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Trichobezoar presenting as a gastric outlet obstruction: A case report
INTRODUCTION: Rapunzel syndrome is a rare intestinal condition that starts with the ingestion of a trichobezoar. The condition is predominately found in females and can be associated with trichotillomania, or the compulsive urge to pull one’s own hair out. There are less than 40 cases described in t...
Autores principales: | , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Elsevier
2017
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5397571/ https://www.ncbi.nlm.nih.gov/pubmed/28431376 http://dx.doi.org/10.1016/j.ijscr.2017.03.011 |
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author | Nwankwo, Eugene Daniele, Edward Woller, Erin Fitzwater, John McGill, Thomas Brooks, Steven E. |
author_facet | Nwankwo, Eugene Daniele, Edward Woller, Erin Fitzwater, John McGill, Thomas Brooks, Steven E. |
author_sort | Nwankwo, Eugene |
collection | PubMed |
description | INTRODUCTION: Rapunzel syndrome is a rare intestinal condition that starts with the ingestion of a trichobezoar. The condition is predominately found in females and can be associated with trichotillomania, or the compulsive urge to pull one’s own hair out. There are less than 40 cases described in the literature with the prevention of recurrence aimed at psychological treatment. PRESENTATION OF CASE: The patient is a 7 year-old girl with a history of trichotillomania with trichophagia as a young child who presented with abdominal pain, nausea, and vomiting, consistent with a gastric outlet obstruction. She had an exploratory laparotomy with gastrostomy performed revealing a 18 cm by 18 cm trichobezoar with extension into the small bowel. DISCUSSION: Bezoars, an already rare entity, can occasionally lead to gastric and small bowel obstructions. Small collections of ingested hair build up in the intestinal tract causing significant symptoms. These obstructions can sometimes be treated through minimally invasive techniques but, in our case described, it is unlikely to have been treated any other way due to the substantial size of the trichobezoar. CONCLUSION: Early consideration of Rapunzel syndrome is important in young females presenting with a gastric outlet obstruction. |
format | Online Article Text |
id | pubmed-5397571 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2017 |
publisher | Elsevier |
record_format | MEDLINE/PubMed |
spelling | pubmed-53975712017-05-01 Trichobezoar presenting as a gastric outlet obstruction: A case report Nwankwo, Eugene Daniele, Edward Woller, Erin Fitzwater, John McGill, Thomas Brooks, Steven E. Int J Surg Case Rep Case Report INTRODUCTION: Rapunzel syndrome is a rare intestinal condition that starts with the ingestion of a trichobezoar. The condition is predominately found in females and can be associated with trichotillomania, or the compulsive urge to pull one’s own hair out. There are less than 40 cases described in the literature with the prevention of recurrence aimed at psychological treatment. PRESENTATION OF CASE: The patient is a 7 year-old girl with a history of trichotillomania with trichophagia as a young child who presented with abdominal pain, nausea, and vomiting, consistent with a gastric outlet obstruction. She had an exploratory laparotomy with gastrostomy performed revealing a 18 cm by 18 cm trichobezoar with extension into the small bowel. DISCUSSION: Bezoars, an already rare entity, can occasionally lead to gastric and small bowel obstructions. Small collections of ingested hair build up in the intestinal tract causing significant symptoms. These obstructions can sometimes be treated through minimally invasive techniques but, in our case described, it is unlikely to have been treated any other way due to the substantial size of the trichobezoar. CONCLUSION: Early consideration of Rapunzel syndrome is important in young females presenting with a gastric outlet obstruction. Elsevier 2017-03-16 /pmc/articles/PMC5397571/ /pubmed/28431376 http://dx.doi.org/10.1016/j.ijscr.2017.03.011 Text en http://creativecommons.org/licenses/by-nc-nd/4.0/ This is an open access article under the CC BY-NC-ND license (http://creativecommons.org/licenses/by-nc-nd/4.0/). |
spellingShingle | Case Report Nwankwo, Eugene Daniele, Edward Woller, Erin Fitzwater, John McGill, Thomas Brooks, Steven E. Trichobezoar presenting as a gastric outlet obstruction: A case report |
title | Trichobezoar presenting as a gastric outlet obstruction: A case report |
title_full | Trichobezoar presenting as a gastric outlet obstruction: A case report |
title_fullStr | Trichobezoar presenting as a gastric outlet obstruction: A case report |
title_full_unstemmed | Trichobezoar presenting as a gastric outlet obstruction: A case report |
title_short | Trichobezoar presenting as a gastric outlet obstruction: A case report |
title_sort | trichobezoar presenting as a gastric outlet obstruction: a case report |
topic | Case Report |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5397571/ https://www.ncbi.nlm.nih.gov/pubmed/28431376 http://dx.doi.org/10.1016/j.ijscr.2017.03.011 |
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