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Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia
Three members of the angiopoietin-like (ANGPTL) protein family-ANGPTL3, ANGPTL4 and ANGPTL8- are important regulators of plasma lipoproteins. They inhibit the enzyme lipoprotein lipase, which plays a key role in the intravascular lipolysis of triglycerides present in some lipoprotein classes. This r...
Autores principales: | , , |
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Formato: | Online Artículo Texto |
Lenguaje: | English |
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Editorial Department of Journal of Biomedical Research
2019
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Acceso en línea: | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6477171/ https://www.ncbi.nlm.nih.gov/pubmed/29752428 http://dx.doi.org/10.7555/JBR.32.20170114 |
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author | Tarugi, Patrizia Bertolini, Stefano Calandra, Sebastiano |
author_facet | Tarugi, Patrizia Bertolini, Stefano Calandra, Sebastiano |
author_sort | Tarugi, Patrizia |
collection | PubMed |
description | Three members of the angiopoietin-like (ANGPTL) protein family-ANGPTL3, ANGPTL4 and ANGPTL8- are important regulators of plasma lipoproteins. They inhibit the enzyme lipoprotein lipase, which plays a key role in the intravascular lipolysis of triglycerides present in some lipoprotein classes. This review focuses on the role of ANGPTL3 as emerged from the study of genetic variants of Angptl3 gene in mice and humans. Both loss of function genetic variants and inactivation of Angptl3 gene in mice are associated with a marked reduction of plasma levels of triglyceride and cholesterol and an increased activity of lipoprotein lipase and endothelial lipase. In humans with ANGPTL3 deficiency, caused by homozygous loss of function (LOF) variants of Angptl3 gene, the levels of all plasma lipoproteins are greatly reduced. This plasma lipid disorder referred to as familial combined hypolipidemia (FHBL2) does not appear to be associated with distinct pathological manifestations. Heterozygous carriers of LOF variants have reduced plasma levels of total cholesterol and triglycerides and are at lower risk of developing atherosclerotic cardiovascular disease, as compared to non-carriers. These observations have paved the way to the development of strategies to reduce the plasma level of atherogenic lipoproteins in man by the inactivation of ANGPTL3, using either a specific monoclonal antibody or anti-sense oligonucleotides. |
format | Online Article Text |
id | pubmed-6477171 |
institution | National Center for Biotechnology Information |
language | English |
publishDate | 2019 |
publisher | Editorial Department of Journal of Biomedical Research |
record_format | MEDLINE/PubMed |
spelling | pubmed-64771712019-06-05 Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia Tarugi, Patrizia Bertolini, Stefano Calandra, Sebastiano J Biomed Res Review Article Three members of the angiopoietin-like (ANGPTL) protein family-ANGPTL3, ANGPTL4 and ANGPTL8- are important regulators of plasma lipoproteins. They inhibit the enzyme lipoprotein lipase, which plays a key role in the intravascular lipolysis of triglycerides present in some lipoprotein classes. This review focuses on the role of ANGPTL3 as emerged from the study of genetic variants of Angptl3 gene in mice and humans. Both loss of function genetic variants and inactivation of Angptl3 gene in mice are associated with a marked reduction of plasma levels of triglyceride and cholesterol and an increased activity of lipoprotein lipase and endothelial lipase. In humans with ANGPTL3 deficiency, caused by homozygous loss of function (LOF) variants of Angptl3 gene, the levels of all plasma lipoproteins are greatly reduced. This plasma lipid disorder referred to as familial combined hypolipidemia (FHBL2) does not appear to be associated with distinct pathological manifestations. Heterozygous carriers of LOF variants have reduced plasma levels of total cholesterol and triglycerides and are at lower risk of developing atherosclerotic cardiovascular disease, as compared to non-carriers. These observations have paved the way to the development of strategies to reduce the plasma level of atherogenic lipoproteins in man by the inactivation of ANGPTL3, using either a specific monoclonal antibody or anti-sense oligonucleotides. Editorial Department of Journal of Biomedical Research 2019 /pmc/articles/PMC6477171/ /pubmed/29752428 http://dx.doi.org/10.7555/JBR.32.20170114 Text en /creativecommons.org/licenses/by/4.0/ This is an open access article under the Creative Commons Attribution (CC BY 4.0) license, which permits others to distribute, remix, adapt and build upon this work, for commercial use, provided the original work is properly cited |
spellingShingle | Review Article Tarugi, Patrizia Bertolini, Stefano Calandra, Sebastiano Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia |
title | Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia |
title_full | Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia |
title_fullStr | Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia |
title_full_unstemmed | Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia |
title_short | Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia |
title_sort | angiopoietin-like protein 3 (angptl3) deficiency and familial combined hypolipidemia |
topic | Review Article |
url | https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6477171/ https://www.ncbi.nlm.nih.gov/pubmed/29752428 http://dx.doi.org/10.7555/JBR.32.20170114 |
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