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A 62-year-old man with dyspnea
We describe the case of a 62-year-old man who presented with shortness of breath that had progressed over several years. He had a history of a paralyzed right hemidiaphragm for at least the previous 10 years. He also reported weakness in his proximal legs and daytime sleepiness. On examination, he w...
Autores principales: | , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Elsevier
2016
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4821326/ https://www.ncbi.nlm.nih.gov/pubmed/27141434 http://dx.doi.org/10.1016/j.rmcr.2016.01.003 |
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author | Baqir, Misbah Ryu, Jay H. Sorenson, Eric J. Olson, Eric J. |
author_facet | Baqir, Misbah Ryu, Jay H. Sorenson, Eric J. Olson, Eric J. |
author_sort | Baqir, Misbah |
collection | PubMed |
description | We describe the case of a 62-year-old man who presented with shortness of breath that had progressed over several years. He had a history of a paralyzed right hemidiaphragm for at least the previous 10 years. He also reported weakness in his proximal legs and daytime sleepiness. On examination, he was found to have thoracoabdominal paradox when in supine position. Pulmonary function testing revealed severe restriction; arterial blood gas showed chronic respiratory acidosis. Electromyography showed chronic phrenic neuropathy bilaterally, with mild proximal myopathy. Serum aldolase level was mildly elevated, but serologic tests for connective tissue disorders were within reference range. After extensive clinical investigations, the patient was found to have severely reduced acid α-glucosidase. Genetic analysis confirmed the diagnosis of adult-onset Pompe disease. The patient started treatment with bilevel positive airway pressure titrated during polysomnography, and acid α-glucosidase enzyme replacement was recommended. |
format | Online Article Text |
id | pubmed-4821326 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2016 |
publisher | Elsevier |
record_format | MEDLINE/PubMed |
spelling | pubmed-48213262016-05-02 A 62-year-old man with dyspnea Baqir, Misbah Ryu, Jay H. Sorenson, Eric J. Olson, Eric J. Respir Med Case Rep Case Report We describe the case of a 62-year-old man who presented with shortness of breath that had progressed over several years. He had a history of a paralyzed right hemidiaphragm for at least the previous 10 years. He also reported weakness in his proximal legs and daytime sleepiness. On examination, he was found to have thoracoabdominal paradox when in supine position. Pulmonary function testing revealed severe restriction; arterial blood gas showed chronic respiratory acidosis. Electromyography showed chronic phrenic neuropathy bilaterally, with mild proximal myopathy. Serum aldolase level was mildly elevated, but serologic tests for connective tissue disorders were within reference range. After extensive clinical investigations, the patient was found to have severely reduced acid α-glucosidase. Genetic analysis confirmed the diagnosis of adult-onset Pompe disease. The patient started treatment with bilevel positive airway pressure titrated during polysomnography, and acid α-glucosidase enzyme replacement was recommended. Elsevier 2016-01-12 /pmc/articles/PMC4821326/ /pubmed/27141434 http://dx.doi.org/10.1016/j.rmcr.2016.01.003 Text en © 2016 The Authors http://creativecommons.org/licenses/by-nc-nd/4.0/ This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/). |
spellingShingle | Case Report Baqir, Misbah Ryu, Jay H. Sorenson, Eric J. Olson, Eric J. A 62-year-old man with dyspnea |
title | A 62-year-old man with dyspnea |
title_full | A 62-year-old man with dyspnea |
title_fullStr | A 62-year-old man with dyspnea |
title_full_unstemmed | A 62-year-old man with dyspnea |
title_short | A 62-year-old man with dyspnea |
title_sort | 62-year-old man with dyspnea |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4821326/ https://www.ncbi.nlm.nih.gov/pubmed/27141434 http://dx.doi.org/10.1016/j.rmcr.2016.01.003 |
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