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Novel compound heterozygous MYO7A mutations in Moroccan families with autosomal recessive non-syndromic hearing loss

The MYO7A gene encodes a protein belonging to the unconventional myosin super family. Mutations within MYO7A can lead to either non syndromic hearing loss or to the Usher syndrome type 1B (USH1B). Here, we report the results of genetic analyses performed on Moroccan families with autosomal recessive...

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Autores principales: Bakhchane, Amina, Charif, Majida, Bousfiha, Amale, Boulouiz, Redouane, Nahili, Halima, Rouba, Hassan, Charoute, Hicham, Lenaers, Guy, Barakat, Abdelhamid
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Public Library of Science 2017
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5417485/
https://www.ncbi.nlm.nih.gov/pubmed/28472130
http://dx.doi.org/10.1371/journal.pone.0176516
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author Bakhchane, Amina
Charif, Majida
Bousfiha, Amale
Boulouiz, Redouane
Nahili, Halima
Rouba, Hassan
Charoute, Hicham
Lenaers, Guy
Barakat, Abdelhamid
author_facet Bakhchane, Amina
Charif, Majida
Bousfiha, Amale
Boulouiz, Redouane
Nahili, Halima
Rouba, Hassan
Charoute, Hicham
Lenaers, Guy
Barakat, Abdelhamid
author_sort Bakhchane, Amina
collection PubMed
description The MYO7A gene encodes a protein belonging to the unconventional myosin super family. Mutations within MYO7A can lead to either non syndromic hearing loss or to the Usher syndrome type 1B (USH1B). Here, we report the results of genetic analyses performed on Moroccan families with autosomal recessive non syndromic hearing loss that identified two families with compound heterozygous MYO7A mutations. Five mutations (c.6025delG, c.6229T>A, c.3500T>A, c.5617C>T and c.4487C>A) were identified in these families, the latter presenting two differently affected branches. Multiple bioinformatics programs and molecular modelling predicted the pathogenic effect of these mutations. In conclusion, the absence of vestibular and retinal symptom in the affected patients suggests that these families have the isolated non-syndromic hearing loss DFNB2 (nonsyndromic autosomal recessive hearing loss) presentation, instead of USH1B.
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spelling pubmed-54174852017-05-14 Novel compound heterozygous MYO7A mutations in Moroccan families with autosomal recessive non-syndromic hearing loss Bakhchane, Amina Charif, Majida Bousfiha, Amale Boulouiz, Redouane Nahili, Halima Rouba, Hassan Charoute, Hicham Lenaers, Guy Barakat, Abdelhamid PLoS One Research Article The MYO7A gene encodes a protein belonging to the unconventional myosin super family. Mutations within MYO7A can lead to either non syndromic hearing loss or to the Usher syndrome type 1B (USH1B). Here, we report the results of genetic analyses performed on Moroccan families with autosomal recessive non syndromic hearing loss that identified two families with compound heterozygous MYO7A mutations. Five mutations (c.6025delG, c.6229T>A, c.3500T>A, c.5617C>T and c.4487C>A) were identified in these families, the latter presenting two differently affected branches. Multiple bioinformatics programs and molecular modelling predicted the pathogenic effect of these mutations. In conclusion, the absence of vestibular and retinal symptom in the affected patients suggests that these families have the isolated non-syndromic hearing loss DFNB2 (nonsyndromic autosomal recessive hearing loss) presentation, instead of USH1B. Public Library of Science 2017-05-04 /pmc/articles/PMC5417485/ /pubmed/28472130 http://dx.doi.org/10.1371/journal.pone.0176516 Text en © 2017 Bakhchane et al http://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/4.0/) , which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited.
spellingShingle Research Article
Bakhchane, Amina
Charif, Majida
Bousfiha, Amale
Boulouiz, Redouane
Nahili, Halima
Rouba, Hassan
Charoute, Hicham
Lenaers, Guy
Barakat, Abdelhamid
Novel compound heterozygous MYO7A mutations in Moroccan families with autosomal recessive non-syndromic hearing loss
title Novel compound heterozygous MYO7A mutations in Moroccan families with autosomal recessive non-syndromic hearing loss
title_full Novel compound heterozygous MYO7A mutations in Moroccan families with autosomal recessive non-syndromic hearing loss
title_fullStr Novel compound heterozygous MYO7A mutations in Moroccan families with autosomal recessive non-syndromic hearing loss
title_full_unstemmed Novel compound heterozygous MYO7A mutations in Moroccan families with autosomal recessive non-syndromic hearing loss
title_short Novel compound heterozygous MYO7A mutations in Moroccan families with autosomal recessive non-syndromic hearing loss
title_sort novel compound heterozygous myo7a mutations in moroccan families with autosomal recessive non-syndromic hearing loss
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5417485/
https://www.ncbi.nlm.nih.gov/pubmed/28472130
http://dx.doi.org/10.1371/journal.pone.0176516
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