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A pilot study of circulating microRNAs as potential biomarkers of Fabry disease
Patients suffering from Fabry disease (FD), a lysosomal storage disorder, show a broad range of symptoms and the diagnosis followed by the therapeutic decision remains a great challenge. The biomarkers available today have not proven to be useful for predicting the evolution of the disease and for a...
Autores principales: | , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Impact Journals LLC
2018
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6007950/ https://www.ncbi.nlm.nih.gov/pubmed/29937989 http://dx.doi.org/10.18632/oncotarget.25542 |
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author | Cammarata, Giuseppe Scalia, Simone Colomba, Paolo Zizzo, Carmela Pisani, Antonio Riccio, Eleonora Montalbano, Michaela Alessandro, Riccardo Giordano, Antonello Duro, Giovanni |
author_facet | Cammarata, Giuseppe Scalia, Simone Colomba, Paolo Zizzo, Carmela Pisani, Antonio Riccio, Eleonora Montalbano, Michaela Alessandro, Riccardo Giordano, Antonello Duro, Giovanni |
author_sort | Cammarata, Giuseppe |
collection | PubMed |
description | Patients suffering from Fabry disease (FD), a lysosomal storage disorder, show a broad range of symptoms and the diagnosis followed by the therapeutic decision remains a great challenge. The biomarkers available today have not proven to be useful for predicting the evolution of the disease and for assessing response to therapy in many patients. Here, we used high-throughput microRNA profiling methodology to identify a specific circulating microRNA profile in FD patients. We discovered a pattern of 10 microRNAs able to identify FD patients when compared to healthy controls. Notably, two of these: the miR199a-5p and the miR-126-3p are able to discriminate FDs from the control subjects with left ventricular hypertrophy, a frequent but non-specific FD symptom. These same microRNAs are also sensitive to enzyme replacement therapy showing variation in the subjects under treatment. Furthermore, two other microRNAs of the profile, the miR-423-5p and the miR-451a, seem useful to highlight cardiac involvement in FD patients. A literature and database search revealed that miR-199a-5p, miR-126-3p, miR-423-5p and miR-451a are known to be linked to pathological states that occur during the FD development. In particular, miR-199a-5p, and miR-126-3p are involved in endothelial dysfunction and miR-423-5p and miR-451a in myocardial remodeling. In conclusion, in this study we identified a common plasma microRNA profile in FD patients, useful not only for the correct classification of Fabry patients regardless of sex and age, but also to evaluate the response to therapy. Furthermore, our observations suggest that some microRNAs of this profile demonstrate prognostic qualities. |
format | Online Article Text |
id | pubmed-6007950 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2018 |
publisher | Impact Journals LLC |
record_format | MEDLINE/PubMed |
spelling | pubmed-60079502018-06-22 A pilot study of circulating microRNAs as potential biomarkers of Fabry disease Cammarata, Giuseppe Scalia, Simone Colomba, Paolo Zizzo, Carmela Pisani, Antonio Riccio, Eleonora Montalbano, Michaela Alessandro, Riccardo Giordano, Antonello Duro, Giovanni Oncotarget Research Paper: Pathology Patients suffering from Fabry disease (FD), a lysosomal storage disorder, show a broad range of symptoms and the diagnosis followed by the therapeutic decision remains a great challenge. The biomarkers available today have not proven to be useful for predicting the evolution of the disease and for assessing response to therapy in many patients. Here, we used high-throughput microRNA profiling methodology to identify a specific circulating microRNA profile in FD patients. We discovered a pattern of 10 microRNAs able to identify FD patients when compared to healthy controls. Notably, two of these: the miR199a-5p and the miR-126-3p are able to discriminate FDs from the control subjects with left ventricular hypertrophy, a frequent but non-specific FD symptom. These same microRNAs are also sensitive to enzyme replacement therapy showing variation in the subjects under treatment. Furthermore, two other microRNAs of the profile, the miR-423-5p and the miR-451a, seem useful to highlight cardiac involvement in FD patients. A literature and database search revealed that miR-199a-5p, miR-126-3p, miR-423-5p and miR-451a are known to be linked to pathological states that occur during the FD development. In particular, miR-199a-5p, and miR-126-3p are involved in endothelial dysfunction and miR-423-5p and miR-451a in myocardial remodeling. In conclusion, in this study we identified a common plasma microRNA profile in FD patients, useful not only for the correct classification of Fabry patients regardless of sex and age, but also to evaluate the response to therapy. Furthermore, our observations suggest that some microRNAs of this profile demonstrate prognostic qualities. Impact Journals LLC 2018-06-08 /pmc/articles/PMC6007950/ /pubmed/29937989 http://dx.doi.org/10.18632/oncotarget.25542 Text en Copyright: © 2018 Cammarata et al. http://creativecommons.org/licenses/by/3.0/ This article is distributed under the terms of the Creative Commons Attribution License (http://creativecommons.org/licenses/by/3.0/) (CC-BY), which permits unrestricted use and redistribution provided that the original author and source are credited. |
spellingShingle | Research Paper: Pathology Cammarata, Giuseppe Scalia, Simone Colomba, Paolo Zizzo, Carmela Pisani, Antonio Riccio, Eleonora Montalbano, Michaela Alessandro, Riccardo Giordano, Antonello Duro, Giovanni A pilot study of circulating microRNAs as potential biomarkers of Fabry disease |
title | A pilot study of circulating microRNAs as potential biomarkers of Fabry disease |
title_full | A pilot study of circulating microRNAs as potential biomarkers of Fabry disease |
title_fullStr | A pilot study of circulating microRNAs as potential biomarkers of Fabry disease |
title_full_unstemmed | A pilot study of circulating microRNAs as potential biomarkers of Fabry disease |
title_short | A pilot study of circulating microRNAs as potential biomarkers of Fabry disease |
title_sort | pilot study of circulating micrornas as potential biomarkers of fabry disease |
topic | Research Paper: Pathology |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6007950/ https://www.ncbi.nlm.nih.gov/pubmed/29937989 http://dx.doi.org/10.18632/oncotarget.25542 |
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