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Aneurysm of the Left Coronary Artery in Postoperative Bland-White-Garland Syndrome

We report a case of anomalous left coronary artery from the pulmonary artery (ALCAPA) or Bland-White-Garland syndrome, present the challenges of performing a differential diagnosis, and discuss the treatment of the syndrome. Although ALCAPA is a rare congenital heart disease, it is one of the most c...

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Autores principales: Bravo-Valenzuela, Nathalie Jeanne Magioli, Silva, Guilherme Ricardo Nunes
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Hindawi Publishing Corporation 2015
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4684846/
https://www.ncbi.nlm.nih.gov/pubmed/26770839
http://dx.doi.org/10.1155/2015/568014
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author Bravo-Valenzuela, Nathalie Jeanne Magioli
Silva, Guilherme Ricardo Nunes
author_facet Bravo-Valenzuela, Nathalie Jeanne Magioli
Silva, Guilherme Ricardo Nunes
author_sort Bravo-Valenzuela, Nathalie Jeanne Magioli
collection PubMed
description We report a case of anomalous left coronary artery from the pulmonary artery (ALCAPA) or Bland-White-Garland syndrome, present the challenges of performing a differential diagnosis, and discuss the treatment of the syndrome. Although ALCAPA is a rare congenital heart disease, it is one of the most common causes of myocardial ischemia in childhood and presents a diagnostic challenge. A four-year-old girl was referred to a pediatric cardiologist for evaluation of mitral valve regurgitation murmur and heart failure. The transthoracic echocardiogram demonstrated the left coronary artery (LCA) not arising from the aorta, presence of coronary collateral circulation, and moderate mitral valve regurgitation. ALCAPA was confirmed using angiotomography. The LCA was surgically reimplanted into the aorta. After 3 years of postoperative follow-up, the patient developed an LCA aneurysm. Diagnosis of cardiac ischemia in childhood remains a challenge, and careful evaluation of coronary arteries on the echocardiogram is an important tool. In this report, we present a case of ALCAPA with an uncommon postoperative outcome.
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spelling pubmed-46848462016-01-14 Aneurysm of the Left Coronary Artery in Postoperative Bland-White-Garland Syndrome Bravo-Valenzuela, Nathalie Jeanne Magioli Silva, Guilherme Ricardo Nunes Case Rep Cardiol Case Report We report a case of anomalous left coronary artery from the pulmonary artery (ALCAPA) or Bland-White-Garland syndrome, present the challenges of performing a differential diagnosis, and discuss the treatment of the syndrome. Although ALCAPA is a rare congenital heart disease, it is one of the most common causes of myocardial ischemia in childhood and presents a diagnostic challenge. A four-year-old girl was referred to a pediatric cardiologist for evaluation of mitral valve regurgitation murmur and heart failure. The transthoracic echocardiogram demonstrated the left coronary artery (LCA) not arising from the aorta, presence of coronary collateral circulation, and moderate mitral valve regurgitation. ALCAPA was confirmed using angiotomography. The LCA was surgically reimplanted into the aorta. After 3 years of postoperative follow-up, the patient developed an LCA aneurysm. Diagnosis of cardiac ischemia in childhood remains a challenge, and careful evaluation of coronary arteries on the echocardiogram is an important tool. In this report, we present a case of ALCAPA with an uncommon postoperative outcome. Hindawi Publishing Corporation 2015 2015-12-06 /pmc/articles/PMC4684846/ /pubmed/26770839 http://dx.doi.org/10.1155/2015/568014 Text en Copyright © 2015 N. J. M. Bravo-Valenzuela and G. R. N. Silva. https://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Bravo-Valenzuela, Nathalie Jeanne Magioli
Silva, Guilherme Ricardo Nunes
Aneurysm of the Left Coronary Artery in Postoperative Bland-White-Garland Syndrome
title Aneurysm of the Left Coronary Artery in Postoperative Bland-White-Garland Syndrome
title_full Aneurysm of the Left Coronary Artery in Postoperative Bland-White-Garland Syndrome
title_fullStr Aneurysm of the Left Coronary Artery in Postoperative Bland-White-Garland Syndrome
title_full_unstemmed Aneurysm of the Left Coronary Artery in Postoperative Bland-White-Garland Syndrome
title_short Aneurysm of the Left Coronary Artery in Postoperative Bland-White-Garland Syndrome
title_sort aneurysm of the left coronary artery in postoperative bland-white-garland syndrome
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4684846/
https://www.ncbi.nlm.nih.gov/pubmed/26770839
http://dx.doi.org/10.1155/2015/568014
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