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A Novel Mutation in ABCA1 Gene Causing Tangier Disease in an Italian Family with Uncommon Neurological Presentation

Tangier disease is an autosomal recessive disorder characterized by severe reduction in high-density lipoprotein cholesterol and peripheral lipid storage. We describe a family with c.5094C > A p.Tyr1698* mutation in the ABCA1 gene, clinically characterized by syringomyelic-like anesthesia, demyel...

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Autores principales: Ceccanti, Marco, Cambieri, Chiara, Frasca, Vittorio, Onesti, Emanuela, Biasiotta, Antonella, Giordano, Carla, Bruno, Sabina M., Testino, Giancarlo, Lucarelli, Marco, Arca, Marcello, Inghilleri, Maurizio
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Frontiers Media S.A. 2016
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5089975/
https://www.ncbi.nlm.nih.gov/pubmed/27853448
http://dx.doi.org/10.3389/fneur.2016.00185
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author Ceccanti, Marco
Cambieri, Chiara
Frasca, Vittorio
Onesti, Emanuela
Biasiotta, Antonella
Giordano, Carla
Bruno, Sabina M.
Testino, Giancarlo
Lucarelli, Marco
Arca, Marcello
Inghilleri, Maurizio
author_facet Ceccanti, Marco
Cambieri, Chiara
Frasca, Vittorio
Onesti, Emanuela
Biasiotta, Antonella
Giordano, Carla
Bruno, Sabina M.
Testino, Giancarlo
Lucarelli, Marco
Arca, Marcello
Inghilleri, Maurizio
author_sort Ceccanti, Marco
collection PubMed
description Tangier disease is an autosomal recessive disorder characterized by severe reduction in high-density lipoprotein cholesterol and peripheral lipid storage. We describe a family with c.5094C > A p.Tyr1698* mutation in the ABCA1 gene, clinically characterized by syringomyelic-like anesthesia, demyelinating multineuropathy, and reduction in intraepidermal small fibers innervation. In the proband patient, cardiac involvement determined a myocardial infarction; lipid storage was demonstrated in gut, cornea, and aortic wall. The reported ABCA1 mutation has never been described before in a Tangier family.
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spelling pubmed-50899752016-11-16 A Novel Mutation in ABCA1 Gene Causing Tangier Disease in an Italian Family with Uncommon Neurological Presentation Ceccanti, Marco Cambieri, Chiara Frasca, Vittorio Onesti, Emanuela Biasiotta, Antonella Giordano, Carla Bruno, Sabina M. Testino, Giancarlo Lucarelli, Marco Arca, Marcello Inghilleri, Maurizio Front Neurol Neuroscience Tangier disease is an autosomal recessive disorder characterized by severe reduction in high-density lipoprotein cholesterol and peripheral lipid storage. We describe a family with c.5094C > A p.Tyr1698* mutation in the ABCA1 gene, clinically characterized by syringomyelic-like anesthesia, demyelinating multineuropathy, and reduction in intraepidermal small fibers innervation. In the proband patient, cardiac involvement determined a myocardial infarction; lipid storage was demonstrated in gut, cornea, and aortic wall. The reported ABCA1 mutation has never been described before in a Tangier family. Frontiers Media S.A. 2016-11-02 /pmc/articles/PMC5089975/ /pubmed/27853448 http://dx.doi.org/10.3389/fneur.2016.00185 Text en Copyright © 2016 Ceccanti, Cambieri, Frasca, Onesti, Biasiotta, Giordano, Bruno, Testino, Lucarelli, Arca and Inghilleri. http://creativecommons.org/licenses/by/4.0/ This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) or licensor are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms.
spellingShingle Neuroscience
Ceccanti, Marco
Cambieri, Chiara
Frasca, Vittorio
Onesti, Emanuela
Biasiotta, Antonella
Giordano, Carla
Bruno, Sabina M.
Testino, Giancarlo
Lucarelli, Marco
Arca, Marcello
Inghilleri, Maurizio
A Novel Mutation in ABCA1 Gene Causing Tangier Disease in an Italian Family with Uncommon Neurological Presentation
title A Novel Mutation in ABCA1 Gene Causing Tangier Disease in an Italian Family with Uncommon Neurological Presentation
title_full A Novel Mutation in ABCA1 Gene Causing Tangier Disease in an Italian Family with Uncommon Neurological Presentation
title_fullStr A Novel Mutation in ABCA1 Gene Causing Tangier Disease in an Italian Family with Uncommon Neurological Presentation
title_full_unstemmed A Novel Mutation in ABCA1 Gene Causing Tangier Disease in an Italian Family with Uncommon Neurological Presentation
title_short A Novel Mutation in ABCA1 Gene Causing Tangier Disease in an Italian Family with Uncommon Neurological Presentation
title_sort novel mutation in abca1 gene causing tangier disease in an italian family with uncommon neurological presentation
topic Neuroscience
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5089975/
https://www.ncbi.nlm.nih.gov/pubmed/27853448
http://dx.doi.org/10.3389/fneur.2016.00185
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