Cargando…

Congenital Langerhans cell histiocytosis: a good prognosis disease?

Langerhans cell histiocytosis is rare and more frequent in children. The skin is affected in 50% of the cases and is the only site in 10%. Its course varies from self-limited and localized forms to severe multisystemic forms. Congenital cases are usually exclusively cutaneous and self-limited, with...

Descripción completa

Detalles Bibliográficos
Autores principales: Frade, Ana Paula, Godinho, Mariana Marteleto, Batalha, Anna Beatriz Willemes, Bueno, Ana Paula Silva
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Sociedade Brasileira de Dermatologia 2017
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5726673/
https://www.ncbi.nlm.nih.gov/pubmed/29267442
http://dx.doi.org/10.1590/abd1806-4841.20175308
_version_ 1783285739411210240
author Frade, Ana Paula
Godinho, Mariana Marteleto
Batalha, Anna Beatriz Willemes
Bueno, Ana Paula Silva
author_facet Frade, Ana Paula
Godinho, Mariana Marteleto
Batalha, Anna Beatriz Willemes
Bueno, Ana Paula Silva
author_sort Frade, Ana Paula
collection PubMed
description Langerhans cell histiocytosis is rare and more frequent in children. The skin is affected in 50% of the cases and is the only site in 10%. Its course varies from self-limited and localized forms to severe multisystemic forms. Congenital cases are usually exclusively cutaneous and self-limited, with spontaneous remission in months. This study presents a rare congenital case, initially restricted to the skin, with subsequent dissemination and fatal outcome. A male newborn presented congenital disseminated erythematous scaly lesions. The biopsy was conclusive for Langerhans cell histiocytosis. The patient evolved into the multisystemic form in weeks, when chemotherapy was started, according to the LCH-2009 protocol; however, the patient was refractory to treatment and died.
format Online
Article
Text
id pubmed-5726673
institution National Center for Biotechnology Information
language English
publishDate 2017
publisher Sociedade Brasileira de Dermatologia
record_format MEDLINE/PubMed
spelling pubmed-57266732017-12-18 Congenital Langerhans cell histiocytosis: a good prognosis disease? Frade, Ana Paula Godinho, Mariana Marteleto Batalha, Anna Beatriz Willemes Bueno, Ana Paula Silva An Bras Dermatol Case Report Langerhans cell histiocytosis is rare and more frequent in children. The skin is affected in 50% of the cases and is the only site in 10%. Its course varies from self-limited and localized forms to severe multisystemic forms. Congenital cases are usually exclusively cutaneous and self-limited, with spontaneous remission in months. This study presents a rare congenital case, initially restricted to the skin, with subsequent dissemination and fatal outcome. A male newborn presented congenital disseminated erythematous scaly lesions. The biopsy was conclusive for Langerhans cell histiocytosis. The patient evolved into the multisystemic form in weeks, when chemotherapy was started, according to the LCH-2009 protocol; however, the patient was refractory to treatment and died. Sociedade Brasileira de Dermatologia 2017 /pmc/articles/PMC5726673/ /pubmed/29267442 http://dx.doi.org/10.1590/abd1806-4841.20175308 Text en ©2017 by Anais Brasileiros de Dermatologia http://creativecommons.org/licenses/by-nc/4.0/ This is an Open Access article distributed under the terms of the Creative Commons Attribution Non-Commercial License which permits unrestricted non-commercial use, distribution, and reproduction in any medium provided the original work is properly cited.
spellingShingle Case Report
Frade, Ana Paula
Godinho, Mariana Marteleto
Batalha, Anna Beatriz Willemes
Bueno, Ana Paula Silva
Congenital Langerhans cell histiocytosis: a good prognosis disease?
title Congenital Langerhans cell histiocytosis: a good prognosis disease?
title_full Congenital Langerhans cell histiocytosis: a good prognosis disease?
title_fullStr Congenital Langerhans cell histiocytosis: a good prognosis disease?
title_full_unstemmed Congenital Langerhans cell histiocytosis: a good prognosis disease?
title_short Congenital Langerhans cell histiocytosis: a good prognosis disease?
title_sort congenital langerhans cell histiocytosis: a good prognosis disease?
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5726673/
https://www.ncbi.nlm.nih.gov/pubmed/29267442
http://dx.doi.org/10.1590/abd1806-4841.20175308
work_keys_str_mv AT fradeanapaula congenitallangerhanscellhistiocytosisagoodprognosisdisease
AT godinhomarianamarteleto congenitallangerhanscellhistiocytosisagoodprognosisdisease
AT batalhaannabeatrizwillemes congenitallangerhanscellhistiocytosisagoodprognosisdisease
AT buenoanapaulasilva congenitallangerhanscellhistiocytosisagoodprognosisdisease