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A “blind” vascular ring in association with congenital cystic adenomatoid malformation: A case report
RATIONALE: The occurrence of congenital cystic adenomatoid malformation (CCAM) and vascular ring (VR) is extremely rare. PATIENT CONCERNS: We present a case of left CCAM with VR consisting of a left aortic arch and right descending aorta with left tracheal compression causing atelectasis. DIAGNOSES:...
Autores principales: | , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Wolters Kluwer Health
2017
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5758127/ https://www.ncbi.nlm.nih.gov/pubmed/29390425 http://dx.doi.org/10.1097/MD.0000000000008915 |
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author | Xia, Bo Hong, Chun Tang, Jing Liu, Cuifen Yu, Gang |
author_facet | Xia, Bo Hong, Chun Tang, Jing Liu, Cuifen Yu, Gang |
author_sort | Xia, Bo |
collection | PubMed |
description | RATIONALE: The occurrence of congenital cystic adenomatoid malformation (CCAM) and vascular ring (VR) is extremely rare. PATIENT CONCERNS: We present a case of left CCAM with VR consisting of a left aortic arch and right descending aorta with left tracheal compression causing atelectasis. DIAGNOSES: A high-risk male neonate with the diagnosis of left CCAM was diagnosed at 20 weeks gestational age by antenatal ultrasound. Chest CT revealed multiple cysts in the left inferior lung. Cardiac CT showed VR consisting of a left aortic arch and right descending aorta with left tracheal compression causing atelectasis. INTERVENTIONS: left inferior lobectomy was performed. Cardiac CT showed VR consisting of a left aortic arch and right descending aorta with left tracheal compression causing atelectasis. Descending aorta transposition was performed. OUTCOMES: The patient recovered smoothly and remained asymptomatic during the 12-months of postoperative follow-up period. LESSONS: We report this rare case of CCAM with VR consisting of left aortic arch and right descending aorta with left tracheal compression causing atelectasis. From the findings of this report, early surgical treatment is recommended. Although the prognosis after surgery remained good, second surgery can be avoided if VR was detected early. |
format | Online Article Text |
id | pubmed-5758127 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2017 |
publisher | Wolters Kluwer Health |
record_format | MEDLINE/PubMed |
spelling | pubmed-57581272018-01-29 A “blind” vascular ring in association with congenital cystic adenomatoid malformation: A case report Xia, Bo Hong, Chun Tang, Jing Liu, Cuifen Yu, Gang Medicine (Baltimore) 6700 RATIONALE: The occurrence of congenital cystic adenomatoid malformation (CCAM) and vascular ring (VR) is extremely rare. PATIENT CONCERNS: We present a case of left CCAM with VR consisting of a left aortic arch and right descending aorta with left tracheal compression causing atelectasis. DIAGNOSES: A high-risk male neonate with the diagnosis of left CCAM was diagnosed at 20 weeks gestational age by antenatal ultrasound. Chest CT revealed multiple cysts in the left inferior lung. Cardiac CT showed VR consisting of a left aortic arch and right descending aorta with left tracheal compression causing atelectasis. INTERVENTIONS: left inferior lobectomy was performed. Cardiac CT showed VR consisting of a left aortic arch and right descending aorta with left tracheal compression causing atelectasis. Descending aorta transposition was performed. OUTCOMES: The patient recovered smoothly and remained asymptomatic during the 12-months of postoperative follow-up period. LESSONS: We report this rare case of CCAM with VR consisting of left aortic arch and right descending aorta with left tracheal compression causing atelectasis. From the findings of this report, early surgical treatment is recommended. Although the prognosis after surgery remained good, second surgery can be avoided if VR was detected early. Wolters Kluwer Health 2017-12-22 /pmc/articles/PMC5758127/ /pubmed/29390425 http://dx.doi.org/10.1097/MD.0000000000008915 Text en Copyright © 2017 the Author(s). Published by Wolters Kluwer Health, Inc. http://creativecommons.org/licenses/by-nc-sa/4.0 This is an open access article distributed under the terms of the Creative Commons Attribution-NonCommercial-ShareAlike 4.0 License, which allows others to remix, tweak, and build upon the work non-commercially, as long as the author is credited and the new creations are licensed under the identical terms. http://creativecommons.org/licenses/by-nc-sa/4.0 |
spellingShingle | 6700 Xia, Bo Hong, Chun Tang, Jing Liu, Cuifen Yu, Gang A “blind” vascular ring in association with congenital cystic adenomatoid malformation: A case report |
title | A “blind” vascular ring in association with congenital cystic adenomatoid malformation: A case report |
title_full | A “blind” vascular ring in association with congenital cystic adenomatoid malformation: A case report |
title_fullStr | A “blind” vascular ring in association with congenital cystic adenomatoid malformation: A case report |
title_full_unstemmed | A “blind” vascular ring in association with congenital cystic adenomatoid malformation: A case report |
title_short | A “blind” vascular ring in association with congenital cystic adenomatoid malformation: A case report |
title_sort | “blind” vascular ring in association with congenital cystic adenomatoid malformation: a case report |
topic | 6700 |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5758127/ https://www.ncbi.nlm.nih.gov/pubmed/29390425 http://dx.doi.org/10.1097/MD.0000000000008915 |
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