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Prelamin A causes aberrant myonuclear arrangement and results in muscle fiber weakness
Physiological and premature aging are frequently associated with an accumulation of prelamin A, a precursor of lamin A, in the nuclear envelope of various cell types. Here, we aimed to underpin the hitherto unknown mechanisms by which prelamin A alters myonuclear organization and muscle fiber functi...
Autores principales: | , , , , , , , , , , , , , , , , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
American Society for Clinical Investigation
2018
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Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6237469/ https://www.ncbi.nlm.nih.gov/pubmed/30282816 http://dx.doi.org/10.1172/jci.insight.120920 |
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author | Levy, Yotam Ross, Jacob A. Niglas, Marili Snetkov, Vladimir A. Lynham, Steven Liao, Chen-Yu Puckelwartz, Megan J. Hsu, Yueh-Mei McNally, Elizabeth M. Alsheimer, Manfred Harridge, Stephen D.R. Young, Stephen G. Fong, Loren G. Español, Yaiza Lopez-Otin, Carlos Kennedy, Brian K. Lowe, Dawn A. Ochala, Julien |
author_facet | Levy, Yotam Ross, Jacob A. Niglas, Marili Snetkov, Vladimir A. Lynham, Steven Liao, Chen-Yu Puckelwartz, Megan J. Hsu, Yueh-Mei McNally, Elizabeth M. Alsheimer, Manfred Harridge, Stephen D.R. Young, Stephen G. Fong, Loren G. Español, Yaiza Lopez-Otin, Carlos Kennedy, Brian K. Lowe, Dawn A. Ochala, Julien |
author_sort | Levy, Yotam |
collection | PubMed |
description | Physiological and premature aging are frequently associated with an accumulation of prelamin A, a precursor of lamin A, in the nuclear envelope of various cell types. Here, we aimed to underpin the hitherto unknown mechanisms by which prelamin A alters myonuclear organization and muscle fiber function. By experimentally studying membrane-permeabilized myofibers from various transgenic mouse lines, our results indicate that, in the presence of prelamin A, the abundance of nuclei and myosin content is markedly reduced within muscle fibers. This leads to a concept by which the remaining myonuclei are very distant from each other and are pushed to function beyond their maximum cytoplasmic capacity, ultimately inducing muscle fiber weakness. |
format | Online Article Text |
id | pubmed-6237469 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2018 |
publisher | American Society for Clinical Investigation |
record_format | MEDLINE/PubMed |
spelling | pubmed-62374692018-11-21 Prelamin A causes aberrant myonuclear arrangement and results in muscle fiber weakness Levy, Yotam Ross, Jacob A. Niglas, Marili Snetkov, Vladimir A. Lynham, Steven Liao, Chen-Yu Puckelwartz, Megan J. Hsu, Yueh-Mei McNally, Elizabeth M. Alsheimer, Manfred Harridge, Stephen D.R. Young, Stephen G. Fong, Loren G. Español, Yaiza Lopez-Otin, Carlos Kennedy, Brian K. Lowe, Dawn A. Ochala, Julien JCI Insight Research Article Physiological and premature aging are frequently associated with an accumulation of prelamin A, a precursor of lamin A, in the nuclear envelope of various cell types. Here, we aimed to underpin the hitherto unknown mechanisms by which prelamin A alters myonuclear organization and muscle fiber function. By experimentally studying membrane-permeabilized myofibers from various transgenic mouse lines, our results indicate that, in the presence of prelamin A, the abundance of nuclei and myosin content is markedly reduced within muscle fibers. This leads to a concept by which the remaining myonuclei are very distant from each other and are pushed to function beyond their maximum cytoplasmic capacity, ultimately inducing muscle fiber weakness. American Society for Clinical Investigation 2018-10-04 /pmc/articles/PMC6237469/ /pubmed/30282816 http://dx.doi.org/10.1172/jci.insight.120920 Text en Copyright © 2018 Levy et al. http://creativecommons.org/licenses/by/4.0/ This work is licensed under the Creative Commons Attribution 4.0 International License. |
spellingShingle | Research Article Levy, Yotam Ross, Jacob A. Niglas, Marili Snetkov, Vladimir A. Lynham, Steven Liao, Chen-Yu Puckelwartz, Megan J. Hsu, Yueh-Mei McNally, Elizabeth M. Alsheimer, Manfred Harridge, Stephen D.R. Young, Stephen G. Fong, Loren G. Español, Yaiza Lopez-Otin, Carlos Kennedy, Brian K. Lowe, Dawn A. Ochala, Julien Prelamin A causes aberrant myonuclear arrangement and results in muscle fiber weakness |
title | Prelamin A causes aberrant myonuclear arrangement and results in muscle fiber weakness |
title_full | Prelamin A causes aberrant myonuclear arrangement and results in muscle fiber weakness |
title_fullStr | Prelamin A causes aberrant myonuclear arrangement and results in muscle fiber weakness |
title_full_unstemmed | Prelamin A causes aberrant myonuclear arrangement and results in muscle fiber weakness |
title_short | Prelamin A causes aberrant myonuclear arrangement and results in muscle fiber weakness |
title_sort | prelamin a causes aberrant myonuclear arrangement and results in muscle fiber weakness |
topic | Research Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6237469/ https://www.ncbi.nlm.nih.gov/pubmed/30282816 http://dx.doi.org/10.1172/jci.insight.120920 |
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