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Spectrum and Prevalence of Pathogenic Variants in Ovarian Cancer Susceptibility Genes in a Group of 333 Patients

Constitutional loss-of-function pathogenic variants in the tumor suppressor genes BRCA1 and BRCA2 are widely associated with an elevated risk of ovarian cancer (OC). As only ~15% of OC individuals carry the BRCA1/2 pathogenic variants, the identification of other potential OC-susceptibility genes is...

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Autores principales: Koczkowska, Magdalena, Krawczynska, Natalia, Stukan, Maciej, Kuzniacka, Alina, Brozek, Izabela, Sniadecki, Marcin, Debniak, Jaroslaw, Wydra, Dariusz, Biernat, Wojciech, Kozlowski, Piotr, Limon, Janusz, Wasag, Bartosz, Ratajska, Magdalena
Formato: Online Artículo Texto
Lenguaje:English
Publicado: MDPI 2018
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6266089/
https://www.ncbi.nlm.nih.gov/pubmed/30441849
http://dx.doi.org/10.3390/cancers10110442
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author Koczkowska, Magdalena
Krawczynska, Natalia
Stukan, Maciej
Kuzniacka, Alina
Brozek, Izabela
Sniadecki, Marcin
Debniak, Jaroslaw
Wydra, Dariusz
Biernat, Wojciech
Kozlowski, Piotr
Limon, Janusz
Wasag, Bartosz
Ratajska, Magdalena
author_facet Koczkowska, Magdalena
Krawczynska, Natalia
Stukan, Maciej
Kuzniacka, Alina
Brozek, Izabela
Sniadecki, Marcin
Debniak, Jaroslaw
Wydra, Dariusz
Biernat, Wojciech
Kozlowski, Piotr
Limon, Janusz
Wasag, Bartosz
Ratajska, Magdalena
author_sort Koczkowska, Magdalena
collection PubMed
description Constitutional loss-of-function pathogenic variants in the tumor suppressor genes BRCA1 and BRCA2 are widely associated with an elevated risk of ovarian cancer (OC). As only ~15% of OC individuals carry the BRCA1/2 pathogenic variants, the identification of other potential OC-susceptibility genes is of great clinical importance. Here, we established the prevalence and spectrum of the germline pathogenic variants in the BRCA1/2 and 23 other cancer-related genes in a large Polish population of 333 unselected OC cases. Approximately 21% of cases (71/333) carried the BRCA1/2 pathogenic or likely pathogenic variants, with c.5266dup (p.Gln1756Profs*74) and c.3700_3704del (p.Val1234Glnfs*8) being the most prevalent. Additionally, ~6% of women (20/333) were carriers of the pathogenic or likely pathogenic variants in other cancer-related genes, with NBN and CHEK2 reported as the most frequently mutated, accounting for 1.8% (6/333) and 1.2% (4/333) of cases, respectively. We also found ten pathogenic or likely pathogenic variants in other genes: 1/333 in APC, 1/333 in ATM, 2/333 in BLM, 1/333 in BRIP1, 1/333 in MRE11A, 2/333 in PALB2, 1/333 in RAD50, and 1/333 in RAD51C, accounting for 50% of all detected variants in moderate- and low-penetrant genes. Our findings confirmed the presence of the additional OC-associated genes in the Polish population that may improve the personalized risk assessment of these individuals.
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spelling pubmed-62660892018-12-03 Spectrum and Prevalence of Pathogenic Variants in Ovarian Cancer Susceptibility Genes in a Group of 333 Patients Koczkowska, Magdalena Krawczynska, Natalia Stukan, Maciej Kuzniacka, Alina Brozek, Izabela Sniadecki, Marcin Debniak, Jaroslaw Wydra, Dariusz Biernat, Wojciech Kozlowski, Piotr Limon, Janusz Wasag, Bartosz Ratajska, Magdalena Cancers (Basel) Article Constitutional loss-of-function pathogenic variants in the tumor suppressor genes BRCA1 and BRCA2 are widely associated with an elevated risk of ovarian cancer (OC). As only ~15% of OC individuals carry the BRCA1/2 pathogenic variants, the identification of other potential OC-susceptibility genes is of great clinical importance. Here, we established the prevalence and spectrum of the germline pathogenic variants in the BRCA1/2 and 23 other cancer-related genes in a large Polish population of 333 unselected OC cases. Approximately 21% of cases (71/333) carried the BRCA1/2 pathogenic or likely pathogenic variants, with c.5266dup (p.Gln1756Profs*74) and c.3700_3704del (p.Val1234Glnfs*8) being the most prevalent. Additionally, ~6% of women (20/333) were carriers of the pathogenic or likely pathogenic variants in other cancer-related genes, with NBN and CHEK2 reported as the most frequently mutated, accounting for 1.8% (6/333) and 1.2% (4/333) of cases, respectively. We also found ten pathogenic or likely pathogenic variants in other genes: 1/333 in APC, 1/333 in ATM, 2/333 in BLM, 1/333 in BRIP1, 1/333 in MRE11A, 2/333 in PALB2, 1/333 in RAD50, and 1/333 in RAD51C, accounting for 50% of all detected variants in moderate- and low-penetrant genes. Our findings confirmed the presence of the additional OC-associated genes in the Polish population that may improve the personalized risk assessment of these individuals. MDPI 2018-11-14 /pmc/articles/PMC6266089/ /pubmed/30441849 http://dx.doi.org/10.3390/cancers10110442 Text en © 2018 by the authors. Licensee MDPI, Basel, Switzerland. This article is an open access article distributed under the terms and conditions of the Creative Commons Attribution (CC BY) license (http://creativecommons.org/licenses/by/4.0/).
spellingShingle Article
Koczkowska, Magdalena
Krawczynska, Natalia
Stukan, Maciej
Kuzniacka, Alina
Brozek, Izabela
Sniadecki, Marcin
Debniak, Jaroslaw
Wydra, Dariusz
Biernat, Wojciech
Kozlowski, Piotr
Limon, Janusz
Wasag, Bartosz
Ratajska, Magdalena
Spectrum and Prevalence of Pathogenic Variants in Ovarian Cancer Susceptibility Genes in a Group of 333 Patients
title Spectrum and Prevalence of Pathogenic Variants in Ovarian Cancer Susceptibility Genes in a Group of 333 Patients
title_full Spectrum and Prevalence of Pathogenic Variants in Ovarian Cancer Susceptibility Genes in a Group of 333 Patients
title_fullStr Spectrum and Prevalence of Pathogenic Variants in Ovarian Cancer Susceptibility Genes in a Group of 333 Patients
title_full_unstemmed Spectrum and Prevalence of Pathogenic Variants in Ovarian Cancer Susceptibility Genes in a Group of 333 Patients
title_short Spectrum and Prevalence of Pathogenic Variants in Ovarian Cancer Susceptibility Genes in a Group of 333 Patients
title_sort spectrum and prevalence of pathogenic variants in ovarian cancer susceptibility genes in a group of 333 patients
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6266089/
https://www.ncbi.nlm.nih.gov/pubmed/30441849
http://dx.doi.org/10.3390/cancers10110442
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