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Deletion of Limk1 and Limk2 in mice does not alter cochlear development or auditory function

Inherited hearing loss is associated with gene mutations that result in sensory hair cell (HC) malfunction. HC structure is defined by the cytoskeleton, which is mainly composed of actin filaments and actin-binding partners. LIM motif-containing protein kinases (LIMKs) are the primary regulators of...

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Autores principales: Fang, Qiaojun, Zhang, Yuhua, Da, Peng, Shao, Buwei, Pan, Haolai, He, Zuhong, Cheng, Cheng, Li, Dan, Guo, Jiaqi, Wu, Xiaohan, Guan, Ming, Liao, Menghui, Zhang, Yuan, Sha, Suhua, Zhou, Zikai, Wang, Jian, Wang, Tian, Su, Kaiming, Chai, Renjie, Chen, Fangyi
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Nature Publishing Group UK 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6399249/
https://www.ncbi.nlm.nih.gov/pubmed/30833597
http://dx.doi.org/10.1038/s41598-019-39769-z
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author Fang, Qiaojun
Zhang, Yuhua
Da, Peng
Shao, Buwei
Pan, Haolai
He, Zuhong
Cheng, Cheng
Li, Dan
Guo, Jiaqi
Wu, Xiaohan
Guan, Ming
Liao, Menghui
Zhang, Yuan
Sha, Suhua
Zhou, Zikai
Wang, Jian
Wang, Tian
Su, Kaiming
Chai, Renjie
Chen, Fangyi
author_facet Fang, Qiaojun
Zhang, Yuhua
Da, Peng
Shao, Buwei
Pan, Haolai
He, Zuhong
Cheng, Cheng
Li, Dan
Guo, Jiaqi
Wu, Xiaohan
Guan, Ming
Liao, Menghui
Zhang, Yuan
Sha, Suhua
Zhou, Zikai
Wang, Jian
Wang, Tian
Su, Kaiming
Chai, Renjie
Chen, Fangyi
author_sort Fang, Qiaojun
collection PubMed
description Inherited hearing loss is associated with gene mutations that result in sensory hair cell (HC) malfunction. HC structure is defined by the cytoskeleton, which is mainly composed of actin filaments and actin-binding partners. LIM motif-containing protein kinases (LIMKs) are the primary regulators of actin dynamics and consist of two members: LIMK1 and LIMK2. Actin arrangement is directly involved in the regulation of cytoskeletal structure and the maturation of synapses in the central nervous system, and LIMKs are involved in structural plasticity by controlling the activation of the actin depolymerization protein cofilin in the olfactory system and in the hippocampus. However, the expression pattern and the role of LIMKs in mouse cochlear development and synapse function also need to be further studied. We show here that the Limk genes are expressed in the mouse cochlea. We examined the morphology and the afferent synapse densities of HCs and measured the auditory function in Limk1 and Limk2 double knockout (DKO) mice. We found that the loss of Limk1 and Limk2 did not appear to affect the overall development of the cochlea, including the number of HCs and the structure of hair bundles. There were no significant differences in auditory thresholds between DKO mice and wild-type littermates. However, the expression of p-cofilin in the DKO mice was significantly decreased. Additionally, no significant differences were found in the number or distribution of ribbon synapses between the DKO and wild-type mice. In summary, our data suggest that the Limk genes play a different role in the development of the cochlea compared to their role in the central nervous system.
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spelling pubmed-63992492019-03-07 Deletion of Limk1 and Limk2 in mice does not alter cochlear development or auditory function Fang, Qiaojun Zhang, Yuhua Da, Peng Shao, Buwei Pan, Haolai He, Zuhong Cheng, Cheng Li, Dan Guo, Jiaqi Wu, Xiaohan Guan, Ming Liao, Menghui Zhang, Yuan Sha, Suhua Zhou, Zikai Wang, Jian Wang, Tian Su, Kaiming Chai, Renjie Chen, Fangyi Sci Rep Article Inherited hearing loss is associated with gene mutations that result in sensory hair cell (HC) malfunction. HC structure is defined by the cytoskeleton, which is mainly composed of actin filaments and actin-binding partners. LIM motif-containing protein kinases (LIMKs) are the primary regulators of actin dynamics and consist of two members: LIMK1 and LIMK2. Actin arrangement is directly involved in the regulation of cytoskeletal structure and the maturation of synapses in the central nervous system, and LIMKs are involved in structural plasticity by controlling the activation of the actin depolymerization protein cofilin in the olfactory system and in the hippocampus. However, the expression pattern and the role of LIMKs in mouse cochlear development and synapse function also need to be further studied. We show here that the Limk genes are expressed in the mouse cochlea. We examined the morphology and the afferent synapse densities of HCs and measured the auditory function in Limk1 and Limk2 double knockout (DKO) mice. We found that the loss of Limk1 and Limk2 did not appear to affect the overall development of the cochlea, including the number of HCs and the structure of hair bundles. There were no significant differences in auditory thresholds between DKO mice and wild-type littermates. However, the expression of p-cofilin in the DKO mice was significantly decreased. Additionally, no significant differences were found in the number or distribution of ribbon synapses between the DKO and wild-type mice. In summary, our data suggest that the Limk genes play a different role in the development of the cochlea compared to their role in the central nervous system. Nature Publishing Group UK 2019-03-04 /pmc/articles/PMC6399249/ /pubmed/30833597 http://dx.doi.org/10.1038/s41598-019-39769-z Text en © The Author(s) 2019 Open Access This article is licensed under a Creative Commons Attribution 4.0 International License, which permits use, sharing, adaptation, distribution and reproduction in any medium or format, as long as you give appropriate credit to the original author(s) and the source, provide a link to the Creative Commons license, and indicate if changes were made. The images or other third party material in this article are included in the article’s Creative Commons license, unless indicated otherwise in a credit line to the material. If material is not included in the article’s Creative Commons license and your intended use is not permitted by statutory regulation or exceeds the permitted use, you will need to obtain permission directly from the copyright holder. To view a copy of this license, visit http://creativecommons.org/licenses/by/4.0/.
spellingShingle Article
Fang, Qiaojun
Zhang, Yuhua
Da, Peng
Shao, Buwei
Pan, Haolai
He, Zuhong
Cheng, Cheng
Li, Dan
Guo, Jiaqi
Wu, Xiaohan
Guan, Ming
Liao, Menghui
Zhang, Yuan
Sha, Suhua
Zhou, Zikai
Wang, Jian
Wang, Tian
Su, Kaiming
Chai, Renjie
Chen, Fangyi
Deletion of Limk1 and Limk2 in mice does not alter cochlear development or auditory function
title Deletion of Limk1 and Limk2 in mice does not alter cochlear development or auditory function
title_full Deletion of Limk1 and Limk2 in mice does not alter cochlear development or auditory function
title_fullStr Deletion of Limk1 and Limk2 in mice does not alter cochlear development or auditory function
title_full_unstemmed Deletion of Limk1 and Limk2 in mice does not alter cochlear development or auditory function
title_short Deletion of Limk1 and Limk2 in mice does not alter cochlear development or auditory function
title_sort deletion of limk1 and limk2 in mice does not alter cochlear development or auditory function
topic Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6399249/
https://www.ncbi.nlm.nih.gov/pubmed/30833597
http://dx.doi.org/10.1038/s41598-019-39769-z
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