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Short telomere length in IPF lung associates with fibrotic lesions and predicts survival

Telomere maintenance dysfunction has been implicated in the pathogenesis of Idiopathic Pulmonary Fibrosis (IPF). However, the mechanism of how telomere length is related to fibrosis in the lungs is unknown. Surgical lung biopsies of IPF patients typically show a heterogeneous pattern of non-fibrotic...

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Autores principales: Snetselaar, Reinier, van Batenburg, Aernoud A., van Oosterhout, Matthijs F. M., Kazemier, Karin M., Roothaan, Suzan M., Peeters, Ton, van der Vis, Joanne J., Goldschmeding, Roel, Grutters, Jan C., van Moorsel, Coline H. M.
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Public Library of Science 2017
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5744955/
https://www.ncbi.nlm.nih.gov/pubmed/29281671
http://dx.doi.org/10.1371/journal.pone.0189467
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author Snetselaar, Reinier
van Batenburg, Aernoud A.
van Oosterhout, Matthijs F. M.
Kazemier, Karin M.
Roothaan, Suzan M.
Peeters, Ton
van der Vis, Joanne J.
Goldschmeding, Roel
Grutters, Jan C.
van Moorsel, Coline H. M.
author_facet Snetselaar, Reinier
van Batenburg, Aernoud A.
van Oosterhout, Matthijs F. M.
Kazemier, Karin M.
Roothaan, Suzan M.
Peeters, Ton
van der Vis, Joanne J.
Goldschmeding, Roel
Grutters, Jan C.
van Moorsel, Coline H. M.
author_sort Snetselaar, Reinier
collection PubMed
description Telomere maintenance dysfunction has been implicated in the pathogenesis of Idiopathic Pulmonary Fibrosis (IPF). However, the mechanism of how telomere length is related to fibrosis in the lungs is unknown. Surgical lung biopsies of IPF patients typically show a heterogeneous pattern of non-fibrotic and fibrotic areas. Therefore, telomere length (TL) in both lung areas of patients with IPF and familial interstitial pneumonia was compared, specifically in alveolar type 2 (AT2) cells. Fluorescent in situ hybridization was used to determine TL in non-fibrotic and fibrotic areas of 35 subjects. Monochrome multiplex quantitative polymerase chain reaction (MMqPCR) was used for 51 whole lung biopsies and blood TL measurements. For sporadic IPF subjects, AT2 cell TL in non-fibrotic areas was 56% longer than in fibrotic areas. No such difference was observed in the surrounding lung cells. In subjects carrying a telomerase reverse transcriptase (TERT) mutation, AT2 cell TL was significantly shorter than in sporadic subjects. However, no difference in surrounding cell TL was observed between these subject groups. Finally, using biopsy MMqPCR TL measurements, it was determined that IPF subjects with shortest lung TL had a significantly worse survival than patients with long TL. This study shows that shortening of telomeres critically affects AT2 cells in fibrotic areas, implying TL as a cause of fibrogenesis. Furthermore, short lung telomere length is associated with decreased survival.
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spelling pubmed-57449552018-01-09 Short telomere length in IPF lung associates with fibrotic lesions and predicts survival Snetselaar, Reinier van Batenburg, Aernoud A. van Oosterhout, Matthijs F. M. Kazemier, Karin M. Roothaan, Suzan M. Peeters, Ton van der Vis, Joanne J. Goldschmeding, Roel Grutters, Jan C. van Moorsel, Coline H. M. PLoS One Research Article Telomere maintenance dysfunction has been implicated in the pathogenesis of Idiopathic Pulmonary Fibrosis (IPF). However, the mechanism of how telomere length is related to fibrosis in the lungs is unknown. Surgical lung biopsies of IPF patients typically show a heterogeneous pattern of non-fibrotic and fibrotic areas. Therefore, telomere length (TL) in both lung areas of patients with IPF and familial interstitial pneumonia was compared, specifically in alveolar type 2 (AT2) cells. Fluorescent in situ hybridization was used to determine TL in non-fibrotic and fibrotic areas of 35 subjects. Monochrome multiplex quantitative polymerase chain reaction (MMqPCR) was used for 51 whole lung biopsies and blood TL measurements. For sporadic IPF subjects, AT2 cell TL in non-fibrotic areas was 56% longer than in fibrotic areas. No such difference was observed in the surrounding lung cells. In subjects carrying a telomerase reverse transcriptase (TERT) mutation, AT2 cell TL was significantly shorter than in sporadic subjects. However, no difference in surrounding cell TL was observed between these subject groups. Finally, using biopsy MMqPCR TL measurements, it was determined that IPF subjects with shortest lung TL had a significantly worse survival than patients with long TL. This study shows that shortening of telomeres critically affects AT2 cells in fibrotic areas, implying TL as a cause of fibrogenesis. Furthermore, short lung telomere length is associated with decreased survival. Public Library of Science 2017-12-27 /pmc/articles/PMC5744955/ /pubmed/29281671 http://dx.doi.org/10.1371/journal.pone.0189467 Text en © 2017 Snetselaar et al http://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/4.0/) , which permits unrestricted use, distribution, and reproduction in any medium, provided the original author and source are credited.
spellingShingle Research Article
Snetselaar, Reinier
van Batenburg, Aernoud A.
van Oosterhout, Matthijs F. M.
Kazemier, Karin M.
Roothaan, Suzan M.
Peeters, Ton
van der Vis, Joanne J.
Goldschmeding, Roel
Grutters, Jan C.
van Moorsel, Coline H. M.
Short telomere length in IPF lung associates with fibrotic lesions and predicts survival
title Short telomere length in IPF lung associates with fibrotic lesions and predicts survival
title_full Short telomere length in IPF lung associates with fibrotic lesions and predicts survival
title_fullStr Short telomere length in IPF lung associates with fibrotic lesions and predicts survival
title_full_unstemmed Short telomere length in IPF lung associates with fibrotic lesions and predicts survival
title_short Short telomere length in IPF lung associates with fibrotic lesions and predicts survival
title_sort short telomere length in ipf lung associates with fibrotic lesions and predicts survival
topic Research Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5744955/
https://www.ncbi.nlm.nih.gov/pubmed/29281671
http://dx.doi.org/10.1371/journal.pone.0189467
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