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Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging
The focal form of congenital hyperinsulinism (CHI) is characterized by a cluster of abnormal insulin-oversecreting β cells within a restricted area of the pancreas. Although identification of the focal lesion is very important in the management of CHI, it has been reported that imaging studies, incl...
Autores principales: | , , , , , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
BioMed Central
2015
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4570655/ https://www.ncbi.nlm.nih.gov/pubmed/26379717 http://dx.doi.org/10.1186/s13633-015-0016-0 |
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author | Hashimoto, Yukiko Sakakibara, Azumi Kawakita, Rie Hosokawa, Yuki Fujimaru, Rika Nakamura, Tetsuro Fukushima, Hiroko Igarashi, Aiko Masue, Michiya Nishibori, Hironori Tamagawa, Nobuyoshi Murakami, Akiko Hatake, Kazue Yorifuji, Tohru |
author_facet | Hashimoto, Yukiko Sakakibara, Azumi Kawakita, Rie Hosokawa, Yuki Fujimaru, Rika Nakamura, Tetsuro Fukushima, Hiroko Igarashi, Aiko Masue, Michiya Nishibori, Hironori Tamagawa, Nobuyoshi Murakami, Akiko Hatake, Kazue Yorifuji, Tohru |
author_sort | Hashimoto, Yukiko |
collection | PubMed |
description | The focal form of congenital hyperinsulinism (CHI) is characterized by a cluster of abnormal insulin-oversecreting β cells within a restricted area of the pancreas. Although identification of the focal lesion is very important in the management of CHI, it has been reported that imaging studies, including computed tomography (CT), magnetic resonance imaging (MRI) scans, or angiography, are not helpful in identifying the focal lesion. Currently, fluorine-18-L-dihydroxyphenylalanine positron emission tomography ((18)F-DOPA PET) is believed to be the only imaging modality that can identify the focal lesions. In this report, however, we present a case of a 7-month-old girl with the focal form of CHI, caused by a loss-of-function mutation in the ABCC8 gene, whose lesion was clearly visible as a hyperenhancing nodule on contrast-enhanced CT and dynamic MRI imaging. |
format | Online Article Text |
id | pubmed-4570655 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2015 |
publisher | BioMed Central |
record_format | MEDLINE/PubMed |
spelling | pubmed-45706552015-09-16 Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging Hashimoto, Yukiko Sakakibara, Azumi Kawakita, Rie Hosokawa, Yuki Fujimaru, Rika Nakamura, Tetsuro Fukushima, Hiroko Igarashi, Aiko Masue, Michiya Nishibori, Hironori Tamagawa, Nobuyoshi Murakami, Akiko Hatake, Kazue Yorifuji, Tohru Int J Pediatr Endocrinol Case Report The focal form of congenital hyperinsulinism (CHI) is characterized by a cluster of abnormal insulin-oversecreting β cells within a restricted area of the pancreas. Although identification of the focal lesion is very important in the management of CHI, it has been reported that imaging studies, including computed tomography (CT), magnetic resonance imaging (MRI) scans, or angiography, are not helpful in identifying the focal lesion. Currently, fluorine-18-L-dihydroxyphenylalanine positron emission tomography ((18)F-DOPA PET) is believed to be the only imaging modality that can identify the focal lesions. In this report, however, we present a case of a 7-month-old girl with the focal form of CHI, caused by a loss-of-function mutation in the ABCC8 gene, whose lesion was clearly visible as a hyperenhancing nodule on contrast-enhanced CT and dynamic MRI imaging. BioMed Central 2015-09-15 2015 /pmc/articles/PMC4570655/ /pubmed/26379717 http://dx.doi.org/10.1186/s13633-015-0016-0 Text en © Hashimoto et al. 2015 Open Access This article is distributed under the terms of the Creative Commons Attribution 4.0 International License (http://creativecommons.org/licenses/by/4.0), which permits unrestricted use, distribution, and reproduction in any medium, provided you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/) applies to the data made available in this article, unless otherwise stated. |
spellingShingle | Case Report Hashimoto, Yukiko Sakakibara, Azumi Kawakita, Rie Hosokawa, Yuki Fujimaru, Rika Nakamura, Tetsuro Fukushima, Hiroko Igarashi, Aiko Masue, Michiya Nishibori, Hironori Tamagawa, Nobuyoshi Murakami, Akiko Hatake, Kazue Yorifuji, Tohru Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging |
title | Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging |
title_full | Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging |
title_fullStr | Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging |
title_full_unstemmed | Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging |
title_short | Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging |
title_sort | focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4570655/ https://www.ncbi.nlm.nih.gov/pubmed/26379717 http://dx.doi.org/10.1186/s13633-015-0016-0 |
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