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Iron modulation of erythropoiesis is associated with Scribble-mediated control of the erythropoietin receptor

Iron-restricted human anemias are associated with the acquisition of marrow resistance to the hematopoietic cytokine erythropoietin (Epo). Regulation of Epo responsiveness by iron availability serves as the basis for intravenous iron therapy in anemias of chronic disease. Epo engagement of its recep...

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Autores principales: Khalil, Shadi, Delehanty, Lorrie, Grado, Stephen, Holy, Maja, White, Zollie, Freeman, Katie, Kurita, Ryo, Nakamura, Yukio, Bullock, Grant, Goldfarb, Adam
Formato: Online Artículo Texto
Lenguaje:English
Publicado: The Rockefeller University Press 2018
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5789406/
https://www.ncbi.nlm.nih.gov/pubmed/29282252
http://dx.doi.org/10.1084/jem.20170396
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author Khalil, Shadi
Delehanty, Lorrie
Grado, Stephen
Holy, Maja
White, Zollie
Freeman, Katie
Kurita, Ryo
Nakamura, Yukio
Bullock, Grant
Goldfarb, Adam
author_facet Khalil, Shadi
Delehanty, Lorrie
Grado, Stephen
Holy, Maja
White, Zollie
Freeman, Katie
Kurita, Ryo
Nakamura, Yukio
Bullock, Grant
Goldfarb, Adam
author_sort Khalil, Shadi
collection PubMed
description Iron-restricted human anemias are associated with the acquisition of marrow resistance to the hematopoietic cytokine erythropoietin (Epo). Regulation of Epo responsiveness by iron availability serves as the basis for intravenous iron therapy in anemias of chronic disease. Epo engagement of its receptor normally promotes survival, proliferation, and differentiation of erythroid progenitors. However, Epo resistance caused by iron restriction selectively impairs proliferation and differentiation while preserving viability. Our results reveal that iron restriction limits surface display of Epo receptor in primary progenitors and that mice with enforced surface retention of the receptor fail to develop anemia with iron deprivation. A mechanistic pathway is identified in which erythroid iron restriction down-regulates a receptor control element, Scribble, through the mediation of the iron-sensing transferrin receptor 2. Scribble deficiency reduces surface expression of Epo receptor but selectively retains survival signaling via Akt. This mechanism integrates nutrient sensing with receptor function to permit modulation of progenitor expansion without compromising survival.
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spelling pubmed-57894062018-08-05 Iron modulation of erythropoiesis is associated with Scribble-mediated control of the erythropoietin receptor Khalil, Shadi Delehanty, Lorrie Grado, Stephen Holy, Maja White, Zollie Freeman, Katie Kurita, Ryo Nakamura, Yukio Bullock, Grant Goldfarb, Adam J Exp Med Research Articles Iron-restricted human anemias are associated with the acquisition of marrow resistance to the hematopoietic cytokine erythropoietin (Epo). Regulation of Epo responsiveness by iron availability serves as the basis for intravenous iron therapy in anemias of chronic disease. Epo engagement of its receptor normally promotes survival, proliferation, and differentiation of erythroid progenitors. However, Epo resistance caused by iron restriction selectively impairs proliferation and differentiation while preserving viability. Our results reveal that iron restriction limits surface display of Epo receptor in primary progenitors and that mice with enforced surface retention of the receptor fail to develop anemia with iron deprivation. A mechanistic pathway is identified in which erythroid iron restriction down-regulates a receptor control element, Scribble, through the mediation of the iron-sensing transferrin receptor 2. Scribble deficiency reduces surface expression of Epo receptor but selectively retains survival signaling via Akt. This mechanism integrates nutrient sensing with receptor function to permit modulation of progenitor expansion without compromising survival. The Rockefeller University Press 2018-02-05 /pmc/articles/PMC5789406/ /pubmed/29282252 http://dx.doi.org/10.1084/jem.20170396 Text en © 2018 Khalil et al. http://www.rupress.org/terms/https://creativecommons.org/licenses/by-nc-sa/4.0/This article is distributed under the terms of an Attribution–Noncommercial–Share Alike–No Mirror Sites license for the first six months after the publication date (see http://www.rupress.org/terms/). After six months it is available under a Creative Commons License (Attribution–Noncommercial–Share Alike 4.0 International license, as described at https://creativecommons.org/licenses/by-nc-sa/4.0/).
spellingShingle Research Articles
Khalil, Shadi
Delehanty, Lorrie
Grado, Stephen
Holy, Maja
White, Zollie
Freeman, Katie
Kurita, Ryo
Nakamura, Yukio
Bullock, Grant
Goldfarb, Adam
Iron modulation of erythropoiesis is associated with Scribble-mediated control of the erythropoietin receptor
title Iron modulation of erythropoiesis is associated with Scribble-mediated control of the erythropoietin receptor
title_full Iron modulation of erythropoiesis is associated with Scribble-mediated control of the erythropoietin receptor
title_fullStr Iron modulation of erythropoiesis is associated with Scribble-mediated control of the erythropoietin receptor
title_full_unstemmed Iron modulation of erythropoiesis is associated with Scribble-mediated control of the erythropoietin receptor
title_short Iron modulation of erythropoiesis is associated with Scribble-mediated control of the erythropoietin receptor
title_sort iron modulation of erythropoiesis is associated with scribble-mediated control of the erythropoietin receptor
topic Research Articles
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5789406/
https://www.ncbi.nlm.nih.gov/pubmed/29282252
http://dx.doi.org/10.1084/jem.20170396
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