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Genetic variants in PLCB4/PLCB1 as susceptibility loci for coronary artery aneurysm formation in Kawasaki disease in Han Chinese in Taiwan

Kawasaki disease (KD) is an acute, inflammatory, and self-limited vasculitis affecting infants and young children. Coronary artery aneurysm (CAA) formation is the major complication of KD and the leading cause of acquired cardiovascular disease among children. To identify susceptible loci that might...

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Autores principales: Lin, Ying-Ju, Chang, Jeng-Sheng, Liu, Xiang, Tsang, Hsinyi, Chien, Wen-Kuei, Chen, Jin-Hua, Hsieh, Hsin-Yang, Hsueh, Kai-Chung, Shiao, Yi-Tzone, Li, Ju-Pi, Lin, Cheng-Wen, Lai, Chih-Ho, Wu, Jer-Yuarn, Chen, Chien-Hsiun, Lin, Jaung-Geng, Lin, Ting-Hsu, Liao, Chiu-Chu, Huang, Shao-Mei, Lan, Yu-Ching, Ho, Tsung-Jung, Liang, Wen-Miin, Yeh, Yi-Chun, Lin, Jung-Chun, Tsai, Fuu-Jen
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Nature Publishing Group 2015
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4593004/
https://www.ncbi.nlm.nih.gov/pubmed/26434682
http://dx.doi.org/10.1038/srep14762
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author Lin, Ying-Ju
Chang, Jeng-Sheng
Liu, Xiang
Tsang, Hsinyi
Chien, Wen-Kuei
Chen, Jin-Hua
Hsieh, Hsin-Yang
Hsueh, Kai-Chung
Shiao, Yi-Tzone
Li, Ju-Pi
Lin, Cheng-Wen
Lai, Chih-Ho
Wu, Jer-Yuarn
Chen, Chien-Hsiun
Lin, Jaung-Geng
Lin, Ting-Hsu
Liao, Chiu-Chu
Huang, Shao-Mei
Lan, Yu-Ching
Ho, Tsung-Jung
Liang, Wen-Miin
Yeh, Yi-Chun
Lin, Jung-Chun
Tsai, Fuu-Jen
author_facet Lin, Ying-Ju
Chang, Jeng-Sheng
Liu, Xiang
Tsang, Hsinyi
Chien, Wen-Kuei
Chen, Jin-Hua
Hsieh, Hsin-Yang
Hsueh, Kai-Chung
Shiao, Yi-Tzone
Li, Ju-Pi
Lin, Cheng-Wen
Lai, Chih-Ho
Wu, Jer-Yuarn
Chen, Chien-Hsiun
Lin, Jaung-Geng
Lin, Ting-Hsu
Liao, Chiu-Chu
Huang, Shao-Mei
Lan, Yu-Ching
Ho, Tsung-Jung
Liang, Wen-Miin
Yeh, Yi-Chun
Lin, Jung-Chun
Tsai, Fuu-Jen
author_sort Lin, Ying-Ju
collection PubMed
description Kawasaki disease (KD) is an acute, inflammatory, and self-limited vasculitis affecting infants and young children. Coronary artery aneurysm (CAA) formation is the major complication of KD and the leading cause of acquired cardiovascular disease among children. To identify susceptible loci that might predispose patients with KD to CAA formation, a genome-wide association screen was performed in a Taiwanese KD cohort. Patients with both KD and CAA had longer fever duration and delayed intravenous immunoglobulin treatment time. After adjusting for these factors, 100 susceptibility loci were identified. Four genes were identified from a single cluster of 35 using the Ingenuity Pathway Analysis (IPA) Knowledge Base. Silencing KCNQ5, PLCB1, PLCB4, and PLCL1 inhibited the effect of lipopolysaccharide-induced endothelial cell inflammation with varying degrees of proinflammatory cytokine expression. PLCB1 showed the most significant inhibition. Endothelial cell inflammation was also inhibited by using a phospholipase C (PLC) inhibitor. The single nucleotide polymorphism rs6140791 was identified between PLCB4 and PLCB1. Plasma PLC levels were higher in patients with KD and CC+CG rs6140791genotypes, and these genotypes were more prevalent in patients with KD who also had CAA. Our results suggest that polymorphism of the PLCB4/B1 genes might be involved in the CAA pathogenesis of KD.
