Cargando…

Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population

The incidence of inborn errors of metabolisms (IEMs) varies dramatically in different countries and regions. Expanded newborn screening for IEMs by tandem mass spectrometry (MS/MS) is an efficient approach for early diagnosis and presymptomatic treatment to prevent severe permanent sequelae and deat...

Descripción completa

Detalles Bibliográficos
Autores principales: Guo, Kejian, Zhou, Xuan, Chen, Xigui, Wu, Yili, Liu, Chuanxin, Kong, Qingsheng
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Frontiers Media S.A. 2018
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5920142/
https://www.ncbi.nlm.nih.gov/pubmed/29731766
http://dx.doi.org/10.3389/fgene.2018.00122
_version_ 1783317775128723456
author Guo, Kejian
Zhou, Xuan
Chen, Xigui
Wu, Yili
Liu, Chuanxin
Kong, Qingsheng
author_facet Guo, Kejian
Zhou, Xuan
Chen, Xigui
Wu, Yili
Liu, Chuanxin
Kong, Qingsheng
author_sort Guo, Kejian
collection PubMed
description The incidence of inborn errors of metabolisms (IEMs) varies dramatically in different countries and regions. Expanded newborn screening for IEMs by tandem mass spectrometry (MS/MS) is an efficient approach for early diagnosis and presymptomatic treatment to prevent severe permanent sequelae and death. To determine the characteristics of IEMs and IEMs-associated mutations in newborns in Jining area, China, 48,297 healthy neonates were recruited for expanded newborn screening by MS/MS. The incidence of IEMs was 1/1178 in Jining, while methylmalonic acidemia, phenylketonuria, and primary carnitine deficiency ranked the top 3 of all detected IEMs. Thirty mutations in nine IEMs-associated genes were identified in 28 confirmed cases. As 19 cases with the mutations in phenylalanine hydroxylase (PAH), solute carrier family 22 member 5 (SLC22A5), and methylmalonic aciduria (cobalamin deficiency) cblC type with homocystinuria (MMACHC) genes, respectively, it suggested that mutations in the PAH, SLC22A5, and MMACHC genes are the predominant causes of IEMs, leading to the high incidence of phenylketonuria, primary carnitine deficiency, and methylmalonic acidemia, respectively. Our work indicated that the overall incidence of IEMs is high and the mutations in PAH, SLC22A5, and MMACHC genes are the leading causes of IEMs in Jining area. Therefore, it is critical to increase the coverage of expanded newborn screening by MS/MS and prenatal genetic consulting in Jining area.
format Online
Article
Text
id pubmed-5920142
institution National Center for Biotechnology Information
language English
publishDate 2018
publisher Frontiers Media S.A.
record_format MEDLINE/PubMed
spelling pubmed-59201422018-05-04 Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population Guo, Kejian Zhou, Xuan Chen, Xigui Wu, Yili Liu, Chuanxin Kong, Qingsheng Front Genet Genetics The incidence of inborn errors of metabolisms (IEMs) varies dramatically in different countries and regions. Expanded newborn screening for IEMs by tandem mass spectrometry (MS/MS) is an efficient approach for early diagnosis and presymptomatic treatment to prevent severe permanent sequelae and death. To determine the characteristics of IEMs and IEMs-associated mutations in newborns in Jining area, China, 48,297 healthy neonates were recruited for expanded newborn screening by MS/MS. The incidence of IEMs was 1/1178 in Jining, while methylmalonic acidemia, phenylketonuria, and primary carnitine deficiency ranked the top 3 of all detected IEMs. Thirty mutations in nine IEMs-associated genes were identified in 28 confirmed cases. As 19 cases with the mutations in phenylalanine hydroxylase (PAH), solute carrier family 22 member 5 (SLC22A5), and methylmalonic aciduria (cobalamin deficiency) cblC type with homocystinuria (MMACHC) genes, respectively, it suggested that mutations in the PAH, SLC22A5, and MMACHC genes are the predominant causes of IEMs, leading to the high incidence of phenylketonuria, primary carnitine deficiency, and methylmalonic acidemia, respectively. Our work indicated that the overall incidence of IEMs is high and the mutations in PAH, SLC22A5, and MMACHC genes are the leading causes of IEMs in Jining area. Therefore, it is critical to increase the coverage of expanded newborn screening by MS/MS and prenatal genetic consulting in Jining area. Frontiers Media S.A. 2018-04-20 /pmc/articles/PMC5920142/ /pubmed/29731766 http://dx.doi.org/10.3389/fgene.2018.00122 Text en Copyright © 2018 Guo, Zhou, Chen, Wu, Liu and Kong. http://creativecommons.org/licenses/by/4.0/ This is an open-access article distributed under the terms of the Creative Commons Attribution License (CC BY). The use, distribution or reproduction in other forums is permitted, provided the original author(s) and the copyright owner are credited and that the original publication in this journal is cited, in accordance with accepted academic practice. No use, distribution or reproduction is permitted which does not comply with these terms.
spellingShingle Genetics
Guo, Kejian
Zhou, Xuan
Chen, Xigui
Wu, Yili
Liu, Chuanxin
Kong, Qingsheng
Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population
title Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population
title_full Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population
title_fullStr Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population
title_full_unstemmed Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population
title_short Expanded Newborn Screening for Inborn Errors of Metabolism and Genetic Characteristics in a Chinese Population
title_sort expanded newborn screening for inborn errors of metabolism and genetic characteristics in a chinese population
topic Genetics
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC5920142/
https://www.ncbi.nlm.nih.gov/pubmed/29731766
http://dx.doi.org/10.3389/fgene.2018.00122
work_keys_str_mv AT guokejian expandednewbornscreeningforinbornerrorsofmetabolismandgeneticcharacteristicsinachinesepopulation
AT zhouxuan expandednewbornscreeningforinbornerrorsofmetabolismandgeneticcharacteristicsinachinesepopulation
AT chenxigui expandednewbornscreeningforinbornerrorsofmetabolismandgeneticcharacteristicsinachinesepopulation
AT wuyili expandednewbornscreeningforinbornerrorsofmetabolismandgeneticcharacteristicsinachinesepopulation
AT liuchuanxin expandednewbornscreeningforinbornerrorsofmetabolismandgeneticcharacteristicsinachinesepopulation
AT kongqingsheng expandednewbornscreeningforinbornerrorsofmetabolismandgeneticcharacteristicsinachinesepopulation