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Array CGH Analysis of Paired Blood and Tumor Samples from Patients with Sporadic Wilms Tumor

Wilms tumor (WT), the most common cancer of the kidney in infants and children, has a complex etiology that is still poorly understood. Identification of genomic copy number variants (CNV) in tumor genomes provides a better understanding of cancer development which may be useful for diagnosis and th...

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Autores principales: Cabral de Almeida Cardoso, Leila, Rodriguez-Laguna, Lara, del Carmen Crespo, María, Vallespín, Elena, Palomares-Bralo, María, Martin-Arenas, Rubén, Rueda-Arenas, Inmaculada, Silvestre de Faria, Paulo Antonio, García-Miguel, Purificación, Lapunzina, Pablo, Regla Vargas, Fernando, Seuanez, Hector N., Martínez-Glez, Víctor
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Public Library of Science 2015
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4552764/
https://www.ncbi.nlm.nih.gov/pubmed/26317783
http://dx.doi.org/10.1371/journal.pone.0136812
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author Cabral de Almeida Cardoso, Leila
Rodriguez-Laguna, Lara
del Carmen Crespo, María
Vallespín, Elena
Palomares-Bralo, María
Martin-Arenas, Rubén
Rueda-Arenas, Inmaculada
Silvestre de Faria, Paulo Antonio
García-Miguel, Purificación
Lapunzina, Pablo
Regla Vargas, Fernando
Seuanez, Hector N.
Martínez-Glez, Víctor
author_facet Cabral de Almeida Cardoso, Leila
Rodriguez-Laguna, Lara
del Carmen Crespo, María
Vallespín, Elena
Palomares-Bralo, María
Martin-Arenas, Rubén
Rueda-Arenas, Inmaculada
Silvestre de Faria, Paulo Antonio
García-Miguel, Purificación
Lapunzina, Pablo
Regla Vargas, Fernando
Seuanez, Hector N.
Martínez-Glez, Víctor
author_sort Cabral de Almeida Cardoso, Leila
collection PubMed
description Wilms tumor (WT), the most common cancer of the kidney in infants and children, has a complex etiology that is still poorly understood. Identification of genomic copy number variants (CNV) in tumor genomes provides a better understanding of cancer development which may be useful for diagnosis and therapeutic targets. In paired blood and tumor DNA samples from 14 patients with sporadic WT, analyzed by aCGH, 22% of chromosome abnormalities were novel. All constitutional alterations identified in blood were segmental (in 28.6% of patients) and were also present in the paired tumor samples. Two segmental gains (2p21 and 20q13.3) and one loss (19q13.31) present in blood had not been previously described in WT. We also describe, for the first time, a small, constitutive partial gain of 3p22.1 comprising 2 exons of CTNNB1, a gene associated to WT. Among somatic alterations, novel structural chromosomal abnormalities were found, like gain of 19p13.3 and 20p12.3, and losses of 2p16.1-p15, 4q32.5-q35.1, 4q35.2-q28.1 and 19p13.3. Candidate genes included in these regions might be constitutively (SIX3, SALL4) or somatically (NEK1, PIAS4, BMP2) operational in the development and progression of WT. To our knowledge this is the first report of CNV in paired blood and tumor samples in sporadic WT.
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spelling pubmed-45527642015-09-10 Array CGH Analysis of Paired Blood and Tumor Samples from Patients with Sporadic Wilms Tumor Cabral de Almeida Cardoso, Leila Rodriguez-Laguna, Lara del Carmen Crespo, María Vallespín, Elena Palomares-Bralo, María Martin-Arenas, Rubén Rueda-Arenas, Inmaculada Silvestre de Faria, Paulo Antonio García-Miguel, Purificación Lapunzina, Pablo Regla Vargas, Fernando Seuanez, Hector N. Martínez-Glez, Víctor PLoS One Research Article Wilms tumor (WT), the most common cancer of the kidney in infants and children, has a complex etiology that is still poorly understood. Identification of genomic copy number variants (CNV) in tumor genomes provides a better understanding of cancer development which may be useful for diagnosis and therapeutic targets. In paired blood and tumor DNA samples from 14 patients with sporadic WT, analyzed by aCGH, 22% of chromosome abnormalities were novel. All constitutional alterations identified in blood were segmental (in 28.6% of patients) and were also present in the paired tumor samples. Two segmental gains (2p21 and 20q13.3) and one loss (19q13.31) present in blood had not been previously described in WT. We also describe, for the first time, a small, constitutive partial gain of 3p22.1 comprising 2 exons of CTNNB1, a gene associated to WT. Among somatic alterations, novel structural chromosomal abnormalities were found, like gain of 19p13.3 and 20p12.3, and losses of 2p16.1-p15, 4q32.5-q35.1, 4q35.2-q28.1 and 19p13.3. Candidate genes included in these regions might be constitutively (SIX3, SALL4) or somatically (NEK1, PIAS4, BMP2) operational in the development and progression of WT. To our knowledge this is the first report of CNV in paired blood and tumor samples in sporadic WT. Public Library of Science 2015-08-28 /pmc/articles/PMC4552764/ /pubmed/26317783 http://dx.doi.org/10.1371/journal.pone.0136812 Text en © 2015 Cabral de Almeida Cardoso et al http://creativecommons.org/licenses/by/4.0/ This is an open-access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are properly credited.
spellingShingle Research Article
Cabral de Almeida Cardoso, Leila
Rodriguez-Laguna, Lara
del Carmen Crespo, María
Vallespín, Elena
Palomares-Bralo, María
Martin-Arenas, Rubén
Rueda-Arenas, Inmaculada
Silvestre de Faria, Paulo Antonio
García-Miguel, Purificación
Lapunzina, Pablo
Regla Vargas, Fernando
Seuanez, Hector N.
Martínez-Glez, Víctor
Array CGH Analysis of Paired Blood and Tumor Samples from Patients with Sporadic Wilms Tumor
title Array CGH Analysis of Paired Blood and Tumor Samples from Patients with Sporadic Wilms Tumor
title_full Array CGH Analysis of Paired Blood and Tumor Samples from Patients with Sporadic Wilms Tumor
title_fullStr Array CGH Analysis of Paired Blood and Tumor Samples from Patients with Sporadic Wilms Tumor
title_full_unstemmed Array CGH Analysis of Paired Blood and Tumor Samples from Patients with Sporadic Wilms Tumor
title_short Array CGH Analysis of Paired Blood and Tumor Samples from Patients with Sporadic Wilms Tumor
title_sort array cgh analysis of paired blood and tumor samples from patients with sporadic wilms tumor
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4552764/
https://www.ncbi.nlm.nih.gov/pubmed/26317783
http://dx.doi.org/10.1371/journal.pone.0136812
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