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A 62-year-old man with dyspnea

We describe the case of a 62-year-old man who presented with shortness of breath that had progressed over several years. He had a history of a paralyzed right hemidiaphragm for at least the previous 10 years. He also reported weakness in his proximal legs and daytime sleepiness. On examination, he w...

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Detalles Bibliográficos
Autores principales: Baqir, Misbah, Ryu, Jay H., Sorenson, Eric J., Olson, Eric J.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2016
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4821326/
https://www.ncbi.nlm.nih.gov/pubmed/27141434
http://dx.doi.org/10.1016/j.rmcr.2016.01.003
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author Baqir, Misbah
Ryu, Jay H.
Sorenson, Eric J.
Olson, Eric J.
author_facet Baqir, Misbah
Ryu, Jay H.
Sorenson, Eric J.
Olson, Eric J.
author_sort Baqir, Misbah
collection PubMed
description We describe the case of a 62-year-old man who presented with shortness of breath that had progressed over several years. He had a history of a paralyzed right hemidiaphragm for at least the previous 10 years. He also reported weakness in his proximal legs and daytime sleepiness. On examination, he was found to have thoracoabdominal paradox when in supine position. Pulmonary function testing revealed severe restriction; arterial blood gas showed chronic respiratory acidosis. Electromyography showed chronic phrenic neuropathy bilaterally, with mild proximal myopathy. Serum aldolase level was mildly elevated, but serologic tests for connective tissue disorders were within reference range. After extensive clinical investigations, the patient was found to have severely reduced acid α-glucosidase. Genetic analysis confirmed the diagnosis of adult-onset Pompe disease. The patient started treatment with bilevel positive airway pressure titrated during polysomnography, and acid α-glucosidase enzyme replacement was recommended.
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spelling pubmed-48213262016-05-02 A 62-year-old man with dyspnea Baqir, Misbah Ryu, Jay H. Sorenson, Eric J. Olson, Eric J. Respir Med Case Rep Case Report We describe the case of a 62-year-old man who presented with shortness of breath that had progressed over several years. He had a history of a paralyzed right hemidiaphragm for at least the previous 10 years. He also reported weakness in his proximal legs and daytime sleepiness. On examination, he was found to have thoracoabdominal paradox when in supine position. Pulmonary function testing revealed severe restriction; arterial blood gas showed chronic respiratory acidosis. Electromyography showed chronic phrenic neuropathy bilaterally, with mild proximal myopathy. Serum aldolase level was mildly elevated, but serologic tests for connective tissue disorders were within reference range. After extensive clinical investigations, the patient was found to have severely reduced acid α-glucosidase. Genetic analysis confirmed the diagnosis of adult-onset Pompe disease. The patient started treatment with bilevel positive airway pressure titrated during polysomnography, and acid α-glucosidase enzyme replacement was recommended. Elsevier 2016-01-12 /pmc/articles/PMC4821326/ /pubmed/27141434 http://dx.doi.org/10.1016/j.rmcr.2016.01.003 Text en © 2016 The Authors http://creativecommons.org/licenses/by-nc-nd/4.0/ This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).
spellingShingle Case Report
Baqir, Misbah
Ryu, Jay H.
Sorenson, Eric J.
Olson, Eric J.
A 62-year-old man with dyspnea
title A 62-year-old man with dyspnea
title_full A 62-year-old man with dyspnea
title_fullStr A 62-year-old man with dyspnea
title_full_unstemmed A 62-year-old man with dyspnea
title_short A 62-year-old man with dyspnea
title_sort 62-year-old man with dyspnea
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4821326/
https://www.ncbi.nlm.nih.gov/pubmed/27141434
http://dx.doi.org/10.1016/j.rmcr.2016.01.003
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