Cargando…

Prevalence and Molecular Characterization of Glucose-6-Phosphate Dehydrogenase Deficiency at the China-Myanmar Border

Glucose-6-phosphate dehydrogenase (G6PD) deficiency is an X-linked hereditary disease that predisposes red blood cells to oxidative damage. G6PD deficiency is particularly prevalent in historically malaria-endemic areas. Use of primaquine for malaria treatment may result in severe hemolysis in G6PD...

Descripción completa

Detalles Bibliográficos
Autores principales: Li, Qing, Yang, Fang, Liu, Rong, Luo, Lan, Yang, Yuling, Zhang, Lu, Liu, Huaie, Zhang, Wen, Fan, Zhixiang, Yang, Zhaoqing, Cui, Liwang, He, Yongshu
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Public Library of Science 2015
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4520570/
https://www.ncbi.nlm.nih.gov/pubmed/26226515
http://dx.doi.org/10.1371/journal.pone.0134593
_version_ 1782383682671083520
author Li, Qing
Yang, Fang
Liu, Rong
Luo, Lan
Yang, Yuling
Zhang, Lu
Liu, Huaie
Zhang, Wen
Fan, Zhixiang
Yang, Zhaoqing
Cui, Liwang
He, Yongshu
author_facet Li, Qing
Yang, Fang
Liu, Rong
Luo, Lan
Yang, Yuling
Zhang, Lu
Liu, Huaie
Zhang, Wen
Fan, Zhixiang
Yang, Zhaoqing
Cui, Liwang
He, Yongshu
author_sort Li, Qing
collection PubMed
description Glucose-6-phosphate dehydrogenase (G6PD) deficiency is an X-linked hereditary disease that predisposes red blood cells to oxidative damage. G6PD deficiency is particularly prevalent in historically malaria-endemic areas. Use of primaquine for malaria treatment may result in severe hemolysis in G6PD deficient patients. In this study, we systematically evaluated the prevalence of G6PD deficiency in the Kachin (Jingpo) ethnic group along the China-Myanmar border and determined the underlying G6PD genotypes. We surveyed G6PD deficiency in 1770 adult individuals (671 males and 1099 females) of the Kachin ethnicity using a G6PD fluorescent spot test. The overall prevalence of G6PD deficiency in the study population was 29.6% (523/1770), among which 27.9% and 30.6% were males and females, respectively. From these G6PD deficient samples, 198 unrelated individuals (147 females and 51 males) were selected for genotyping at 11 known G6PD single nucleotide polymorphisms (SNPs) in Southeast Asia (ten in exons and one in intron 11) using a multiplex SNaPshot assay. Mutations with known association to a deficient phenotype were detected in 43.9% (87/198) of cases, intronic and synonymous mutations were detected alone in 34.8% (69/198) cases and no mutation were found in 21.2% (42/198) cases. Five non-synonymous mutations, Mahidol 487G>A, Kaiping 1388G>A, Canton 1376G>T, Chinese 4 392G>T, and Viangchan 871G>A were detected. Of the 87 cases with known deficient mutations, the Mahidol variant was the most common (89.7%; 78/87), followed by the Kaiping (8.0%; 7/87) and the Viangchan (2.2%; 2/87) variants. The Canton and Chinese 4 variants were found in 1.1% of these 87 cases. Among them, two females carried the Mahidol/Viangchan and Mahidol/Kaiping double mutations, respectively. Interestingly, the silent SNPs 1311C>T and IVS11nt93T>C both occurred in the same 95 subjects with frequencies at 56.4% and 23.5% in tested females and males, respectively (P<0.05). It is noteworthy that 24 subjects carrying the Mahidol mutation and two carrying the Kaiping mutation also carried the 1311C>T/IVS11nt93T>C SNPs. Further studies are needed to determine the enzyme levels of the G6PD deficient people and presence of additional G6PD mutations in the study population.
format Online
Article
Text
id pubmed-4520570
institution National Center for Biotechnology Information
language English
publishDate 2015
publisher Public Library of Science
record_format MEDLINE/PubMed
