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Chromosomal Integrity after UV Irradiation Requires FANCD2-Mediated Repair of Double Strand Breaks

Fanconi Anemia (FA) is a rare autosomal recessive disorder characterized by hypersensitivity to inter-strand crosslinks (ICLs). FANCD2, a central factor of the FA pathway, is essential for the repair of double strand breaks (DSBs) generated during fork collapse at ICLs. While lesions different from...

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Autores principales: Federico, María Belén, Vallerga, María Belén, Radl, Analía, Paviolo, Natalia Soledad, Bocco, José Luis, Di Giorgio, Marina, Soria, Gastón, Gottifredi, Vanesa
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Public Library of Science 2016
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4712966/
https://www.ncbi.nlm.nih.gov/pubmed/26765540
http://dx.doi.org/10.1371/journal.pgen.1005792
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author Federico, María Belén
Vallerga, María Belén
Radl, Analía
Paviolo, Natalia Soledad
Bocco, José Luis
Di Giorgio, Marina
Soria, Gastón
Gottifredi, Vanesa
author_facet Federico, María Belén
Vallerga, María Belén
Radl, Analía
Paviolo, Natalia Soledad
Bocco, José Luis
Di Giorgio, Marina
Soria, Gastón
Gottifredi, Vanesa
author_sort Federico, María Belén
collection PubMed
description Fanconi Anemia (FA) is a rare autosomal recessive disorder characterized by hypersensitivity to inter-strand crosslinks (ICLs). FANCD2, a central factor of the FA pathway, is essential for the repair of double strand breaks (DSBs) generated during fork collapse at ICLs. While lesions different from ICLs can also trigger fork collapse, the contribution of FANCD2 to the resolution of replication-coupled DSBs generated independently from ICLs is unknown. Intriguingly, FANCD2 is readily activated after UV irradiation, a DNA-damaging agent that generates predominantly intra-strand crosslinks but not ICLs. Hence, UV irradiation is an ideal tool to explore the contribution of FANCD2 to the DNA damage response triggered by DNA lesions other than ICL repair. Here we show that, in contrast to ICL-causing agents, UV radiation compromises cell survival independently from FANCD2. In agreement, FANCD2 depletion does not increase the amount of DSBs generated during the replication of UV-damaged DNA and is dispensable for UV-induced checkpoint activation. Remarkably however, FANCD2 protects UV-dependent, replication-coupled DSBs from aberrant processing by non-homologous end joining, preventing the accumulation of micronuclei and chromatid aberrations including non-homologous chromatid exchanges. Hence, while dispensable for cell survival, FANCD2 selectively safeguards chromosomal stability after UV-triggered replication stress.
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spelling pubmed-47129662016-01-26 Chromosomal Integrity after UV Irradiation Requires FANCD2-Mediated Repair of Double Strand Breaks Federico, María Belén Vallerga, María Belén Radl, Analía Paviolo, Natalia Soledad Bocco, José Luis Di Giorgio, Marina Soria, Gastón Gottifredi, Vanesa PLoS Genet Research Article Fanconi Anemia (FA) is a rare autosomal recessive disorder characterized by hypersensitivity to inter-strand crosslinks (ICLs). FANCD2, a central factor of the FA pathway, is essential for the repair of double strand breaks (DSBs) generated during fork collapse at ICLs. While lesions different from ICLs can also trigger fork collapse, the contribution of FANCD2 to the resolution of replication-coupled DSBs generated independently from ICLs is unknown. Intriguingly, FANCD2 is readily activated after UV irradiation, a DNA-damaging agent that generates predominantly intra-strand crosslinks but not ICLs. Hence, UV irradiation is an ideal tool to explore the contribution of FANCD2 to the DNA damage response triggered by DNA lesions other than ICL repair. Here we show that, in contrast to ICL-causing agents, UV radiation compromises cell survival independently from FANCD2. In agreement, FANCD2 depletion does not increase the amount of DSBs generated during the replication of UV-damaged DNA and is dispensable for UV-induced checkpoint activation. Remarkably however, FANCD2 protects UV-dependent, replication-coupled DSBs from aberrant processing by non-homologous end joining, preventing the accumulation of micronuclei and chromatid aberrations including non-homologous chromatid exchanges. Hence, while dispensable for cell survival, FANCD2 selectively safeguards chromosomal stability after UV-triggered replication stress. Public Library of Science 2016-01-14 /pmc/articles/PMC4712966/ /pubmed/26765540 http://dx.doi.org/10.1371/journal.pgen.1005792 Text en © 2016 Federico et al http://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/4.0/) , which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited.
spellingShingle Research Article
Federico, María Belén
Vallerga, María Belén
Radl, Analía
Paviolo, Natalia Soledad
Bocco, José Luis
Di Giorgio, Marina
Soria, Gastón
Gottifredi, Vanesa
Chromosomal Integrity after UV Irradiation Requires FANCD2-Mediated Repair of Double Strand Breaks
title Chromosomal Integrity after UV Irradiation Requires FANCD2-Mediated Repair of Double Strand Breaks
title_full Chromosomal Integrity after UV Irradiation Requires FANCD2-Mediated Repair of Double Strand Breaks
title_fullStr Chromosomal Integrity after UV Irradiation Requires FANCD2-Mediated Repair of Double Strand Breaks
title_full_unstemmed Chromosomal Integrity after UV Irradiation Requires FANCD2-Mediated Repair of Double Strand Breaks
title_short Chromosomal Integrity after UV Irradiation Requires FANCD2-Mediated Repair of Double Strand Breaks
title_sort chromosomal integrity after uv irradiation requires fancd2-mediated repair of double strand breaks
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4712966/
https://www.ncbi.nlm.nih.gov/pubmed/26765540
http://dx.doi.org/10.1371/journal.pgen.1005792
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