Cargando…
Stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach
Amyotrophic lateral sclerosis (ALS) is a fatal neurodegenerative disease where substantial heterogeneity in clinical presentation urgently requires a better stratification of patients for the development of drug trials and clinical care. In this study we explored stratification through a crowdsourci...
Autores principales: | , , , , , , , , , , , , , , , , , , , , , , , , |
---|---|
Formato: | Online Artículo Texto |
Lenguaje: | English |
Publicado: |
Nature Publishing Group UK
2019
|
Materias: | |
Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6345935/ https://www.ncbi.nlm.nih.gov/pubmed/30679616 http://dx.doi.org/10.1038/s41598-018-36873-4 |
_version_ | 1783389661160275968 |
---|---|
author | Kueffner, Robert Zach, Neta Bronfeld, Maya Norel, Raquel Atassi, Nazem Balagurusamy, Venkat Di Camillo, Barbara Chio, Adriano Cudkowicz, Merit Dillenberger, Donna Garcia-Garcia, Javier Hardiman, Orla Hoff, Bruce Knight, Joshua Leitner, Melanie L. Li, Guang Mangravite, Lara Norman, Thea Wang, Liuxia Xiao, Jinfeng Fang, Wen-Chieh Peng, Jian Yang, Chen Chang, Huan-Jui Stolovitzky, Gustavo |
author_facet | Kueffner, Robert Zach, Neta Bronfeld, Maya Norel, Raquel Atassi, Nazem Balagurusamy, Venkat Di Camillo, Barbara Chio, Adriano Cudkowicz, Merit Dillenberger, Donna Garcia-Garcia, Javier Hardiman, Orla Hoff, Bruce Knight, Joshua Leitner, Melanie L. Li, Guang Mangravite, Lara Norman, Thea Wang, Liuxia Xiao, Jinfeng Fang, Wen-Chieh Peng, Jian Yang, Chen Chang, Huan-Jui Stolovitzky, Gustavo |
author_sort | Kueffner, Robert |
collection | PubMed |
description | Amyotrophic lateral sclerosis (ALS) is a fatal neurodegenerative disease where substantial heterogeneity in clinical presentation urgently requires a better stratification of patients for the development of drug trials and clinical care. In this study we explored stratification through a crowdsourcing approach, the DREAM Prize4Life ALS Stratification Challenge. Using data from >10,000 patients from ALS clinical trials and 1479 patients from community-based patient registers, more than 30 teams developed new approaches for machine learning and clustering, outperforming the best current predictions of disease outcome. We propose a new method to integrate and analyze patient clusters across methods, showing a clear pattern of consistent and clinically relevant sub-groups of patients that also enabled the reliable classification of new patients. Our analyses reveal novel insights in ALS and describe for the first time the potential of a crowdsourcing to uncover hidden patient sub-populations, and to accelerate disease understanding and therapeutic development. |
format | Online Article Text |
id | pubmed-6345935 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2019 |
publisher | Nature Publishing Group UK |
record_format | MEDLINE/PubMed |
spelling | pubmed-63459352019-01-29 Stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach Kueffner, Robert Zach, Neta Bronfeld, Maya Norel, Raquel Atassi, Nazem Balagurusamy, Venkat Di Camillo, Barbara Chio, Adriano Cudkowicz, Merit Dillenberger, Donna Garcia-Garcia, Javier Hardiman, Orla Hoff, Bruce Knight, Joshua Leitner, Melanie L. Li, Guang Mangravite, Lara Norman, Thea Wang, Liuxia Xiao, Jinfeng Fang, Wen-Chieh Peng, Jian Yang, Chen Chang, Huan-Jui Stolovitzky, Gustavo Sci Rep Article Amyotrophic lateral sclerosis (ALS) is a fatal neurodegenerative disease where substantial heterogeneity in clinical presentation urgently requires a better stratification of patients for the development of drug trials and clinical care. In this study we explored stratification through a crowdsourcing approach, the DREAM Prize4Life ALS Stratification Challenge. Using data from >10,000 patients from ALS clinical trials and 1479 patients from community-based patient registers, more than 30 teams developed new approaches for machine learning and clustering, outperforming the best current predictions of disease outcome. We propose a new method to integrate and analyze patient clusters across methods, showing a clear pattern of consistent and clinically relevant sub-groups of patients that also enabled the reliable classification of new patients. Our analyses reveal novel insights in ALS and describe for the first time the potential of a crowdsourcing to uncover hidden patient sub-populations, and to accelerate disease understanding and therapeutic development. Nature Publishing Group UK 2019-01-24 /pmc/articles/PMC6345935/ /pubmed/30679616 http://dx.doi.org/10.1038/s41598-018-36873-4 Text en © The Author(s) 2019 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/. |
spellingShingle | Article Kueffner, Robert Zach, Neta Bronfeld, Maya Norel, Raquel Atassi, Nazem Balagurusamy, Venkat Di Camillo, Barbara Chio, Adriano Cudkowicz, Merit Dillenberger, Donna Garcia-Garcia, Javier Hardiman, Orla Hoff, Bruce Knight, Joshua Leitner, Melanie L. Li, Guang Mangravite, Lara Norman, Thea Wang, Liuxia Xiao, Jinfeng Fang, Wen-Chieh Peng, Jian Yang, Chen Chang, Huan-Jui Stolovitzky, Gustavo Stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach |
title | Stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach |
title_full | Stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach |
title_fullStr | Stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach |
title_full_unstemmed | Stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach |
title_short | Stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach |
title_sort | stratification of amyotrophic lateral sclerosis patients: a crowdsourcing approach |
topic | Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6345935/ https://www.ncbi.nlm.nih.gov/pubmed/30679616 http://dx.doi.org/10.1038/s41598-018-36873-4 |
work_keys_str_mv | AT kueffnerrobert stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT zachneta stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT bronfeldmaya stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT norelraquel stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT atassinazem stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT balagurusamyvenkat stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT dicamillobarbara stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT chioadriano stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT cudkowiczmerit stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT dillenbergerdonna stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT garciagarciajavier stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT hardimanorla stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT hoffbruce stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT knightjoshua stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT leitnermelaniel stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT liguang stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT mangravitelara stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT normanthea stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT wangliuxia stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT xiaojinfeng stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT fangwenchieh stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT pengjian stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT yangchen stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT changhuanjui stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach AT stolovitzkygustavo stratificationofamyotrophiclateralsclerosispatientsacrowdsourcingapproach |