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Trichobezoar presenting as a gastric outlet obstruction: A case report

INTRODUCTION: Rapunzel syndrome is a rare intestinal condition that starts with the ingestion of a trichobezoar. The condition is predominately found in females and can be associated with trichotillomania, or the compulsive urge to pull one’s own hair out. There are less than 40 cases described in t...

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Autores principales: Nwankwo, Eugene, Daniele, Edward, Woller, Erin, Fitzwater, John, McGill, Thomas, Brooks, Steven E.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Elsevier 2017
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5397571/
https://www.ncbi.nlm.nih.gov/pubmed/28431376
http://dx.doi.org/10.1016/j.ijscr.2017.03.011
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author Nwankwo, Eugene
Daniele, Edward
Woller, Erin
Fitzwater, John
McGill, Thomas
Brooks, Steven E.
author_facet Nwankwo, Eugene
Daniele, Edward
Woller, Erin
Fitzwater, John
McGill, Thomas
Brooks, Steven E.
author_sort Nwankwo, Eugene
collection PubMed
description INTRODUCTION: Rapunzel syndrome is a rare intestinal condition that starts with the ingestion of a trichobezoar. The condition is predominately found in females and can be associated with trichotillomania, or the compulsive urge to pull one’s own hair out. There are less than 40 cases described in the literature with the prevention of recurrence aimed at psychological treatment. PRESENTATION OF CASE: The patient is a 7 year-old girl with a history of trichotillomania with trichophagia as a young child who presented with abdominal pain, nausea, and vomiting, consistent with a gastric outlet obstruction. She had an exploratory laparotomy with gastrostomy performed revealing a 18 cm by 18 cm trichobezoar with extension into the small bowel. DISCUSSION: Bezoars, an already rare entity, can occasionally lead to gastric and small bowel obstructions. Small collections of ingested hair build up in the intestinal tract causing significant symptoms. These obstructions can sometimes be treated through minimally invasive techniques but, in our case described, it is unlikely to have been treated any other way due to the substantial size of the trichobezoar. CONCLUSION: Early consideration of Rapunzel syndrome is important in young females presenting with a gastric outlet obstruction.
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spelling pubmed-53975712017-05-01 Trichobezoar presenting as a gastric outlet obstruction: A case report Nwankwo, Eugene Daniele, Edward Woller, Erin Fitzwater, John McGill, Thomas Brooks, Steven E. Int J Surg Case Rep Case Report INTRODUCTION: Rapunzel syndrome is a rare intestinal condition that starts with the ingestion of a trichobezoar. The condition is predominately found in females and can be associated with trichotillomania, or the compulsive urge to pull one’s own hair out. There are less than 40 cases described in the literature with the prevention of recurrence aimed at psychological treatment. PRESENTATION OF CASE: The patient is a 7 year-old girl with a history of trichotillomania with trichophagia as a young child who presented with abdominal pain, nausea, and vomiting, consistent with a gastric outlet obstruction. She had an exploratory laparotomy with gastrostomy performed revealing a 18 cm by 18 cm trichobezoar with extension into the small bowel. DISCUSSION: Bezoars, an already rare entity, can occasionally lead to gastric and small bowel obstructions. Small collections of ingested hair build up in the intestinal tract causing significant symptoms. These obstructions can sometimes be treated through minimally invasive techniques but, in our case described, it is unlikely to have been treated any other way due to the substantial size of the trichobezoar. CONCLUSION: Early consideration of Rapunzel syndrome is important in young females presenting with a gastric outlet obstruction. Elsevier 2017-03-16 /pmc/articles/PMC5397571/ /pubmed/28431376 http://dx.doi.org/10.1016/j.ijscr.2017.03.011 Text en http://creativecommons.org/licenses/by-nc-nd/4.0/ This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/).
spellingShingle Case Report
Nwankwo, Eugene
Daniele, Edward
Woller, Erin
Fitzwater, John
McGill, Thomas
Brooks, Steven E.
Trichobezoar presenting as a gastric outlet obstruction: A case report
title Trichobezoar presenting as a gastric outlet obstruction: A case report
title_full Trichobezoar presenting as a gastric outlet obstruction: A case report
title_fullStr Trichobezoar presenting as a gastric outlet obstruction: A case report
title_full_unstemmed Trichobezoar presenting as a gastric outlet obstruction: A case report
title_short Trichobezoar presenting as a gastric outlet obstruction: A case report
title_sort trichobezoar presenting as a gastric outlet obstruction: a case report
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5397571/
https://www.ncbi.nlm.nih.gov/pubmed/28431376
http://dx.doi.org/10.1016/j.ijscr.2017.03.011
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