in target treatment of CML. |
format | Online Article Text |
id | pubmed-4071805 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2014 |
publisher | BioMed Central |
record_format | MEDLINE/PubMed |
spelling | pubmed-40718052014-06-27 Blast crisis Ph+ chronic myeloid leukemia with NUP98/HOXA13 up-regulating MSI2 Di Giacomo, Danika Pierini, Valentina Barba, Gianluca Ceccarelli, Veronica Vecchini, Alba Mecucci, Cristina Mol Cytogenet Case Report BACKGROUND: Musashi2(Msi2)-Numb pathway de-regulation is a molecular mechanism underlying the transition of chronic phase Ph + CML to deadly blast crisis, particularly in cases with a NUP98/HOXA9 fusion from a t(7;11)(p15;p15). This study provides new insights on the mechanisms cooperating in driving MSI2 over-expression and progression of Ph-positive CML. RESULTS: Herein we describe a t(7;11)(p15;p15) originating a NUP98 fusion with HOXA13, at 7p15, in a 39 year-old man in blast crisis of Ph-positive CML. Both MSI2 and HOXA9 were evaluated by quantitative RT-PCR in our patient and in a series of haematological malignancies. Up-regulation of both genes emerged only in the presence of NUP98/HOXA13 gene fusion. However, over-expression of MSI2, but not HOXA9, was found in 2 cases of Ph + blast crisis with additional chromosome aberrations other than t(7;11). To determine the mechanisms underlying MSI2 over-expression in our patient we performed Chromatin Immunoprecipitation and found that NUP98/HOXA13 fusion protein deregulates MSI2 gene by binding its promoter. CONCLUSIONS: To the best of our knowledge, this is the first molecular characterization of NUP98/HOXA13 fusion in blast crisis of Ph + CML. Our findings suggest cooperative mechanisms of MSI2 over-expression driven by HOXA proteins and strongly supports MSI2 as a prognostic marker and a candidate in target treatment of CML. BioMed Central 2014-06-20 /pmc/articles/PMC4071805/ /pubmed/24971156 http://dx.doi.org/10.1186/1755-8166-7-42 Text en Copyright © 2014 Di Giacomo et al.; licensee BioMed Central Ltd. http://creativecommons.org/licenses/by/4.0 This is an Open Access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/4.0), which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly credited. The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/) applies to the data made available in this article, unless otherwise stated. |
spellingShingle | Case Report Di Giacomo, Danika Pierini, Valentina Barba, Gianluca Ceccarelli, Veronica Vecchini, Alba Mecucci, Cristina Blast crisis Ph+ chronic myeloid leukemia with NUP98/HOXA13 up-regulating MSI2 |
title | Blast crisis Ph+ chronic myeloid leukemia with NUP98/HOXA13 up-regulating MSI2 |
title_full | Blast crisis Ph+ chronic myeloid leukemia with NUP98/HOXA13 up-regulating MSI2 |
title_fullStr | Blast crisis Ph+ chronic myeloid leukemia with NUP98/HOXA13 up-regulating MSI2 |
title_full_unstemmed | Blast crisis Ph+ chronic myeloid leukemia with NUP98/HOXA13 up-regulating MSI2 |
title_short | Blast crisis Ph+ chronic myeloid leukemia with NUP98/HOXA13 up-regulating MSI2 |
title_sort | blast crisis ph+ chronic myeloid leukemia with nup98/hoxa13 up-regulating msi2 |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4071805/ https://www.ncbi.nlm.nih.gov/pubmed/24971156 http://dx.doi.org/10.1186/1755-8166-7-42 |
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