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A Rare Case of Systemic AL Amyloidosis with Muscle Involvement: A Misleading Diagnosis

Muscle involvement in AL amyloidosis is a rare condition, and the diagnosis of amyloid myopathy is often delayed and underdiagnosed. Amyloid myopathy may be the initial manifestation and may precede the diagnosis of systemic AL amyloidosis. Here, we report the case of a 73-year-old man who was refer...

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Autores principales: Accardi, Fabrizio, Papa, Valentina, Capozzi, Anna Rita, Capello, Gian Luca, Verga, Laura, Mancini, Cristina, Martella, Eugenia, Costa, Roberta, Notarfranchi, Laura, Dalla Palma, Benedetta, Aversa, Franco, Pietrini, Vladimiro, Cenacchi, Giovanna, Giuliani, Nicola
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Hindawi 2018
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5831914/
https://www.ncbi.nlm.nih.gov/pubmed/29651353
http://dx.doi.org/10.1155/2018/9840405
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author Accardi, Fabrizio
Papa, Valentina
Capozzi, Anna Rita
Capello, Gian Luca
Verga, Laura
Mancini, Cristina
Martella, Eugenia
Costa, Roberta
Notarfranchi, Laura
Dalla Palma, Benedetta
Aversa, Franco
Pietrini, Vladimiro
Cenacchi, Giovanna
Giuliani, Nicola
author_facet Accardi, Fabrizio
Papa, Valentina
Capozzi, Anna Rita
Capello, Gian Luca
Verga, Laura
Mancini, Cristina
Martella, Eugenia
Costa, Roberta
Notarfranchi, Laura
Dalla Palma, Benedetta
Aversa, Franco
Pietrini, Vladimiro
Cenacchi, Giovanna
Giuliani, Nicola
author_sort Accardi, Fabrizio
collection PubMed
description Muscle involvement in AL amyloidosis is a rare condition, and the diagnosis of amyloid myopathy is often delayed and underdiagnosed. Amyloid myopathy may be the initial manifestation and may precede the diagnosis of systemic AL amyloidosis. Here, we report the case of a 73-year-old man who was referred to our center for a monoclonal gammopathy of undetermined significance (MGUS) diagnosed since 1999. He reported a progressive weakness of proximal muscles of the legs with onset six months previously. Muscle biopsy showed mild histopathology featuring alterations of nonspecific type with a mixed myopathic and neurogenic involvement, and the diagnostic turning point was the demonstration of characteristic green birefringence under cross-polarized light following Congo red staining of perimysial vessels. Transmission electron microscopy (TEM) confirmed amyloid fibrils around perimysial vessels associated with collagen fibrils. A stepwise approach to diagnosis and staging of this disorder is critical and involves confirmation of amyloid deposition, identification of the fibril type, assessment of underlying amyloidogenic disorder, and evaluation of the extent and severity of amyloidotic organ involvement.
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spelling pubmed-58319142018-04-12 A Rare Case of Systemic AL Amyloidosis with Muscle Involvement: A Misleading Diagnosis Accardi, Fabrizio Papa, Valentina Capozzi, Anna Rita Capello, Gian Luca Verga, Laura Mancini, Cristina Martella, Eugenia Costa, Roberta Notarfranchi, Laura Dalla Palma, Benedetta Aversa, Franco Pietrini, Vladimiro Cenacchi, Giovanna Giuliani, Nicola Case Rep Hematol Case Report Muscle involvement in AL amyloidosis is a rare condition, and the diagnosis of amyloid myopathy is often delayed and underdiagnosed. Amyloid myopathy may be the initial manifestation and may precede the diagnosis of systemic AL amyloidosis. Here, we report the case of a 73-year-old man who was referred to our center for a monoclonal gammopathy of undetermined significance (MGUS) diagnosed since 1999. He reported a progressive weakness of proximal muscles of the legs with onset six months previously. Muscle biopsy showed mild histopathology featuring alterations of nonspecific type with a mixed myopathic and neurogenic involvement, and the diagnostic turning point was the demonstration of characteristic green birefringence under cross-polarized light following Congo red staining of perimysial vessels. Transmission electron microscopy (TEM) confirmed amyloid fibrils around perimysial vessels associated with collagen fibrils. A stepwise approach to diagnosis and staging of this disorder is critical and involves confirmation of amyloid deposition, identification of the fibril type, assessment of underlying amyloidogenic disorder, and evaluation of the extent and severity of amyloidotic organ involvement. Hindawi 2018-01-31 /pmc/articles/PMC5831914/ /pubmed/29651353 http://dx.doi.org/10.1155/2018/9840405 Text en Copyright © 2018 Fabrizio Accardi et al. http://creativecommons.org/licenses/by/4.0/ This is an open access article distributed under the Creative Commons Attribution License, which permits unrestricted use, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Case Report
Accardi, Fabrizio
Papa, Valentina
Capozzi, Anna Rita
Capello, Gian Luca
Verga, Laura
Mancini, Cristina
Martella, Eugenia
Costa, Roberta
Notarfranchi, Laura
Dalla Palma, Benedetta
Aversa, Franco
Pietrini, Vladimiro
Cenacchi, Giovanna
Giuliani, Nicola
A Rare Case of Systemic AL Amyloidosis with Muscle Involvement: A Misleading Diagnosis
title A Rare Case of Systemic AL Amyloidosis with Muscle Involvement: A Misleading Diagnosis
title_full A Rare Case of Systemic AL Amyloidosis with Muscle Involvement: A Misleading Diagnosis
title_fullStr A Rare Case of Systemic AL Amyloidosis with Muscle Involvement: A Misleading Diagnosis
title_full_unstemmed A Rare Case of Systemic AL Amyloidosis with Muscle Involvement: A Misleading Diagnosis
title_short A Rare Case of Systemic AL Amyloidosis with Muscle Involvement: A Misleading Diagnosis
title_sort rare case of systemic al amyloidosis with muscle involvement: a misleading diagnosis
topic Case Report
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5831914/
https://www.ncbi.nlm.nih.gov/pubmed/29651353
http://dx.doi.org/10.1155/2018/9840405
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