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spelling pubmed-45930042015-10-19 Genetic variants in PLCB4/PLCB1 as susceptibility loci for coronary artery aneurysm formation in Kawasaki disease in Han Chinese in Taiwan Lin, Ying-Ju Chang, Jeng-Sheng Liu, Xiang Tsang, Hsinyi Chien, Wen-Kuei Chen, Jin-Hua Hsieh, Hsin-Yang Hsueh, Kai-Chung Shiao, Yi-Tzone Li, Ju-Pi Lin, Cheng-Wen Lai, Chih-Ho Wu, Jer-Yuarn Chen, Chien-Hsiun Lin, Jaung-Geng Lin, Ting-Hsu Liao, Chiu-Chu Huang, Shao-Mei Lan, Yu-Ching Ho, Tsung-Jung Liang, Wen-Miin Yeh, Yi-Chun Lin, Jung-Chun Tsai, Fuu-Jen Sci Rep Article Kawasaki disease (KD) is an acute, inflammatory, and self-limited vasculitis affecting infants and young children. Coronary artery aneurysm (CAA) formation is the major complication of KD and the leading cause of acquired cardiovascular disease among children. To identify susceptible loci that might predispose patients with KD to CAA formation, a genome-wide association screen was performed in a Taiwanese KD cohort. Patients with both KD and CAA had longer fever duration and delayed intravenous immunoglobulin treatment time. After adjusting for these factors, 100 susceptibility loci were identified. Four genes were identified from a single cluster of 35 using the Ingenuity Pathway Analysis (IPA) Knowledge Base. Silencing KCNQ5, PLCB1, PLCB4, and PLCL1 inhibited the effect of lipopolysaccharide-induced endothelial cell inflammation with varying degrees of proinflammatory cytokine expression. PLCB1 showed the most significant inhibition. Endothelial cell inflammation was also inhibited by using a phospholipase C (PLC) inhibitor. The single nucleotide polymorphism rs6140791 was identified between PLCB4 and PLCB1. Plasma PLC levels were higher in patients with KD and CC+CG rs6140791genotypes, and these genotypes were more prevalent in patients with KD who also had CAA. Our results suggest that polymorphism of the PLCB4/B1 genes might be involved in the CAA pathogenesis of KD. Nature Publishing Group 2015-10-05 /pmc/articles/PMC4593004/ /pubmed/26434682 http://dx.doi.org/10.1038/srep14762 Text en Copyright © 2015, Macmillan Publishers Limited http://creativecommons.org/licenses/by/4.0/ This work is licensed under a Creative Commons Attribution 4.0 International License. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in the credit line; if the material is not included under the Creative Commons license, users will need to obtain permission from the license holder to reproduce the material. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/
spellingShingle Article
Lin, Ying-Ju
Chang, Jeng-Sheng
Liu, Xiang
Tsang, Hsinyi
Chien, Wen-Kuei
Chen, Jin-Hua
Hsieh, Hsin-Yang
Hsueh, Kai-Chung
Shiao, Yi-Tzone
Li, Ju-Pi
Lin, Cheng-Wen
Lai, Chih-Ho
Wu, Jer-Yuarn
Chen, Chien-Hsiun
Lin, Jaung-Geng
Lin, Ting-Hsu
Liao, Chiu-Chu
Huang, Shao-Mei
Lan, Yu-Ching
Ho, Tsung-Jung
Liang, Wen-Miin
Yeh, Yi-Chun
Lin, Jung-Chun
Tsai, Fuu-Jen
Genetic variants in PLCB4/PLCB1 as susceptibility loci for coronary artery aneurysm formation in Kawasaki disease in Han Chinese in Taiwan
title Genetic variants in PLCB4/PLCB1 as susceptibility loci for coronary artery aneurysm formation in Kawasaki disease in Han Chinese in Taiwan
title_full Genetic variants in PLCB4/PLCB1 as susceptibility loci for coronary artery aneurysm formation in Kawasaki disease in Han Chinese in Taiwan
title_fullStr Genetic variants in PLCB4/PLCB1 as susceptibility loci for coronary artery aneurysm formation in Kawasaki disease in Han Chinese in Taiwan
title_full_unstemmed Genetic variants in PLCB4/PLCB1 as susceptibility loci for coronary artery aneurysm formation in Kawasaki disease in Han Chinese in Taiwan
title_short Genetic variants in PLCB4/PLCB1 as susceptibility loci for coronary artery aneurysm formation in Kawasaki disease in Han Chinese in Taiwan
title_sort genetic variants in plcb4/plcb1 as susceptibility loci for coronary artery aneurysm formation in kawasaki disease in han chinese in taiwan
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4593004/
https://www.ncbi.nlm.nih.gov/pubmed/26434682
http://dx.doi.org/10.1038/srep14762
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