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The Genetic Spectrum of Familial Hypercholesterolemia (FH) in the Iranian Population

Familial hypercholesterolemia (FH) is an autosomal dominant disorder associated with premature cardiovascular disease (CVD). Mutations in the LDLR, APOB, and PCSK9 genes are known to cause FH. In this study, we analysed the genetic spectrum of the disease in subjects from the Iranian population with...

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Autores principales: Fairoozy, R. H., Futema, M., Vakili, R., Abbaszadegan, M. R., Hosseini, S., Aminzadeh, M., Zaeri, H., Mobini, M., Humphries, S. E., Sahebkar, A.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Nature Publishing Group UK 2017
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5719081/
https://www.ncbi.nlm.nih.gov/pubmed/29213121
http://dx.doi.org/10.1038/s41598-017-17181-9
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author Fairoozy, R. H.
Futema, M.
Vakili, R.
Abbaszadegan, M. R.
Hosseini, S.
Aminzadeh, M.
Zaeri, H.
Mobini, M.
Humphries, S. E.
Sahebkar, A.
author_facet Fairoozy, R. H.
Futema, M.
Vakili, R.
Abbaszadegan, M. R.
Hosseini, S.
Aminzadeh, M.
Zaeri, H.
Mobini, M.
Humphries, S. E.
Sahebkar, A.
author_sort Fairoozy, R. H.
collection PubMed
description Familial hypercholesterolemia (FH) is an autosomal dominant disorder associated with premature cardiovascular disease (CVD). Mutations in the LDLR, APOB, and PCSK9 genes are known to cause FH. In this study, we analysed the genetic spectrum of the disease in subjects from the Iranian population with a clinical diagnosis of FH. Samples were collected from 16 children and family members from five different cities of Iran. Probands were screened for mutations in the LDLR, APOB, and PCSK9 genes using next generation sequencing, with results confirmed by Sanger sequencing. The likely pathology of identified variants was examined using in silico tools. Of the probands, 14 had a clinical diagnosis of homozygous FH and two of heterozygous FH. No mutations were found in either APOB or PCSK9, but nine probands were homozygous for seven different LDLR mutations, with p.(Trp577Arg) occurring in three and p.Val806Glyfs*11 occurring in two patients. Two mutations were novel: p.(Leu479Gln) and p.(Glu668*). Seven probands with a clinical diagnosis of FH were mutation negative. This pilot study, integrating clinical and molecular-based techniques, begins to elucidate the FH heterogeneity and the mutation spectrum in the Iranian population. Such information is important for future disease management and cost savings.
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spelling pubmed-57190812017-12-08 The Genetic Spectrum of Familial Hypercholesterolemia (FH) in the Iranian Population Fairoozy, R. H. Futema, M. Vakili, R. Abbaszadegan, M. R. Hosseini, S. Aminzadeh, M. Zaeri, H. Mobini, M. Humphries, S. E. Sahebkar, A. Sci Rep Article Familial hypercholesterolemia (FH) is an autosomal dominant disorder associated with premature cardiovascular disease (CVD). Mutations in the LDLR, APOB, and PCSK9 genes are known to cause FH. In this study, we analysed the genetic spectrum of the disease in subjects from the Iranian population with a clinical diagnosis of FH. Samples were collected from 16 children and family members from five different cities of Iran. Probands were screened for mutations in the LDLR, APOB, and PCSK9 genes using next generation sequencing, with results confirmed by Sanger sequencing. The likely pathology of identified variants was examined using in silico tools. Of the probands, 14 had a clinical diagnosis of homozygous FH and two of heterozygous FH. No mutations were found in either APOB or PCSK9, but nine probands were homozygous for seven different LDLR mutations, with p.(Trp577Arg) occurring in three and p.Val806Glyfs*11 occurring in two patients. Two mutations were novel: p.(Leu479Gln) and p.(Glu668*). Seven probands with a clinical diagnosis of FH were mutation negative. This pilot study, integrating clinical and molecular-based techniques, begins to elucidate the FH heterogeneity and the mutation spectrum in the Iranian population. Such information is important for future disease management and cost savings. Nature Publishing Group UK 2017-12-06 /pmc/articles/PMC5719081/ /pubmed/29213121 http://dx.doi.org/10.1038/s41598-017-17181-9 Text en © The Author(s) 2017 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/.
spellingShingle Article
Fairoozy, R. H.
Futema, M.
Vakili, R.
Abbaszadegan, M. R.
Hosseini, S.
Aminzadeh, M.
Zaeri, H.
Mobini, M.
Humphries, S. E.
Sahebkar, A.
The Genetic Spectrum of Familial Hypercholesterolemia (FH) in the Iranian Population
title The Genetic Spectrum of Familial Hypercholesterolemia (FH) in the Iranian Population
title_full The Genetic Spectrum of Familial Hypercholesterolemia (FH) in the Iranian Population
title_fullStr The Genetic Spectrum of Familial Hypercholesterolemia (FH) in the Iranian Population
title_full_unstemmed The Genetic Spectrum of Familial Hypercholesterolemia (FH) in the Iranian Population
title_short The Genetic Spectrum of Familial Hypercholesterolemia (FH) in the Iranian Population
title_sort genetic spectrum of familial hypercholesterolemia (fh) in the iranian population
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5719081/
https://www.ncbi.nlm.nih.gov/pubmed/29213121
http://dx.doi.org/10.1038/s41598-017-17181-9
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