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Monitoring clinical progression with mitochondrial disease biomarkers
Mitochondrial disorders are genetically determined metabolic diseases due to a biochemical deficiency of the respiratory chain. Given that multi-system involvement and disease progression are common features of mitochondrial disorders they carry substantial morbidity and mortality. Despite this, no...
Autores principales: | , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Oxford University Press
2017
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5841218/ https://www.ncbi.nlm.nih.gov/pubmed/28969370 http://dx.doi.org/10.1093/brain/awx168 |
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author | Steele, Hannah E Horvath, Rita Lyon, Jon J Chinnery, Patrick F |
author_facet | Steele, Hannah E Horvath, Rita Lyon, Jon J Chinnery, Patrick F |
author_sort | Steele, Hannah E |
collection | PubMed |
description | Mitochondrial disorders are genetically determined metabolic diseases due to a biochemical deficiency of the respiratory chain. Given that multi-system involvement and disease progression are common features of mitochondrial disorders they carry substantial morbidity and mortality. Despite this, no disease-modifying treatments exist with clear clinical benefits, and the current best management of mitochondrial disease is supportive. Several therapeutic strategies for mitochondrial disorders are now at a mature preclinical stage. Some are making the transition into early-phase patient trials, but the lack of validated biomarkers of disease progression presents a challenge when developing new therapies for patients. This update discusses current biomarkers of mitochondrial disease progression including metabolomics, circulating serum markers, exercise physiology, and both structural and functional imaging. We discuss the advantages and disadvantages of each approach, and consider emerging techniques with a potential role in trials of new therapies. |
format | Online Article Text |
id | pubmed-5841218 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2017 |
publisher | Oxford University Press |
record_format | MEDLINE/PubMed |
spelling | pubmed-58412182018-03-28 Monitoring clinical progression with mitochondrial disease biomarkers Steele, Hannah E Horvath, Rita Lyon, Jon J Chinnery, Patrick F Brain Updates Mitochondrial disorders are genetically determined metabolic diseases due to a biochemical deficiency of the respiratory chain. Given that multi-system involvement and disease progression are common features of mitochondrial disorders they carry substantial morbidity and mortality. Despite this, no disease-modifying treatments exist with clear clinical benefits, and the current best management of mitochondrial disease is supportive. Several therapeutic strategies for mitochondrial disorders are now at a mature preclinical stage. Some are making the transition into early-phase patient trials, but the lack of validated biomarkers of disease progression presents a challenge when developing new therapies for patients. This update discusses current biomarkers of mitochondrial disease progression including metabolomics, circulating serum markers, exercise physiology, and both structural and functional imaging. We discuss the advantages and disadvantages of each approach, and consider emerging techniques with a potential role in trials of new therapies. Oxford University Press 2017-10 2017-08-03 /pmc/articles/PMC5841218/ /pubmed/28969370 http://dx.doi.org/10.1093/brain/awx168 Text en © The Author (2017). Published by Oxford University Press on behalf of the Guarantors of Brain. http://creativecommons.org/licenses/by/4.0/ This is an Open Access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/4.0/), which permits unrestricted reuse, distribution, and reproduction in any medium, provided the original work is properly cited. |
spellingShingle | Updates Steele, Hannah E Horvath, Rita Lyon, Jon J Chinnery, Patrick F Monitoring clinical progression with mitochondrial disease biomarkers |
title | Monitoring clinical progression with mitochondrial disease biomarkers |
title_full | Monitoring clinical progression with mitochondrial disease biomarkers |
title_fullStr | Monitoring clinical progression with mitochondrial disease biomarkers |
title_full_unstemmed | Monitoring clinical progression with mitochondrial disease biomarkers |
title_short | Monitoring clinical progression with mitochondrial disease biomarkers |
title_sort | monitoring clinical progression with mitochondrial disease biomarkers |
topic | Updates |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5841218/ https://www.ncbi.nlm.nih.gov/pubmed/28969370 http://dx.doi.org/10.1093/brain/awx168 |
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