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Monitoring clinical progression with mitochondrial disease biomarkers

Mitochondrial disorders are genetically determined metabolic diseases due to a biochemical deficiency of the respiratory chain. Given that multi-system involvement and disease progression are common features of mitochondrial disorders they carry substantial morbidity and mortality. Despite this, no...

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Detalles Bibliográficos
Autores principales: Steele, Hannah E, Horvath, Rita, Lyon, Jon J, Chinnery, Patrick F
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Oxford University Press 2017
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5841218/
https://www.ncbi.nlm.nih.gov/pubmed/28969370
http://dx.doi.org/10.1093/brain/awx168
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author Steele, Hannah E
Horvath, Rita
Lyon, Jon J
Chinnery, Patrick F
author_facet Steele, Hannah E
Horvath, Rita
Lyon, Jon J
Chinnery, Patrick F
author_sort Steele, Hannah E
collection PubMed
description Mitochondrial disorders are genetically determined metabolic diseases due to a biochemical deficiency of the respiratory chain. Given that multi-system involvement and disease progression are common features of mitochondrial disorders they carry substantial morbidity and mortality. Despite this, no disease-modifying treatments exist with clear clinical benefits, and the current best management of mitochondrial disease is supportive. Several therapeutic strategies for mitochondrial disorders are now at a mature preclinical stage. Some are making the transition into early-phase patient trials, but the lack of validated biomarkers of disease progression presents a challenge when developing new therapies for patients. This update discusses current biomarkers of mitochondrial disease progression including metabolomics, circulating serum markers, exercise physiology, and both structural and functional imaging. We discuss the advantages and disadvantages of each approach, and consider emerging techniques with a potential role in trials of new therapies.
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spelling pubmed-58412182018-03-28 Monitoring clinical progression with mitochondrial disease biomarkers Steele, Hannah E Horvath, Rita Lyon, Jon J Chinnery, Patrick F Brain Updates Mitochondrial disorders are genetically determined metabolic diseases due to a biochemical deficiency of the respiratory chain. Given that multi-system involvement and disease progression are common features of mitochondrial disorders they carry substantial morbidity and mortality. Despite this, no disease-modifying treatments exist with clear clinical benefits, and the current best management of mitochondrial disease is supportive. Several therapeutic strategies for mitochondrial disorders are now at a mature preclinical stage. Some are making the transition into early-phase patient trials, but the lack of validated biomarkers of disease progression presents a challenge when developing new therapies for patients. This update discusses current biomarkers of mitochondrial disease progression including metabolomics, circulating serum markers, exercise physiology, and both structural and functional imaging. We discuss the advantages and disadvantages of each approach, and consider emerging techniques with a potential role in trials of new therapies. Oxford University Press 2017-10 2017-08-03 /pmc/articles/PMC5841218/ /pubmed/28969370 http://dx.doi.org/10.1093/brain/awx168 Text en © The Author (2017). Published by Oxford University Press on behalf of the Guarantors of Brain. http://creativecommons.org/licenses/by/4.0/ This is an Open Access article distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/4.0/), which permits unrestricted reuse, distribution, and reproduction in any medium, provided the original work is properly cited.
spellingShingle Updates
Steele, Hannah E
Horvath, Rita
Lyon, Jon J
Chinnery, Patrick F
Monitoring clinical progression with mitochondrial disease biomarkers
title Monitoring clinical progression with mitochondrial disease biomarkers
title_full Monitoring clinical progression with mitochondrial disease biomarkers
title_fullStr Monitoring clinical progression with mitochondrial disease biomarkers
title_full_unstemmed Monitoring clinical progression with mitochondrial disease biomarkers
title_short Monitoring clinical progression with mitochondrial disease biomarkers
title_sort monitoring clinical progression with mitochondrial disease biomarkers
topic Updates
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5841218/
https://www.ncbi.nlm.nih.gov/pubmed/28969370
http://dx.doi.org/10.1093/brain/awx168
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