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Adult presentation of Bartter syndrome type IV with erythrocytosis

Bartter syndrome comprises a group of rare autosomal-recessive salt-losing disorders with distinct phenotypes, but one unifying pathophysiology consisting of severe reductions of sodium reabsorption caused by mutations in five genes expressed in the thick ascending limb of Henle, coupled with increa...

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Autores principales: Heilberg, Ita Pfeferman, Tótoli, Cláudia, Calado, Joaquim Tomaz
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Instituto Israelita de Ensino e Pesquisa Albert Einstein 2015
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4878638/
https://www.ncbi.nlm.nih.gov/pubmed/26537508
http://dx.doi.org/10.1590/S1679-45082015RC3013
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author Heilberg, Ita Pfeferman
Tótoli, Cláudia
Calado, Joaquim Tomaz
author_facet Heilberg, Ita Pfeferman
Tótoli, Cláudia
Calado, Joaquim Tomaz
author_sort Heilberg, Ita Pfeferman
collection PubMed
description Bartter syndrome comprises a group of rare autosomal-recessive salt-losing disorders with distinct phenotypes, but one unifying pathophysiology consisting of severe reductions of sodium reabsorption caused by mutations in five genes expressed in the thick ascending limb of Henle, coupled with increased urinary excretion of potassium and hydrogen, which leads to hypokalemic alkalosis. Bartter syndrome type IV, caused by loss-of-function mutations in barttin, a subunit of chloride channel CLC-Kb expressed in the kidney and inner ear, usually occurs in the antenatal-neonatal period. We report an unusual case of late onset presentation of Bartter syndrome IV and mild phenotype in a 20 years-old man who had hypokalemia, deafness, secondary hyperparathyroidism and erythrocytosis.
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spelling pubmed-48786382016-08-10 Adult presentation of Bartter syndrome type IV with erythrocytosis Heilberg, Ita Pfeferman Tótoli, Cláudia Calado, Joaquim Tomaz Einstein (Sao Paulo) Case Report Bartter syndrome comprises a group of rare autosomal-recessive salt-losing disorders with distinct phenotypes, but one unifying pathophysiology consisting of severe reductions of sodium reabsorption caused by mutations in five genes expressed in the thick ascending limb of Henle, coupled with increased urinary excretion of potassium and hydrogen, which leads to hypokalemic alkalosis. Bartter syndrome type IV, caused by loss-of-function mutations in barttin, a subunit of chloride channel CLC-Kb expressed in the kidney and inner ear, usually occurs in the antenatal-neonatal period. We report an unusual case of late onset presentation of Bartter syndrome IV and mild phenotype in a 20 years-old man who had hypokalemia, deafness, secondary hyperparathyroidism and erythrocytosis. Instituto Israelita de Ensino e Pesquisa Albert Einstein 2015 /pmc/articles/PMC4878638/ /pubmed/26537508 http://dx.doi.org/10.1590/S1679-45082015RC3013 Text en http://creativecommons.org/licenses/by/4.0/ This is an Open Access article distributed under the terms of the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Heilberg, Ita Pfeferman
Tótoli, Cláudia
Calado, Joaquim Tomaz
Adult presentation of Bartter syndrome type IV with erythrocytosis
title Adult presentation of Bartter syndrome type IV with erythrocytosis
title_full Adult presentation of Bartter syndrome type IV with erythrocytosis
title_fullStr Adult presentation of Bartter syndrome type IV with erythrocytosis
title_full_unstemmed Adult presentation of Bartter syndrome type IV with erythrocytosis
title_short Adult presentation of Bartter syndrome type IV with erythrocytosis
title_sort adult presentation of bartter syndrome type iv with erythrocytosis
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC4878638/
https://www.ncbi.nlm.nih.gov/pubmed/26537508
http://dx.doi.org/10.1590/S1679-45082015RC3013
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