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Congenital Cyst Adenoid Malformation Masquerading as Bronchial Asthma

Congenital cyst adenoid malformation (CCAM) is a rare congenital malformation occurring in approximately 1–4 in 100,000 births. It is classified into five subtypes with type 1 CCAM is most common subtype. The diagnosis of CCAM is usually made in infancy, and it is rare in adolescents and adults. We...

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Autores principales: Goyal, Jagdish Prasad, Jindal, Shishir, Mishra, Mayank, Bhakhri, Bhanu Kiran
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Medknow Publications & Media Pvt Ltd 2017
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5590386/
https://www.ncbi.nlm.nih.gov/pubmed/28904923
http://dx.doi.org/10.4103/ijabmr.IJABMR_216_16
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author Goyal, Jagdish Prasad
Jindal, Shishir
Mishra, Mayank
Bhakhri, Bhanu Kiran
author_facet Goyal, Jagdish Prasad
Jindal, Shishir
Mishra, Mayank
Bhakhri, Bhanu Kiran
author_sort Goyal, Jagdish Prasad
collection PubMed
description Congenital cyst adenoid malformation (CCAM) is a rare congenital malformation occurring in approximately 1–4 in 100,000 births. It is classified into five subtypes with type 1 CCAM is most common subtype. The diagnosis of CCAM is usually made in infancy, and it is rare in adolescents and adults. We report a 15-year-old female, who presented in pediatric outpatient department with a history of recurrent cough since infancy. On the basis of clinical examination, provisional diagnosis of asthma was considered and patient was started on inhaled corticosteroid and long-term β2 agonist. Lung function of the patient revealed low forced expiratory volume-1 s but without bronchodilator reversibility. Therefore, alternative diagnosis was suspected, and the patient was further evaluated with X-ray chest and high resolution computed tomography thorax. Based on radiological findings, a final diagnosis of CCAM was established. The case was highly unusual due to its atypical and late age of presentation. Acquaintance about this condition benefit clinician in making differential diagnosis of recurrent cough.
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spelling pubmed-55903862017-09-13 Congenital Cyst Adenoid Malformation Masquerading as Bronchial Asthma Goyal, Jagdish Prasad Jindal, Shishir Mishra, Mayank Bhakhri, Bhanu Kiran Int J Appl Basic Med Res Case Report Congenital cyst adenoid malformation (CCAM) is a rare congenital malformation occurring in approximately 1–4 in 100,000 births. It is classified into five subtypes with type 1 CCAM is most common subtype. The diagnosis of CCAM is usually made in infancy, and it is rare in adolescents and adults. We report a 15-year-old female, who presented in pediatric outpatient department with a history of recurrent cough since infancy. On the basis of clinical examination, provisional diagnosis of asthma was considered and patient was started on inhaled corticosteroid and long-term β2 agonist. Lung function of the patient revealed low forced expiratory volume-1 s but without bronchodilator reversibility. Therefore, alternative diagnosis was suspected, and the patient was further evaluated with X-ray chest and high resolution computed tomography thorax. Based on radiological findings, a final diagnosis of CCAM was established. The case was highly unusual due to its atypical and late age of presentation. Acquaintance about this condition benefit clinician in making differential diagnosis of recurrent cough. Medknow Publications & Media Pvt Ltd 2017 /pmc/articles/PMC5590386/ /pubmed/28904923 http://dx.doi.org/10.4103/ijabmr.IJABMR_216_16 Text en Copyright: © 2017 International Journal of Applied and Basic Medical Research http://creativecommons.org/licenses/by-nc-sa/3.0 This is an open access article distributed under the terms of the Creative Commons Attribution-NonCommercial-ShareAlike 3.0 License, which allows others to remix, tweak, and build upon the work non-commercially, as long as the author is credited and the new creations are licensed under the identical terms.
spellingShingle Case Report
Goyal, Jagdish Prasad
Jindal, Shishir
Mishra, Mayank
Bhakhri, Bhanu Kiran
Congenital Cyst Adenoid Malformation Masquerading as Bronchial Asthma
title Congenital Cyst Adenoid Malformation Masquerading as Bronchial Asthma
title_full Congenital Cyst Adenoid Malformation Masquerading as Bronchial Asthma
title_fullStr Congenital Cyst Adenoid Malformation Masquerading as Bronchial Asthma
title_full_unstemmed Congenital Cyst Adenoid Malformation Masquerading as Bronchial Asthma
title_short Congenital Cyst Adenoid Malformation Masquerading as Bronchial Asthma
title_sort congenital cyst adenoid malformation masquerading as bronchial asthma
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5590386/
https://www.ncbi.nlm.nih.gov/pubmed/28904923
http://dx.doi.org/10.4103/ijabmr.IJABMR_216_16
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