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Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging

The focal form of congenital hyperinsulinism (CHI) is characterized by a cluster of abnormal insulin-oversecreting β cells within a restricted area of the pancreas. Although identification of the focal lesion is very important in the management of CHI, it has been reported that imaging studies, incl...

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Autores principales: Hashimoto, Yukiko, Sakakibara, Azumi, Kawakita, Rie, Hosokawa, Yuki, Fujimaru, Rika, Nakamura, Tetsuro, Fukushima, Hiroko, Igarashi, Aiko, Masue, Michiya, Nishibori, Hironori, Tamagawa, Nobuyoshi, Murakami, Akiko, Hatake, Kazue, Yorifuji, Tohru
Formato: Online Artículo Texto
Lenguaje:English
Publicado: BioMed Central 2015
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4570655/
https://www.ncbi.nlm.nih.gov/pubmed/26379717
http://dx.doi.org/10.1186/s13633-015-0016-0
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author Hashimoto, Yukiko
Sakakibara, Azumi
Kawakita, Rie
Hosokawa, Yuki
Fujimaru, Rika
Nakamura, Tetsuro
Fukushima, Hiroko
Igarashi, Aiko
Masue, Michiya
Nishibori, Hironori
Tamagawa, Nobuyoshi
Murakami, Akiko
Hatake, Kazue
Yorifuji, Tohru
author_facet Hashimoto, Yukiko
Sakakibara, Azumi
Kawakita, Rie
Hosokawa, Yuki
Fujimaru, Rika
Nakamura, Tetsuro
Fukushima, Hiroko
Igarashi, Aiko
Masue, Michiya
Nishibori, Hironori
Tamagawa, Nobuyoshi
Murakami, Akiko
Hatake, Kazue
Yorifuji, Tohru
author_sort Hashimoto, Yukiko
collection PubMed
description The focal form of congenital hyperinsulinism (CHI) is characterized by a cluster of abnormal insulin-oversecreting β cells within a restricted area of the pancreas. Although identification of the focal lesion is very important in the management of CHI, it has been reported that imaging studies, including computed tomography (CT), magnetic resonance imaging (MRI) scans, or angiography, are not helpful in identifying the focal lesion. Currently, fluorine-18-L-dihydroxyphenylalanine positron emission tomography ((18)F-DOPA PET) is believed to be the only imaging modality that can identify the focal lesions. In this report, however, we present a case of a 7-month-old girl with the focal form of CHI, caused by a loss-of-function mutation in the ABCC8 gene, whose lesion was clearly visible as a hyperenhancing nodule on contrast-enhanced CT and dynamic MRI imaging.
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spelling pubmed-45706552015-09-16 Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging Hashimoto, Yukiko Sakakibara, Azumi Kawakita, Rie Hosokawa, Yuki Fujimaru, Rika Nakamura, Tetsuro Fukushima, Hiroko Igarashi, Aiko Masue, Michiya Nishibori, Hironori Tamagawa, Nobuyoshi Murakami, Akiko Hatake, Kazue Yorifuji, Tohru Int J Pediatr Endocrinol Case Report The focal form of congenital hyperinsulinism (CHI) is characterized by a cluster of abnormal insulin-oversecreting β cells within a restricted area of the pancreas. Although identification of the focal lesion is very important in the management of CHI, it has been reported that imaging studies, including computed tomography (CT), magnetic resonance imaging (MRI) scans, or angiography, are not helpful in identifying the focal lesion. Currently, fluorine-18-L-dihydroxyphenylalanine positron emission tomography ((18)F-DOPA PET) is believed to be the only imaging modality that can identify the focal lesions. In this report, however, we present a case of a 7-month-old girl with the focal form of CHI, caused by a loss-of-function mutation in the ABCC8 gene, whose lesion was clearly visible as a hyperenhancing nodule on contrast-enhanced CT and dynamic MRI imaging. BioMed Central 2015-09-15 2015 /pmc/articles/PMC4570655/ /pubmed/26379717 http://dx.doi.org/10.1186/s13633-015-0016-0 Text en © Hashimoto et al. 2015 Open Access This article is distributed under the terms of the Creative Commons Attribution 4.0 International License (http://creativecommons.org/licenses/by/4.0), which permits unrestricted use, distribution, and reproduction in any medium, provided you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The Creative Commons Public Domain Dedication waiver (http://creativecommons.org/publicdomain/zero/1.0/) applies to the data made available in this article, unless otherwise stated.
spellingShingle Case Report
Hashimoto, Yukiko
Sakakibara, Azumi
Kawakita, Rie
Hosokawa, Yuki
Fujimaru, Rika
Nakamura, Tetsuro
Fukushima, Hiroko
Igarashi, Aiko
Masue, Michiya
Nishibori, Hironori
Tamagawa, Nobuyoshi
Murakami, Akiko
Hatake, Kazue
Yorifuji, Tohru
Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging
title Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging
title_full Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging
title_fullStr Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging
title_full_unstemmed Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging
title_short Focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging
title_sort focal form of congenital hyperinsulinism clearly detectable by contrast-enhanced computed tomography imaging
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4570655/
https://www.ncbi.nlm.nih.gov/pubmed/26379717
http://dx.doi.org/10.1186/s13633-015-0016-0
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