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Ileocecal ulcers accompanied by relapsing polychondritis: a case report

INTRODUCTION: Mouth and genital ulcers with inflamed cartilage (MAGIC) syndrome is a rare overlap syndrome that includes features characteristic of both Behçet’s disease (BD) and relapsing polychondritis (RP). CASE DESCRIPTION: A 30-year-old female complained of lower abdominal pain and bloody stool...

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Autores principales: Kawakami, Yoko, Endo, Katsuya, Ishii, Tomonori, Haneda, Sho, Fujishima, Fumiyoshi, Kakuta, Yoichi, Shiga, Hisashi, Kinouchi, Yoshitaka, Shimosegawa, Tooru
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Springer International Publishing 2014
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4320181/
https://www.ncbi.nlm.nih.gov/pubmed/25674454
http://dx.doi.org/10.1186/2193-1801-3-714
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author Kawakami, Yoko
Endo, Katsuya
Ishii, Tomonori
Haneda, Sho
Fujishima, Fumiyoshi
Kakuta, Yoichi
Shiga, Hisashi
Kinouchi, Yoshitaka
Shimosegawa, Tooru
author_facet Kawakami, Yoko
Endo, Katsuya
Ishii, Tomonori
Haneda, Sho
Fujishima, Fumiyoshi
Kakuta, Yoichi
Shiga, Hisashi
Kinouchi, Yoshitaka
Shimosegawa, Tooru
author_sort Kawakami, Yoko
collection PubMed
description INTRODUCTION: Mouth and genital ulcers with inflamed cartilage (MAGIC) syndrome is a rare overlap syndrome that includes features characteristic of both Behçet’s disease (BD) and relapsing polychondritis (RP). CASE DESCRIPTION: A 30-year-old female complained of lower abdominal pain and bloody stools during medical treatment for RP. Total colonoscopy revealed oval-shaped deep ulcers on the terminal ileum similar to those of intestinal BD. After performing the ileocecal resection, both RP and gastrointestinal lesions relapsed, but improved with infliximab treatment. DISCUSSION AND EVALUATION: During medical treatment for RP, we experienced a rare case with ileocecal ulcers similar to intestinal BD. Although our case did not meet the diagnosis criteria of intestinal BD because of the lack of BD’s major clinical symptoms, intestinal lesions shared quite similar features with intestinal BD. Our case could possibly be a rare subtype of MAGIC syndrome that had the features characteristic of both intestinal BD and RP. CONCLUSIONS: We described a rare case of ileocecal ulcers without any BD symptoms but accompanied by RP, possibly be a subtype of MAGIC syndrome. ELECTRONIC SUPPLEMENTARY MATERIAL: The online version of this article (doi:10.1186/2193-1801-3-714) contains supplementary material, which is available to authorized users.
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spelling pubmed-43201812015-02-11 Ileocecal ulcers accompanied by relapsing polychondritis: a case report Kawakami, Yoko Endo, Katsuya Ishii, Tomonori Haneda, Sho Fujishima, Fumiyoshi Kakuta, Yoichi Shiga, Hisashi Kinouchi, Yoshitaka Shimosegawa, Tooru Springerplus Case Study INTRODUCTION: Mouth and genital ulcers with inflamed cartilage (MAGIC) syndrome is a rare overlap syndrome that includes features characteristic of both Behçet’s disease (BD) and relapsing polychondritis (RP). CASE DESCRIPTION: A 30-year-old female complained of lower abdominal pain and bloody stools during medical treatment for RP. Total colonoscopy revealed oval-shaped deep ulcers on the terminal ileum similar to those of intestinal BD. After performing the ileocecal resection, both RP and gastrointestinal lesions relapsed, but improved with infliximab treatment. DISCUSSION AND EVALUATION: During medical treatment for RP, we experienced a rare case with ileocecal ulcers similar to intestinal BD. Although our case did not meet the diagnosis criteria of intestinal BD because of the lack of BD’s major clinical symptoms, intestinal lesions shared quite similar features with intestinal BD. Our case could possibly be a rare subtype of MAGIC syndrome that had the features characteristic of both intestinal BD and RP. CONCLUSIONS: We described a rare case of ileocecal ulcers without any BD symptoms but accompanied by RP, possibly be a subtype of MAGIC syndrome. ELECTRONIC SUPPLEMENTARY MATERIAL: The online version of this article (doi:10.1186/2193-1801-3-714) contains supplementary material, which is available to authorized users. Springer International Publishing 2014-12-07 /pmc/articles/PMC4320181/ /pubmed/25674454 http://dx.doi.org/10.1186/2193-1801-3-714 Text en © Kawakami et al.; licensee Springer. 2014 This article is published under license to BioMed Central Ltd. This is an Open Access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/4.0), which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly credited.
spellingShingle Case Study
Kawakami, Yoko
Endo, Katsuya
Ishii, Tomonori
Haneda, Sho
Fujishima, Fumiyoshi
Kakuta, Yoichi
Shiga, Hisashi
Kinouchi, Yoshitaka
Shimosegawa, Tooru
Ileocecal ulcers accompanied by relapsing polychondritis: a case report
title Ileocecal ulcers accompanied by relapsing polychondritis: a case report
title_full Ileocecal ulcers accompanied by relapsing polychondritis: a case report
title_fullStr Ileocecal ulcers accompanied by relapsing polychondritis: a case report
title_full_unstemmed Ileocecal ulcers accompanied by relapsing polychondritis: a case report
title_short Ileocecal ulcers accompanied by relapsing polychondritis: a case report
title_sort ileocecal ulcers accompanied by relapsing polychondritis: a case report
topic Case Study
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4320181/
https://www.ncbi.nlm.nih.gov/pubmed/25674454
http://dx.doi.org/10.1186/2193-1801-3-714
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