Cargando…

Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia

Three members of the angiopoietin-like (ANGPTL) protein family-ANGPTL3, ANGPTL4 and ANGPTL8- are important regulators of plasma lipoproteins. They inhibit the enzyme lipoprotein lipase, which plays a key role in the intravascular lipolysis of triglycerides present in some lipoprotein classes. This r...

Descripción completa

Detalles Bibliográficos
Autores principales: Tarugi, Patrizia, Bertolini, Stefano, Calandra, Sebastiano
Formato: Online Artículo Texto
Lenguaje:English
Publicado: Editorial Department of Journal of Biomedical Research 2019
Materias:
Acceso en línea:https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6477171/
https://www.ncbi.nlm.nih.gov/pubmed/29752428
http://dx.doi.org/10.7555/JBR.32.20170114
_version_ 1783413012748566528
author Tarugi, Patrizia
Bertolini, Stefano
Calandra, Sebastiano
author_facet Tarugi, Patrizia
Bertolini, Stefano
Calandra, Sebastiano
author_sort Tarugi, Patrizia
collection PubMed
description Three members of the angiopoietin-like (ANGPTL) protein family-ANGPTL3, ANGPTL4 and ANGPTL8- are important regulators of plasma lipoproteins. They inhibit the enzyme lipoprotein lipase, which plays a key role in the intravascular lipolysis of triglycerides present in some lipoprotein classes. This review focuses on the role of ANGPTL3 as emerged from the study of genetic variants of Angptl3 gene in mice and humans. Both loss of function genetic variants and inactivation of Angptl3 gene in mice are associated with a marked reduction of plasma levels of triglyceride and cholesterol and an increased activity of lipoprotein lipase and endothelial lipase. In humans with ANGPTL3 deficiency, caused by homozygous loss of function (LOF) variants of Angptl3 gene, the levels of all plasma lipoproteins are greatly reduced. This plasma lipid disorder referred to as familial combined hypolipidemia (FHBL2) does not appear to be associated with distinct pathological manifestations. Heterozygous carriers of LOF variants have reduced plasma levels of total cholesterol and triglycerides and are at lower risk of developing atherosclerotic cardiovascular disease, as compared to non-carriers. These observations have paved the way to the development of strategies to reduce the plasma level of atherogenic lipoproteins in man by the inactivation of ANGPTL3, using either a specific monoclonal antibody or anti-sense oligonucleotides.
format Online
Article
Text
id pubmed-6477171
institution National Center for Biotechnology Information
language English
publishDate 2019
publisher Editorial Department of Journal of Biomedical Research
record_format MEDLINE/PubMed
spelling pubmed-64771712019-06-05 Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia Tarugi, Patrizia Bertolini, Stefano Calandra, Sebastiano J Biomed Res Review Article Three members of the angiopoietin-like (ANGPTL) protein family-ANGPTL3, ANGPTL4 and ANGPTL8- are important regulators of plasma lipoproteins. They inhibit the enzyme lipoprotein lipase, which plays a key role in the intravascular lipolysis of triglycerides present in some lipoprotein classes. This review focuses on the role of ANGPTL3 as emerged from the study of genetic variants of Angptl3 gene in mice and humans. Both loss of function genetic variants and inactivation of Angptl3 gene in mice are associated with a marked reduction of plasma levels of triglyceride and cholesterol and an increased activity of lipoprotein lipase and endothelial lipase. In humans with ANGPTL3 deficiency, caused by homozygous loss of function (LOF) variants of Angptl3 gene, the levels of all plasma lipoproteins are greatly reduced. This plasma lipid disorder referred to as familial combined hypolipidemia (FHBL2) does not appear to be associated with distinct pathological manifestations. Heterozygous carriers of LOF variants have reduced plasma levels of total cholesterol and triglycerides and are at lower risk of developing atherosclerotic cardiovascular disease, as compared to non-carriers. These observations have paved the way to the development of strategies to reduce the plasma level of atherogenic lipoproteins in man by the inactivation of ANGPTL3, using either a specific monoclonal antibody or anti-sense oligonucleotides. Editorial Department of Journal of Biomedical Research 2019 /pmc/articles/PMC6477171/ /pubmed/29752428 http://dx.doi.org/10.7555/JBR.32.20170114 Text en /creativecommons.org/licenses/by/4.0/ This is an open access article under the Creative Commons Attribution (CC BY 4.0) license, which permits others to distribute, remix, adapt and build upon this work, for commercial use, provided the original work is properly cited
spellingShingle Review Article
Tarugi, Patrizia
Bertolini, Stefano
Calandra, Sebastiano
Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia
title Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia
title_full Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia
title_fullStr Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia
title_full_unstemmed Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia
title_short Angiopoietin-like protein 3 (ANGPTL3) deficiency and familial combined hypolipidemia
title_sort angiopoietin-like protein 3 (angptl3) deficiency and familial combined hypolipidemia
topic Review Article
url https://www.ncbi.nlm.nih.gov/pmc/articles/PMC6477171/
https://www.ncbi.nlm.nih.gov/pubmed/29752428
http://dx.doi.org/10.7555/JBR.32.20170114
work_keys_str_mv AT tarugipatrizia angiopoietinlikeprotein3angptl3deficiencyandfamilialcombinedhypolipidemia
AT bertolinistefano angiopoietinlikeprotein3angptl3deficiencyandfamilialcombinedhypolipidemia
AT calandrasebastiano angiopoietinlikeprotein3angptl3deficiencyandfamilialcombinedhypolipidemia