spelling pubmed-45205702015-08-06 Prevalence and Molecular Characterization of Glucose-6-Phosphate Dehydrogenase Deficiency at the China-Myanmar Border Li, Qing Yang, Fang Liu, Rong Luo, Lan Yang, Yuling Zhang, Lu Liu, Huaie Zhang, Wen Fan, Zhixiang Yang, Zhaoqing Cui, Liwang He, Yongshu PLoS One Research Article Glucose-6-phosphate dehydrogenase (G6PD) deficiency is an X-linked hereditary disease that predisposes red blood cells to oxidative damage. G6PD deficiency is particularly prevalent in historically malaria-endemic areas. Use of primaquine for malaria treatment may result in severe hemolysis in G6PD deficient patients. In this study, we systematically evaluated the prevalence of G6PD deficiency in the Kachin (Jingpo) ethnic group along the China-Myanmar border and determined the underlying G6PD genotypes. We surveyed G6PD deficiency in 1770 adult individuals (671 males and 1099 females) of the Kachin ethnicity using a G6PD fluorescent spot test. The overall prevalence of G6PD deficiency in the study population was 29.6% (523/1770), among which 27.9% and 30.6% were males and females, respectively. From these G6PD deficient samples, 198 unrelated individuals (147 females and 51 males) were selected for genotyping at 11 known G6PD single nucleotide polymorphisms (SNPs) in Southeast Asia (ten in exons and one in intron 11) using a multiplex SNaPshot assay. Mutations with known association to a deficient phenotype were detected in 43.9% (87/198) of cases, intronic and synonymous mutations were detected alone in 34.8% (69/198) cases and no mutation were found in 21.2% (42/198) cases. Five non-synonymous mutations, Mahidol 487G>A, Kaiping 1388G>A, Canton 1376G>T, Chinese 4 392G>T, and Viangchan 871G>A were detected. Of the 87 cases with known deficient mutations, the Mahidol variant was the most common (89.7%; 78/87), followed by the Kaiping (8.0%; 7/87) and the Viangchan (2.2%; 2/87) variants. The Canton and Chinese 4 variants were found in 1.1% of these 87 cases. Among them, two females carried the Mahidol/Viangchan and Mahidol/Kaiping double mutations, respectively. Interestingly, the silent SNPs 1311C>T and IVS11nt93T>C both occurred in the same 95 subjects with frequencies at 56.4% and 23.5% in tested females and males, respectively (P<0.05). It is noteworthy that 24 subjects carrying the Mahidol mutation and two carrying the Kaiping mutation also carried the 1311C>T/IVS11nt93T>C SNPs. Further studies are needed to determine the enzyme levels of the G6PD deficient people and presence of additional G6PD mutations in the study population. Public Library of Science 2015-07-30 /pmc/articles/PMC4520570/ /pubmed/26226515 http://dx.doi.org/10.1371/journal.pone.0134593 Text en © 2015 Li et al http://creativecommons.org/licenses/by/4.0/ This is an open-access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are properly credited.
spellingShingle Research Article
Li, Qing
Yang, Fang
Liu, Rong
Luo, Lan
Yang, Yuling
Zhang, Lu
Liu, Huaie
Zhang, Wen
Fan, Zhixiang
Yang, Zhaoqing
Cui, Liwang
He, Yongshu
Prevalence and Molecular Characterization of Glucose-6-Phosphate Dehydrogenase Deficiency at the China-Myanmar Border
title Prevalence and Molecular Characterization of Glucose-6-Phosphate Dehydrogenase Deficiency at the China-Myanmar Border
title_full Prevalence and Molecular Characterization of Glucose-6-Phosphate Dehydrogenase Deficiency at the China-Myanmar Border
title_fullStr Prevalence and Molecular Characterization of Glucose-6-Phosphate Dehydrogenase Deficiency at the China-Myanmar Border
title_full_unstemmed Prevalence and Molecular Characterization of Glucose-6-Phosphate Dehydrogenase Deficiency at the China-Myanmar Border
title_short Prevalence and Molecular Characterization of Glucose-6-Phosphate Dehydrogenase Deficiency at the China-Myanmar Border
title_sort prevalence and molecular characterization of glucose-6-phosphate dehydrogenase deficiency at the china-myanmar border
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4520570/
https://www.ncbi.nlm.nih.gov/pubmed/26226515
http://dx.doi.org/10.1371/journal.pone.0134593
work_keys_str_mv AT liqing prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT yangfang prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT liurong prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT luolan prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT yangyuling prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT zhanglu prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT liuhuaie prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT zhangwen prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT fanzhixiang prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT yangzhaoqing prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT cuiliwang prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder
AT heyongshu prevalenceandmolecularcharacterizationofglucose6phosphatedehydrogenasedeficiencyatthechinamyanmarborder