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Congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops
Firstly described by Rudolf Virchow in the 19th century, congenital generalized lymphangiectasia is a rare entity characterized by dilation of lymphatic vessels, and was recently classified in primary or secondary lymphangiectasia. Generalized forms may be diagnosed during pre-natal follow-up with u...
Autores principales: | , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
São Paulo, SP: Universidade de São Paulo, Hospital Universitário
2015
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4757917/ https://www.ncbi.nlm.nih.gov/pubmed/26894043 http://dx.doi.org/10.4322/acr.2015.027 |
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author | Ferreira, Cristiane Rúbia Sibre, Verônica Schultz, Regina de Melo, Ana Maria Andrello Gonçalves Pereira Ibidi, Silvia Maria Torre, Jackeline Della |
author_facet | Ferreira, Cristiane Rúbia Sibre, Verônica Schultz, Regina de Melo, Ana Maria Andrello Gonçalves Pereira Ibidi, Silvia Maria Torre, Jackeline Della |
author_sort | Ferreira, Cristiane Rúbia |
collection | PubMed |
description | Firstly described by Rudolf Virchow in the 19th century, congenital generalized lymphangiectasia is a rare entity characterized by dilation of lymphatic vessels, and was recently classified in primary or secondary lymphangiectasia. Generalized forms may be diagnosed during pre-natal follow-up with ultrasound examination, and, depending on its severity, the newborn outcome is very poor. The authors report the case of a female newborn with a previous diagnosis of fetal hydropsy who was born after a full-term gestation with respiratory failure due to bilateral voluminous pleural effusion and ascites. Physical examination also disclosed syndromic facies. Despite all efforts of the intensive supportive care, the patient died after 24 days of life. The autopsy findings were consistent with the diagnosis of congenital pulmonary lymphangiectasia. The authors call attention to this rare diagnosis in patients with cavitary effusion and respiratory insufficiency at birth. |
format | Online Article Text |
id | pubmed-4757917 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2015 |
publisher | São Paulo, SP: Universidade de São Paulo, Hospital Universitário |
record_format | MEDLINE/PubMed |
spelling | pubmed-47579172016-02-18 Congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops Ferreira, Cristiane Rúbia Sibre, Verônica Schultz, Regina de Melo, Ana Maria Andrello Gonçalves Pereira Ibidi, Silvia Maria Torre, Jackeline Della Autops Case Rep Article / Autopsy Case Report Firstly described by Rudolf Virchow in the 19th century, congenital generalized lymphangiectasia is a rare entity characterized by dilation of lymphatic vessels, and was recently classified in primary or secondary lymphangiectasia. Generalized forms may be diagnosed during pre-natal follow-up with ultrasound examination, and, depending on its severity, the newborn outcome is very poor. The authors report the case of a female newborn with a previous diagnosis of fetal hydropsy who was born after a full-term gestation with respiratory failure due to bilateral voluminous pleural effusion and ascites. Physical examination also disclosed syndromic facies. Despite all efforts of the intensive supportive care, the patient died after 24 days of life. The autopsy findings were consistent with the diagnosis of congenital pulmonary lymphangiectasia. The authors call attention to this rare diagnosis in patients with cavitary effusion and respiratory insufficiency at birth. São Paulo, SP: Universidade de São Paulo, Hospital Universitário 2015-12-30 /pmc/articles/PMC4757917/ /pubmed/26894043 http://dx.doi.org/10.4322/acr.2015.027 Text en Autopsy and Case Reports. ISSN 2236-1960. Copyright © 2015. http://creativecommons.org/licenses/by-nc/3.0/ This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License which permits unrestricted non-commercial use, distribution, and reproduction in any medium provided article is properly cited. |
spellingShingle | Article / Autopsy Case Report Ferreira, Cristiane Rúbia Sibre, Verônica Schultz, Regina de Melo, Ana Maria Andrello Gonçalves Pereira Ibidi, Silvia Maria Torre, Jackeline Della Congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops |
title | Congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops |
title_full | Congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops |
title_fullStr | Congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops |
title_full_unstemmed | Congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops |
title_short | Congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops |
title_sort | congenital generalized lymphangiectasia: a rare developmental disorder for non-immune fetal hydrops |
topic | Article / Autopsy Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4757917/ https://www.ncbi.nlm.nih.gov/pubmed/26894043 http://dx.doi.org/10.4322/acr.2015.027 |
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